| Literature DB >> 28976636 |
Aurélie Marti1, Eulalie Lasseaux2, Khaled Ezzedine3, Christine Léauté-Labrèze1, Franck Boralevi1, Clément Paya4, Valentine Coste4, Vincent Deroissart5, Benoit Arveiler2,6, Alain Taieb1,7, Fanny Morice-Picard1,2.
Abstract
Albinism is a rare genetic disease, comprising syndromic and non-syndromic forms. We assessed clinical and genetic characteristics in a prospective evaluation of 64 patients (33 children and 31 adults) seen at a specialized day hospital. Causative genetic mutations were found in TYR (23/64, 35.9%), OCA2 (19/64, 29.7%), TYRP1 (1/64, 1.6%), SLC45A2 (12/64, 18.7%), C10orf11 (1/64, 1.6%), HPS1 (3/64, 4.7%), HPS5 (1/64, 1.5%), HPS6 (1/64, 1.6%) and GPR143 (2/64, 3.1%). Causative mutations remained undetermined for one patient (1.6%). Heterogeneity for hair and skin phenotype was noted across and within the different genotypes. Skin and hair hypopigmentation did not correlate with visual impairment. The diagnosis of unrecognized syndromic forms and of cases of ocular albinism in this prospective and comprehensive series of patients with albinism in a European setting is remarkable. Photoprotection was overall good but not optimal.Entities:
Keywords: genetics; oculocutaneous albinism; pigmentation
Mesh:
Year: 2017 PMID: 28976636 DOI: 10.1111/pcmr.12651
Source DB: PubMed Journal: Pigment Cell Melanoma Res ISSN: 1755-1471 Impact factor: 4.693