Literature DB >> 18313856

Postnatal analysis of the effect of embryonic knockdown and overexpression of candidate dyslexia susceptibility gene homolog Dcdc2 in the rat.

T J Burbridge1, Y Wang, A J Volz, V J Peschansky, L Lisann, A M Galaburda, J J Lo Turco, G D Rosen.   

Abstract

Embryonic knockdown of candidate dyslexia susceptibility gene (CDSG) homologs in cerebral cortical progenitor cells in the rat results in acute disturbances of neocortical migration. In the current report we investigated the effects of embryonic knockdown and overexpression of the homolog of DCDC2, one of the CDSGs, on the postnatal organization of the cerebral cortex. Using a within-litter design, we transfected cells in rat embryo neocortical ventricular zone around embryonic day (E) 15 with either 1) small hairpin RNA (shRNA) vectors targeting Dcdc2, 2) a DCDC2 overexpression construct, 3) Dcdc2 shRNA along with DCDC2 overexpression construct, 4) an overexpression construct composed of the C terminal domain of DCDC2, or 5) an overexpression construct composed of the DCX terminal domain of DCDC2. RNAi of Dcdc2 resulted in pockets of heterotopic neurons in the periventricular region. Approximately 25% of the transfected brains had hippocampal pyramidal cell migration anomalies. Dcdc2 shRNA-transfected neurons migrated in a bimodal pattern, with approximately 7% of the neurons migrating a short distance from the ventricular zone, and another 30% migrating past their expected lamina. Rats transfected with Dcdc2 shRNA along with the DCDC2 overexpression construct rescued the periventricular heterotopia phenotype, but did not affect the percentage of transfected neurons that migrate past their expected laminar location. There were no malformations associated with any of the overexpression constructs, nor was there a significant laminar disruption of migration. These results support the claim that knockdown of Dcdc2 expression results in neuronal migration disorders similar to those seen in the brains of dyslexics.

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Year:  2008        PMID: 18313856      PMCID: PMC2424111          DOI: 10.1016/j.neuroscience.2008.01.020

Source DB:  PubMed          Journal:  Neuroscience        ISSN: 0306-4522            Impact factor:   3.590


  53 in total

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Journal:  Cell       Date:  1998-01-09       Impact factor: 41.582

4.  Cytoarchitectonic abnormalities in developmental dyslexia: a case study.

Authors:  A M Galaburda; T L Kemper
Journal:  Ann Neurol       Date:  1979-08       Impact factor: 10.422

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Authors:  H J Luhmann; K Raabe
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Authors:  A M Galaburda; G F Sherman; G D Rosen; F Aboitiz; N Geschwind
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  41 in total

1.  Neocortical disruption and behavioral impairments in rats following in utero RNAi of candidate dyslexia risk gene Kiaa0319.

Authors:  Caitlin E Szalkowski; Christopher G Fiondella; Albert M Galaburda; Glenn D Rosen; Joseph J Loturco; R Holly Fitch
Journal:  Int J Dev Neurosci       Date:  2012-02-03       Impact factor: 2.457

2.  Genetic variation in the KIAA0319 5' region as a possible contributor to dyslexia.

Authors:  Adrienne Elbert; Maureen W Lovett; Tasha Cate-Carter; Ashley Pitch; Elizabeth N Kerr; Cathy L Barr
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Review 4.  Neural Noise Hypothesis of Developmental Dyslexia.

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Authors:  Veronica J Peschansky; Timothy J Burbridge; Amy J Volz; Christopher Fiondella; Zach Wissner-Gross; Albert M Galaburda; Joseph J Lo Turco; Glenn D Rosen
Journal:  Cereb Cortex       Date:  2009-08-13       Impact factor: 5.357

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Authors:  L A Gabel; I Marin; J J LoTurco; A Che; C Murphy; M Manglani; S Kass
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8.  Meta-analysis of the association between DCDC2 polymorphisms and risk of dyslexia.

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9.  The effects of Kiaa0319 knockdown on cortical and subcortical anatomy in male rats.

Authors:  Caitlin E Szalkowski; Christopher F Fiondella; Dongnhu T Truong; Glenn D Rosen; Joseph J LoTurco; Roslyn H Fitch
Journal:  Int J Dev Neurosci       Date:  2012-12-05       Impact factor: 2.457

10.  Mutation of the Dyslexia-Associated Gene Dcdc2 Enhances Glutamatergic Synaptic Transmission Between Layer 4 Neurons in Mouse Neocortex.

Authors:  Alicia Che; Dongnhu T Truong; R Holly Fitch; Joseph J LoTurco
Journal:  Cereb Cortex       Date:  2015-08-06       Impact factor: 5.357

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