| Literature DB >> 30333305 |
Fanny Laroumanie1, Arina Korneva2, Matthew R Bersi2,3, Matthew R Alexander4, Liang Xiao1, Xue Zhong5, Justin P Van Beusecum1, Yuhan Chen1, Mohamed A Saleh1,6, William G McMaster7, Kyle A Gavulic1, Bethany L Dale8, Shilin Zhao9, Yan Guo9, Yu Shyr9, Daniel S Perrien1,10, Nancy J Cox5, John A Curci11, Jay D Humphrey2, Meena S Madhur1,4,11.
Abstract
Aortic dissection (AD) is a life-threatening vascular disease with limited treatment strategies. Here, we show that loss of the GWAS-identified SH2B3 gene, encoding lymphocyte adaptor protein LNK, markedly increases susceptibility to acute AD and rupture in response to angiotensin (Ang) II infusion. As early as day 3 following Ang II infusion, prior to the development of AD, Lnk-/- aortas display altered mechanical properties, increased elastin breaks, collagen thinning, enhanced neutrophil accumulation, and increased MMP-9 activity compared with WT mice. Adoptive transfer of Lnk-/- leukocytes into Rag1-/- mice induces AD and rupture in response to Ang II, demonstrating that LNK deficiency in hematopoietic cells plays a key role in this disease. Interestingly, treatment with doxycycline prevents the early accumulation of aortic neutrophils and significantly reduces the incidence of AD and rupture. PrediXcan analysis in a biobank of more than 23,000 individuals reveals that decreased expression of SH2B3 is significantly associated with increased frequency of AD-related phenotypes (odds ratio 0.81). Thus, we identified a role for LNK in the pathology of AD in experimental animals and humans and describe a new model that can be used to inform both inherited and acquired forms of this disease.Entities:
Keywords: Adaptor proteins; Cardiovascular disease; Inflammation; Innate immunity; Vascular Biology
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Year: 2018 PMID: 30333305 PMCID: PMC6237478 DOI: 10.1172/jci.insight.122558
Source DB: PubMed Journal: JCI Insight ISSN: 2379-3708