| Literature DB >> 33712441 |
Nicolas Toussaint1, Yushi Redhead2,3, Marta Vidal-García4, Lucas Lo Vercio4, Wei Liu4, Elizabeth M C Fisher5, Benedikt Hallgrímsson6, Victor L J Tybulewicz7,8, Julia A Schnabel1, Jeremy B A Green9.
Abstract
Characterising phenotypes often requires quantification of anatomical shape. Quantitative shape comparison (morphometrics) traditionally uses manually located landmarks and is limited by landmark number and operator accuracy. Here, we apply a landmark-free method to characterise the craniofacial skeletal phenotype of the Dp1Tyb mouse model of Down syndrome and a population of the Diversity Outbred (DO) mouse model, comparing it with a landmark-based approach. We identified cranial dysmorphologies in Dp1Tyb mice, especially smaller size and brachycephaly (front-back shortening), homologous to the human phenotype. Shape variation in the DO mice was partly attributable to allometry (size-dependent shape variation) and sexual dimorphism. The landmark-free method performed as well as, or better than, the landmark-based method but was less labour-intensive, required less user training and, uniquely, enabled fine mapping of local differences as planar expansion or shrinkage. Its higher resolution pinpointed reductions in interior mid-snout structures and occipital bones in both the models that were not otherwise apparent. We propose that this landmark-free pipeline could make morphometrics widely accessible beyond its traditional niches in zoology and palaeontology, especially in characterising developmental mutant phenotypes.Entities:
Keywords: Craniofacial; Cranium; Down syndrome; Morphometrics; Mouse model; Phenotyping
Mesh:
Year: 2021 PMID: 33712441 PMCID: PMC7969589 DOI: 10.1242/dev.188631
Source DB: PubMed Journal: Development ISSN: 0950-1991 Impact factor: 6.862