Literature DB >> 24150548

A novel mutation of DNAH5 in chronic rhinosinusitis and primary ciliary dyskinesia in a Chinese family.

Jing Zhang1, Liping Guan, Weiping Wen, Yu Lu, Qianyan Zhu, Huijun Yuan, Yulan Chen, Hongtian Wang, Jianguo Zhang, Huabin Li.   

Abstract

The genetic factors underlying the pathogenesis of chronic rhinosinusitis (CRS) remains unclear. We herein identified four related subjects with CRS and primary ciliary dyskinesia (PCD) from geographically disperse Chinese Han communities and performed exome capture and sequencing of one affected individual and unaffected parents. We found a novel mutation in DNAH5 (c. 8030G>A) in CRS and PCD which was different from those attributed to cystic fibrosis and a defect of cilia motility in a Chinese family through exome capture and sequencing. Our findings showed that c. 8030G>A of DNAH5 may be implicated as the disease-causing gene of CRS and PCD in this Chinese family, which may expand the understanding of clinicians on the pathogenesis of CRS. Moreover, the identification of this novel mutation in DNAH5 indirectly indicates that exome capture and sequencing are beneficial in the genetic research of midget consanguinity families.

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Year:  2013        PMID: 24150548     DOI: 10.1007/s00405-013-2788-2

Source DB:  PubMed          Journal:  Eur Arch Otorhinolaryngol        ISSN: 0937-4477            Impact factor:   2.503


  11 in total

1.  Model for the motor component of dynein heavy chain based on homology to the AAA family of oligomeric ATPases.

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Journal:  Structure       Date:  2001-02-07       Impact factor: 5.006

2.  The 2.8 Å crystal structure of the dynein motor domain.

Authors:  Takahide Kon; Takuji Oyama; Rieko Shimo-Kon; Kenji Imamula; Tomohiro Shima; Kazuo Sutoh; Genji Kurisu
Journal:  Nature       Date:  2012-03-07       Impact factor: 49.962

Review 3.  Alterations in epithelial barrier function and host defense responses in chronic rhinosinusitis.

Authors:  David D Tieu; Robert C Kern; Robert P Schleimer
Journal:  J Allergy Clin Immunol       Date:  2009-07       Impact factor: 10.793

4.  X-ray structure of a functional full-length dynein motor domain.

Authors:  Takahide Kon; Kazuo Sutoh; Genji Kurisu
Journal:  Nat Struct Mol Biol       Date:  2011-05-22       Impact factor: 15.369

5.  Whole-exome capture and sequencing identifies HEATR2 mutation as a cause of primary ciliary dyskinesia.

Authors:  Amjad Horani; Todd E Druley; Maimoona A Zariwala; Anand C Patel; Benjamin T Levinson; Laura G Van Arendonk; Katherine C Thornton; Joe C Giacalone; Alison J Albee; Kate S Wilson; Emily H Turner; Deborah A Nickerson; Jay Shendure; Philip V Bayly; Margaret W Leigh; Michael R Knowles; Steven L Brody; Susan K Dutcher; Thomas W Ferkol
Journal:  Am J Hum Genet       Date:  2012-10-05       Impact factor: 11.025

Review 6.  The emerging genetics of primary ciliary dyskinesia.

Authors:  Maimoona A Zariwala; Heymut Omran; Thomas W Ferkol
Journal:  Proc Am Thorac Soc       Date:  2011-09

7.  Mutations in DNAH5 cause primary ciliary dyskinesia and randomization of left-right asymmetry.

Authors:  Heike Olbrich; Karsten Häffner; Andreas Kispert; Alexander Völkel; Andreas Volz; Gürsel Sasmaz; Richard Reinhardt; Steffen Hennig; Hans Lehrach; Nikolaus Konietzko; Maimoona Zariwala; Peadar G Noone; Michael Knowles; Hannah M Mitchison; Maggie Meeks; Eddie M K Chung; Friedhelm Hildebrandt; Ralf Sudbrak; Heymut Omran
Journal:  Nat Genet       Date:  2002-01-14       Impact factor: 38.330

8.  ENT manifestations in patients with primary ciliary dyskinesia: prevalence and significance of otorhinolaryngologic co-morbidities.

Authors:  J Ulrich Sommer; Kerstin Schäfer; Heymut Omran; Heike Olbrich; Julia Wallmeier; Andreas Blum; Karl Hörmann; Boris A Stuck
Journal:  Eur Arch Otorhinolaryngol       Date:  2010-07-22       Impact factor: 2.503

9.  EPOS 2012: European position paper on rhinosinusitis and nasal polyps 2012. A summary for otorhinolaryngologists.

Authors:  Wytske J Fokkens; Valerie J Lund; Joachim Mullol; Claus Bachert; Isam Alobid; Fuad Baroody; Noam Cohen; Anders Cervin; Richard Douglas; Philippe Gevaert; Christos Georgalas; Herman Goossens; Richard Harvey; Peter Hellings; Claire Hopkins; Nick Jones; Guy Joos; Livije Kalogjera; Bob Kern; Marek Kowalski; David Price; Herbert Riechelmann; Rodney Schlosser; Brent Senior; Mike Thomas; Elina Toskala; Richard Voegels; De Yun Wang; Peter John Wormald
Journal:  Rhinology       Date:  2012-03       Impact factor: 3.681

10.  [Clinical characteristics of primary ciliary dyskinesia in children].

Authors:  Bao-ping Xu; Kun-ling Shen; Ying-hui Hu; Xue-li Feng; Hui-min Li; Zhi-qi Lang
Journal:  Zhonghua Er Ke Za Zhi       Date:  2008-08
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  4 in total

Review 1.  Clinical and genetic spectrum of primary ciliary dyskinesia in Chinese patients: a systematic review.

Authors:  Bo Peng; Yong-Hua Gao; Jia-Qi Xie; Xiao-Wen He; Cong-Cong Wang; Jin-Fu Xu; Guo-Jun Zhang
Journal:  Orphanet J Rare Dis       Date:  2022-07-19       Impact factor: 4.303

Review 2.  Risk Factors and Comorbidities in Chronic Rhinosinusitis.

Authors:  Derrick Tint; Stephanie Kubala; Elina Toskala
Journal:  Curr Allergy Asthma Rep       Date:  2016-02       Impact factor: 4.806

Review 3.  Motile Ciliary Disorders in Chronic Airway Inflammatory Diseases: Critical Target for Interventions.

Authors:  Wei-Jie Guan; Yang Peng; Xiao-Xue Zi; Kai Sen Tan; Ting-Ting He; Nan-Shan Zhong; De Yun Wang
Journal:  Curr Allergy Asthma Rep       Date:  2018-07-26       Impact factor: 4.806

4.  Whole-exome sequencing identification of novel DNAH5 mutations in a young patient with primary ciliary dyskinesia.

Authors:  Gen Kano; Hisashi Tsujii; Kazuhiko Takeuchi; Kaname Nakatani; Makoto Ikejiri; Satoru Ogawa; Hisami Kubo; Mizuho Nagao; Takao Fujisawa
Journal:  Mol Med Rep       Date:  2016-10-21       Impact factor: 2.952

  4 in total

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