Literature DB >> 2834369

Ehlers-Danlos syndrome type IV: a multi-exon deletion in one of the two COL3A1 alleles affecting structure, stability, and processing of type III procollagen.

A Superti-Furga1, E Gugler, R Gitzelmann, B Steinmann.   

Abstract

We have studied a patient with severe, dominantly inherited Ehlers-Danlos syndrome type IV. The results indicate that this patient carries a deletion of 3.3 kilo-base pairs in the triple helical coding domain of one of the two alleles for the pro-alpha-chains of type III collagen (COL3A1). His cultured skin fibroblasts contain equal amounts of normal length mRNA and of mRNA shortened by approximately 600 bases, and synthesize both normal and shortened pro-alpha 1(III)-chains. In procollagen molecules containing one or more shortened chains, a triple helix is formed with a length of only about 780 amino acids. The mutant procollagen molecules have decreased thermal stability, are less efficiently secreted, and are not processed as their normal counterpart. The deletion in this family is the first mutation to be described in COL3A1.

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Year:  1988        PMID: 2834369

Source DB:  PubMed          Journal:  J Biol Chem        ISSN: 0021-9258            Impact factor:   5.157


  61 in total

1.  A 27-bp deletion from one allele of the type III collagen gene (COL3A1) in a large family with Ehlers-Danlos syndrome type IV.

Authors:  A J Richards; J C Lloyd; P Narcisi; P N Ward; A C Nicholls; A De Paepe; F M Pope
Journal:  Hum Genet       Date:  1992-01       Impact factor: 4.132

2.  Hemizygous deletion of COL3A1, COL5A2, and MSTN causes a complex phenotype with aortic dissection: a lesson for and from true haploinsufficiency.

Authors:  Janine Meienberg; Marianne Rohrbach; Stefan Neuenschwander; Katharina Spanaus; Cecilia Giunta; Sira Alonso; Eliane Arnold; Caroline Henggeler; Stephan Regenass; Andrea Patrignani; Silvia Azzarello-Burri; Bernhard Steiner; Anders O H Nygren; Thierry Carrel; Beat Steinmann; Gábor Mátyás
Journal:  Eur J Hum Genet       Date:  2010-07-21       Impact factor: 4.246

Review 3.  Molecular heterogeneity in chondrodysplasias.

Authors:  P H Byers
Journal:  Am J Hum Genet       Date:  1989-07       Impact factor: 11.025

4.  Rapid detection of gene mutations responsible for non-syndromic aortic aneurysm and dissection using two different methods: resequencing microarray technology and next-generation sequencing.

Authors:  Haruya Sakai; Shinichi Suzuki; Takeshi Mizuguchi; Kiyotaka Imoto; Yuki Yamashita; Hiroshi Doi; Masakazu Kikuchi; Yoshinori Tsurusaki; Hirotomo Saitsu; Noriko Miyake; Munetaka Masuda; Naomichi Matsumoto
Journal:  Hum Genet       Date:  2011-10-15       Impact factor: 4.132

Review 5.  Genetics of the extracellular matrix in aortic aneurysmal diseases.

Authors:  Chien-Jung Lin; Chieh-Yu Lin; Nathan O Stitziel
Journal:  Matrix Biol       Date:  2018-04-12       Impact factor: 11.583

Review 6.  Experimental in vivo and ex vivo models for the study of human aortic dissection: promises and challenges.

Authors:  Ding-Sheng Jiang; Xin Yi; Xue-Hai Zhu; Xiang Wei
Journal:  Am J Transl Res       Date:  2016-12-15       Impact factor: 4.060

Review 7.  Molecular pathogenesis of genetic and sporadic aortic aneurysms and dissections.

Authors:  Ying H Shen; Scott A LeMaire
Journal:  Curr Probl Surg       Date:  2017-02-03       Impact factor: 1.909

8.  Inheritance of an RNA splicing mutation (G+ 1 IVS20) in the type III procollagen gene (COL3A1) in a family having aortic aneurysms and easy bruisability: phenotypic overlap between familial arterial aneurysms and Ehlers-Danlos syndrome type IV.

Authors:  S Kontusaari; G Tromp; H Kuivaniemi; R L Ladda; D J Prockop
Journal:  Am J Hum Genet       Date:  1990-07       Impact factor: 11.025

9.  Gene expression analysis of cultured amniotic fluid cell with Down syndrome by DNA microarray.

Authors:  In-Hyuk Chung; Sook-Hwan Lee; Kyo-Won Lee; Sang-hee Park; Kwang-Yul Cha; Nam-Soon Kim; Hyang-Sook Yoo; Yong Sung Kim; Suman Lee
Journal:  J Korean Med Sci       Date:  2005-02       Impact factor: 2.153

Review 10.  Vascular type Ehlers-Danlos Syndrome with fatal spontaneous rupture of a right common iliac artery dissection: case report and review of literature.

Authors:  Aly Abayazeed; Emily Hayman; Mana Moghadamfalahi; Darren Cain
Journal:  J Radiol Case Rep       Date:  2014-02-01
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