| Literature DB >> 34450030 |
Angela Mo1, Sini Nagpal1, Kyle Gettler2, Talin Haritunians3, Mamta Giri2, Yael Haberman4, Rebekah Karns5, Jarod Prince6, Dalia Arafat1, Nai-Yun Hsu2, Ling-Shiang Chuang2, Carmen Argmann7, Andrew Kasarskis7, Mayte Suarez-Farinas7, Nathan Gotman8, Emebet Mengesha3, Suresh Venkateswaran6, Paul A Rufo9, Susan S Baker10, Cary G Sauer6, James Markowitz11, Marian D Pfefferkorn12, Joel R Rosh13, Brendan M Boyle14, David R Mack15, Robert N Baldassano16, Sapana Shah17, Neal S LeLeiko18, Melvin B Heyman19, Anne M Griffiths20, Ashish S Patel21, Joshua D Noe22, Sonia Davis Thomas23, Bruce J Aronow5, Thomas D Walters20, Dermot P B McGovern3, Jeffrey S Hyams24, Subra Kugathasan6, Judy H Cho2, Lee A Denson5, Greg Gibson25.
Abstract
An important goal of clinical genomics is to be able to estimate the risk of adverse disease outcomes. Between 5% and 10% of individuals with ulcerative colitis (UC) require colectomy within 5 years of diagnosis, but polygenic risk scores (PRSs) utilizing findings from genome-wide association studies (GWASs) are unable to provide meaningful prediction of this adverse status. By contrast, in Crohn disease, gene expression profiling of GWAS-significant genes does provide some stratification of risk of progression to complicated disease in the form of a transcriptional risk score (TRS). Here, we demonstrate that a measured TRS based on bulk rectal gene expression in the PROTECT inception cohort study has a positive predictive value approaching 50% for colectomy. Single-cell profiling demonstrates that the genes are active in multiple diverse cell types from both the epithelial and immune compartments. Expression quantitative trait locus (QTL) analysis identifies genes with differential effects at baseline and week 52 follow-up, but for the most part, differential expression associated with colectomy risk is independent of local genetic regulation. Nevertheless, a predicted polygenic transcriptional risk score (PPTRS) derived by summation of transcriptome-wide association study (TWAS) effects identifies UC-affected individuals at 5-fold elevated risk of colectomy with data from the UK Biobank population cohort studies, independently replicated in an NIDDK-IBDGC dataset. Prediction of gene expression from relatively small transcriptome datasets can thus be used in conjunction with TWASs for stratification of risk of disease complications.Entities:
Keywords: cell-type-specific gene expression; eQTLs; predicted polygenic transcriptional risk scores; prediction of disease progression; transcriptional risk scores; transcriptome-wide association studies
Mesh:
Year: 2021 PMID: 34450030 PMCID: PMC8456180 DOI: 10.1016/j.ajhg.2021.07.013
Source DB: PubMed Journal: Am J Hum Genet ISSN: 0002-9297 Impact factor: 11.025