Literature DB >> 21752892

Standardized multidisciplinary evaluation yields significant previously undiagnosed morbidity in adult women with Turner syndrome.

Kim Freriks1, Janneke Timmermans, Catharina C M Beerendonk, Chris M Verhaak, Romana T Netea-Maier, Barto J Otten, Didi D M Braat, Dominique F C M Smeets, Dirk H P M Kunst, Ad R M M Hermus, Henri J L M Timmers.   

Abstract

CONTEXT: Besides short stature and gonadal dysgenesis, Turner syndrome (TS) is associated with various abnormalities. Adults with TS have a reduced life expectancy, mainly related to structural abnormalities of the heart and aorta, and an increased risk of atherosclerosis.
OBJECTIVE: Our objective was to investigate the yield of an initial standardized multidisciplinary screening in adult TS patients. DESIGN AND
SETTING: This was an observational study at a multidisciplinary care unit for adult women with TS. PARTICIPANTS: Participants were adult women with TS (n = 150). Mean age was 31.0 ± 10.4 yr, with 47% karyotype 45,X.
INTERVENTIONS: All women were consulted by an endocrinologist, a gynecologist, a cardiologist, an otorhinolaryngologist, and when indicated, a psychologist. The screening included magnetic resonance imaging of the heart and aorta, echocardiography, electrocardiogram, dual-energy x-ray absorptiometry, renal ultrasound, audiogram, and laboratory investigations according to international expert recommendations. MAIN OUTCOME MEASURES: New diagnoses and prevalence of TS-associated morbidity were evaluated.
RESULTS: Thirty percent of patients currently lacked medical follow-up, and 15% lacked estrogen replacement therapy in the recent last years. The following disorders were newly diagnosed: bicuspid aortic valve (n = 13), coarctation of the aorta (n = 9), elongation of the transverse aortic arch (n = 27), dilation of the aorta (n = 34), osteoporosis (n = 8), osteopenia (n = 56), renal abnormalities (n = 7), subclinical hypothyroidism (n = 33), celiac disease (n = 3), glucose intolerance (n = 12), dyslipidemia (n = 52), hypertension (n = 39), and hearing loss warranting a hearing aid (n = 8). Psychological consultation was needed in 23 cases.
CONCLUSIONS: Standardized multidisciplinary evaluation of adult women with TS as advocated by expert opinion is effective and identifies significant morbidity. Girls with TS benefit from a careful transition to ongoing adult medical care.

Entities:  

Mesh:

Year:  2011        PMID: 21752892     DOI: 10.1210/jc.2011-0346

Source DB:  PubMed          Journal:  J Clin Endocrinol Metab        ISSN: 0021-972X            Impact factor:   5.958


  18 in total

Review 1.  Sex hormone replacement in Turner syndrome.

Authors:  Christian Trolle; Britta Hjerrild; Line Cleemann; Kristian H Mortensen; Claus H Gravholt
Journal:  Endocrine       Date:  2011-12-07       Impact factor: 3.633

2.  Heart Transplantation in Children with Turner Syndrome: Analysis of a Linked Dataset.

Authors:  Joshua D Chew; Jonathan H Soslow; Cary Thurm; Matt Hall; Debra A Dodd; Brian Feingold; Jill Simmons; Justin Godown
Journal:  Pediatr Cardiol       Date:  2018-01-03       Impact factor: 1.655

3.  New insights into the comorbid conditions of Turner syndrome: results from a long-term monocentric cohort study.

Authors:  A Gambineri; E Scarano; P Rucci; A Perri; F Tamburrino; P Altieri; F Corzani; C Cecchetti; P Dionese; E Belardinelli; D Ibarra-Gasparini; S Menabò; V Vicennati; A Repaci; G di Dalmazi; C Pelusi; G Zavatta; A Virdi; I Neri; F Fanelli; L Mazzanti; U Pagotto
Journal:  J Endocrinol Invest       Date:  2022-07-30       Impact factor: 5.467

4.  Psychosocial Characteristics of Women with a Delayed Diagnosis of Turner Syndrome.

Authors:  Gabrielle E Reimann; Martha M Bernad Perman; Pei-Shu Ho; Rebecca A Parks; Leora E Comis
Journal:  J Pediatr       Date:  2018-05-09       Impact factor: 4.406

Review 5.  The patient with Turner syndrome: puberty and medical management concerns.

Authors:  Luisa Gonzalez; Selma Feldman Witchel
Journal:  Fertil Steril       Date:  2012-08-09       Impact factor: 7.329

Review 6.  Care of girls and women with Turner syndrome: beyond growth and hormones.

Authors:  Caroline Culen; Diana-Alexandra Ertl; Katharina Schubert; Lisa Bartha-Doering; Gabriele Haeusler
Journal:  Endocr Connect       Date:  2017-03-23       Impact factor: 3.335

7.  Health status, quality of life and medical care in adult women with Turner syndrome.

Authors:  Diana-Alexandra Ertl; Andreas Gleiss; Katharina Schubert; Caroline Culen; Peer Hauck; Johannes Ott; Alois Gessl; Gabriele Haeusler
Journal:  Endocr Connect       Date:  2018-03-07       Impact factor: 3.335

Review 8.  HRT for women with premature ovarian insufficiency: a comprehensive review.

Authors:  Lisa Webber; Richard A Anderson; Melanie Davies; Femi Janse; Nathalie Vermeulen
Journal:  Hum Reprod Open       Date:  2017-07-12

9.  Physical and Reported Subjective Health Status in 222 Individuals with XY Disorder of Sex Development.

Authors:  Xin Li Gong; Klemens Raile; Jolanta Slowikowska-Hilczer; Catherine Pienkowski; Marcus Quinkler; Robert Roehle; Anna Nordenström; Uta Neumann
Journal:  J Endocr Soc       Date:  2021-06-02

Review 10.  Cardiovascular health in patients with premature ovarian insufficiency. Management of long-term consequences.

Authors:  Agnieszka Podfigurna; Błażej Męczekalski
Journal:  Prz Menopauzalny       Date:  2018-09-30
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