Literature DB >> 22240007

Factors that influence parents' experiences with results disclosure after newborn screening identifies genetic carrier status for cystic fibrosis or sickle cell hemoglobinopathy.

Jenelle L Collins1, Alison La Pean, Faith O'Tool, Kerry L Eskra, Sara J Roedl, Audrey Tluczek, Michael H Farrell.   

Abstract

OBJECTIVE: Newborn screening (NBS) identifies genetic carriers for sickle cell hemoglobinopathy and cystic fibrosis. We aimed to identify factors during initial NBS carrier results disclosure by primary care providers (PCPs) that influenced parents' experiences and reactions.
METHODS: Open-ended responses from telephone interviews with 270 parents of carriers were analyzed using mixed-methods. Conventional content analysis identified influential factors; chi-square tests analyzed relationships between factors and parent-reported reactions.
RESULTS: Parents reported positive (35%) or negative (31%) reactions to results disclosure. Parents' experiences were influenced by specific factors: content messages (72%), PCP traits (47%), and aspects of the setting (30%). Including at least one of five specific content messages was associated (p<0.05) with positive parental reactions; omitting at least one of four specific content messages was associated (p<0.05) with negative parental reactions. Parents reported positive reactions when PCPs avoided jargon or were perceived as calm. Parents reported negative reactions to jargon usage and results disclosure by voicemail.
CONCLUSION: Parents identified aspects of PCP communication which influenced their reactions and results disclosure experiences. PRACTICE IMPLICATIONS: Our findings suggest ways PCPs may improve communication of carrier results. PCPs should provide specific content messages and consider how their actions, characteristics, and setting can influence parental reactions.
Copyright © 2011 Elsevier Ireland Ltd. All rights reserved.

Entities:  

Mesh:

Year:  2012        PMID: 22240007      PMCID: PMC3328613          DOI: 10.1016/j.pec.2011.12.007

Source DB:  PubMed          Journal:  Patient Educ Couns        ISSN: 0738-3991


  23 in total

1.  Psychological effects of false-positive results in cystic fibrosis newborn screening: a two-year follow-up.

Authors:  Julie Beucher; Emmanuelle Leray; Eric Deneuville; Monique Roblin; Isabelle Pin; François Bremont; Dominique Turck; Jean-Louis Giniès; Pascal Foucaud; Gilles Rault; Jocelyne Derelle; Valérie David; Hubert Journel; Sophie Marchand; David Veillard; Michel Roussey
Journal:  J Pediatr       Date:  2010-02-20       Impact factor: 4.406

2.  Psychological impact of false-positive results when screening for cystic fibrosis.

Authors:  A Tluczek; E H Mischler; B Bowers; N M Peterson; M E Morris; P M Farrell; W T Bruns; H Colby; C McCarthy; N Fost
Journal:  Pediatr Pulmonol Suppl       Date:  1991

3.  Four-year follow-up of psychological reactions to false positive screening tests for congenital hypothyroidism.

Authors:  K Fyrö; G Bodegård
Journal:  Acta Paediatr Scand       Date:  1987-01

4.  Psychological reactions in 102 families with a newborn who has a falsely positive screening test for congenital hypothyroidism.

Authors:  G Bodegård; K Fyrö; A Larsson
Journal:  Acta Paediatr Scand Suppl       Date:  1983

5.  Parental understanding of newborn screening for cystic fibrosis after a negative sweat-test.

Authors:  Colleen Walsh Lang; Susanna A McColley; Lucille A Lester; Lainie Friedman Ross
Journal:  Pediatrics       Date:  2011-01-10       Impact factor: 7.124

6.  Psychosocial consequences of false-positive newborn screens for cystic fibrosis.

Authors:  Audrey Tluczek; Kate Murphy Orland; Laura Cavanagh
Journal:  Qual Health Res       Date:  2010-09-17

7.  Genetic counseling and neonatal screening for cystic fibrosis: an assessment of the communication process.

Authors:  D J Ciske; A Haavisto; A Laxova; L Z Rock; P M Farrell
Journal:  Pediatrics       Date:  2001-04       Impact factor: 7.124

8.  Genetic counseling and risk communication services of newborn screening programs.

Authors:  M Farrell; L Certain; P Farrell
Journal:  Arch Pediatr Adolesc Med       Date:  2001-02

9.  Communication of carrier status information following universal newborn screening for sickle cell disorders and cystic fibrosis: qualitative study of experience and practice.

Authors:  J Kai; F Ulph; T Cullinan; N Qureshi
Journal:  Health Technol Assess       Date:  2009-11       Impact factor: 4.014

10.  Carrier screening in individuals of Ashkenazi Jewish descent.

Authors:  Susan J Gross; Beth A Pletcher; Kristin G Monaghan
Journal:  Genet Med       Date:  2008-01       Impact factor: 8.822

View more
  12 in total

1.  Sickle cell trait newborn screen results: disclosure and management.

Authors:  Margaret Lilley; Stephanie Hoang; Pamela Blumenschein; Ann-Marie Peturson; Iveta Sosova; Lauren Macneil; Ross Ridsdale; Susan Christian
Journal:  J Community Genet       Date:  2020-10-26

2.  Patient vs Clinician Perspectives on Communication About Results of Lung Cancer Screening: A Qualitative Study.

Authors:  Renda Soylemez Wiener; Jack A Clark; Elisa Koppelman; Rendelle Bolton; Gemmae M Fix; Christopher G Slatore; Hasmeena Kathuria
Journal:  Chest       Date:  2020-05-07       Impact factor: 9.410

3.  Informing parents about positive newborn screen results: parents' recommendations.

Authors:  Natalie Salm; Elena Yetter; Audrey Tluczek
Journal:  J Child Health Care       Date:  2012-09-14       Impact factor: 1.979

4.  Disparities in current and future childhood and newborn carrier identification.

Authors:  Melissa Noke; Alison Wearden; Sarah Peters; Fiona Ulph
Journal:  J Genet Couns       Date:  2014-07-11       Impact factor: 2.537

5.  Frequency of high-quality communication behaviors used by primary care providers of heterozygous infants after newborn screening.

Authors:  Michael H Farrell; Stephanie A Christopher
Journal:  Patient Educ Couns       Date:  2012-11-26

6.  A qualitative secondary evaluation of statewide follow-up interviews for abnormal newborn screening results for cystic fibrosis and sickle cell hemoglobinopathy.

Authors:  Alison La Pean; Jenelle L Collins; Stephanie A Christopher; Kerry L Eskra; Sara J Roedl; Audrey Tluczek; Michael H Farrell
Journal:  Genet Med       Date:  2012-02       Impact factor: 8.822

7.  Healthcare professionals' and parents' experiences of the confirmatory testing period: a qualitative study of the UK expanded newborn screening pilot.

Authors:  Louise Moody; Lou Atkinson; Isher Kehal; James R Bonham
Journal:  BMC Pediatr       Date:  2017-05-08       Impact factor: 2.125

8.  Health services use by children identified as heterozygous hemoglobinopathy mutation carriers via newborn screening.

Authors:  Sara D Khangura; Beth K Potter; Christine Davies; Robin Ducharme; A Brianne Bota; Steven Hawken; Kumanan Wilson; Maria D Karaceper; Robert J Klaassen; Julian Little; Ewurabena Simpson; Pranesh Chakraborty
Journal:  BMC Pediatr       Date:  2021-07-01       Impact factor: 2.125

9.  Parents' responses to receiving sickle cell or cystic fibrosis carrier results for their child following newborn screening.

Authors:  Fiona Ulph; Tim Cullinan; Nadeem Qureshi; Joe Kai
Journal:  Eur J Hum Genet       Date:  2014-07-09       Impact factor: 4.246

10.  Parents' Experiences of Receiving the Initial Positive Newborn Screening (NBS) Result for Cystic Fibrosis and Sickle Cell Disease.

Authors:  Jane Chudleigh; Sarah Buckingham; Jo Dignan; Sandra O'Driscoll; Kemi Johnson; David Rees; Hilary Wyatt; Alison Metcalfe
Journal:  J Genet Couns       Date:  2016-04-20       Impact factor: 2.537

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.