Literature DB >> 29537378

Nationwide Study of Turner Syndrome in Ukrainian Children: Prevalence, Genetic Variants and Phenotypic Features

Nataliya Zelinska1, Iryna Shevchenko1, Evgenia Globa1.   

Abstract

Objective: We aimed to investigate the prevalence of Turner syndrome (TS) in the Ukrainian population, the frequency of karyotype variants, the age of children at diagnosis, the degree of short stature and phenotypic features in TS girls.
Methods: A retrospective analysis was made in 538 TS girls aged 0.11-18.2 years within the time period of 2005-2015 with detailed examination of 150 patients.
Results: The prevalence of TS in Ukraine is 77.5 in 100.000 live female births. The average age at diagnosis is 9.33±4.93 years. The relative proportions of karyotypic abnormalities found were: 45,X (59.3%); mosaicism 45,X/46,XX (22.9%); and structural abnormalities in chromosome X (17.8%). The most frequently encountered findings were growth delay (98.8%), shortening of the 4th and 5th metacarpal bones (74.6%), abnormal nails (73.3%), broad chest (60.7%), short neck (58.6%), hypertelorism of nipples (51.4%), malformations of the cardiovascular (19.6%) and urinary systems (13.8%) and pathology related to vision (20.1%) and hearing (22.0%).
Conclusion: In the Ukrainian population, the highest proportion of patients with TS had a karyotype 45,X. TS was accompanied by a lower frequency of malformations of internal organs compared to other countries.

Entities:  

Keywords:  Turner syndrome; prevalence; growth retardation; karyotype; phenotype; malformations

Mesh:

Year:  2018        PMID: 29537378      PMCID: PMC6083464          DOI: 10.4274/jcrpe.5119

Source DB:  PubMed          Journal:  J Clin Res Pediatr Endocrinol


  46 in total

1.  Standardized multidisciplinary evaluation yields significant previously undiagnosed morbidity in adult women with Turner syndrome.

Authors:  Kim Freriks; Janneke Timmermans; Catharina C M Beerendonk; Chris M Verhaak; Romana T Netea-Maier; Barto J Otten; Didi D M Braat; Dominique F C M Smeets; Dirk H P M Kunst; Ad R M M Hermus; Henri J L M Timmers
Journal:  J Clin Endocrinol Metab       Date:  2011-07-13       Impact factor: 5.958

2.  Trends in age at diagnosis of Turner syndrome.

Authors:  G Massa; F Verlinde; J De Schepper; M Thomas; J P Bourguignon; M Craen; F de Zegher; I François; M Du Caju; M Maes; C Heinrichs
Journal:  Arch Dis Child       Date:  2005-03       Impact factor: 3.791

3.  Cardiovascular findings and management in Turner syndrome: insights from a French cohort.

Authors:  Bruno Donadille; Alexandra Rousseau; Delphine Zenaty; Sylvie Cabrol; Carine Courtillot; Dinane Samara-Boustani; Sylvie Salenave; Laurence Monnier-Cholley; Catherine Meuleman; Guillaume Jondeau; Laurence Iserin; Lise Duranteau; Laure Cabanes; Nathalie Bourcigaux; Damien Bonnet; Philippe Bouchard; Philippe Chanson; Michel Polak; Philippe Touraine; Yves Lebouc; Jean-Claude Carel; Juliane Léger; Sophie Christin-Maitre
Journal:  Eur J Endocrinol       Date:  2012-07-16       Impact factor: 6.664

4.  Otologic disease in turner syndrome.

Authors:  Ingeborg J M Dhooge; E De Vel; C Verhoye; M Lemmerling; B Vinck
Journal:  Otol Neurotol       Date:  2005-03       Impact factor: 2.311

5.  Incidence and dynamics of thyroid dysfunction and thyroid autoimmunity in girls with Turner's syndrome: a long-term follow-up study.

Authors:  Aneta Gawlik; Tomasz Gawlik; Aleksandra Januszek-Trzciakowska; Hemangini Patel; Ewa Malecka-Tendera
Journal:  Horm Res Paediatr       Date:  2011-10-13       Impact factor: 2.852

6.  Analysis of Turner syndrome patients within the Jordanian population, with a focus on four patients with Y chromosome abnormalities.

Authors:  H Daggag; W Srour; M El-Khateeb; K Ajlouni
Journal:  Sex Dev       Date:  2013-08-29       Impact factor: 1.824

7.  Prenatal and postnatal prevalence of Turner's syndrome: a registry study.

Authors:  C H Gravholt; S Juul; R W Naeraa; J Hansen
Journal:  BMJ       Date:  1996-01-06

Review 8.  Turner syndrome revisited: review of new data supports the hypothesis that all viable 45,X cases are cryptic mosaics with a rescue cell line, implying an origin by mitotic loss.

Authors:  Ernest B Hook; Dorothy Warburton
Journal:  Hum Genet       Date:  2014-01-30       Impact factor: 4.132

9.  Endocrine autoimmunity in Turner syndrome.

Authors:  Armando Grossi; Antonino Crinò; Rosa Luciano; Antonietta Lombardo; Marco Cappa; Alessandra Fierabracci
Journal:  Ital J Pediatr       Date:  2013-12-20       Impact factor: 2.638

10.  Widespread DNA hypomethylation and differential gene expression in Turner syndrome.

Authors:  Christian Trolle; Morten Muhlig Nielsen; Anne Skakkebæk; Philippe Lamy; Søren Vang; Jakob Hedegaard; Iver Nordentoft; Torben Falck Ørntoft; Jakob Skou Pedersen; Claus Højbjerg Gravholt
Journal:  Sci Rep       Date:  2016-09-30       Impact factor: 4.379

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  1 in total

1.  Genetic Investigation of 261 Cases of Turner Syndrome Patients Referred to the Genetic Clinic.

Authors:  Dariush Farhud; Rojiar Asgarian; Amelia Seifalian; Paria Mostafaeinejad; Maryam Eslami
Journal:  Iran J Public Health       Date:  2021-10       Impact factor: 1.429

  1 in total

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