Literature DB >> 23220425

Association of histologic variants in FSGS clinical trial with presenting features and outcomes.

Vivette D D'Agati1, Joan M Alster, J Charles Jennette, David B Thomas, James Pullman, Daniel A Savino, Arthur H Cohen, Debbie S Gipson, Jennifer J Gassman, Milena K Radeva, Marva M Moxey-Mims, Aaron L Friedman, Frederick J Kaskel, Howard Trachtman, Charles E Alpers, Agnes B Fogo, Tom H Greene, Cynthia C Nast.   

Abstract

BACKGROUND AND OBJECTIVES: FSGS histologic variants have correlated with outcomes in retrospective studies. The FSGS Clinical Trial provided a unique opportunity to study the clinical impact of histologic variants in a well defined prospective cohort with steroid-resistant primary FSGS. DESIGN, SETTING, PARTICIPANTS, & MEASUREMENTS: Renal biopsies of 138 FSGS Clinical Trial participants aged 2-38 years enrolled from 2004 to 2008 were analyzed using the Columbia classification by core pathologists. This study assessed the distribution of histologic variants and examined their clinical and biopsy characteristics and relationships to patient outcomes.
RESULTS: The distribution of histologic variants was 68% (n=94) FSGS not otherwise specified, 12% (n=16) collapsing, 10% (n=14) tip, 7% (n=10) perihilar, and 3% (n=4) cellular. Individuals with not otherwise specified FSGS were more likely to have subnephrotic proteinuria (P=0.01); 33% of teenagers and adults had tip or collapsing variants compared with 10% of children, and subjects with these variants had greater proteinuria and hypoalbuminemia than not otherwise specified patients. Tip variant had the strongest association with white race (86%) and the lowest pathologic injury scores, baseline creatinine, and rate of progression. Collapsing variant had the strongest association with black race (63%, P=0.03) and the highest pathologic injury scores (P=0.003), baseline serum creatinine (P=0.003), and rate of progression. At 3 years, 47% of collapsing, 20% of not otherwise specified, and 7% of tip variant patients reached ESRD (P=0.005).
CONCLUSIONS: This is the first prospective study with protocol-defined immunomodulating therapies confirming poor renal survival in collapsing variant and showing better renal survival in tip variant among steroid-resistant patients.

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Year:  2012        PMID: 23220425      PMCID: PMC3586971          DOI: 10.2215/CJN.06100612

Source DB:  PubMed          Journal:  Clin J Am Soc Nephrol        ISSN: 1555-9041            Impact factor:   8.237


  20 in total

1.  Primary focal segmental glomerular sclerosis in children: clinical course and prognosis.

Authors:  Kyung Hoon Paik; Bum Hee Lee; Hee Yeon Cho; Hee Gyung Kang; Il Soo Ha; Hae Il Cheong; Dong-Kyu Jin; Kyung Chul Moon; Yong Choi
Journal:  Pediatr Nephrol       Date:  2006-10-21       Impact factor: 3.714

2.  Cellular focal segmental glomerulosclerosis: Clinical and pathologic features.

Authors:  M B Stokes; A M Valeri; G S Markowitz; V D D'Agati
Journal:  Kidney Int       Date:  2006-10-04       Impact factor: 10.612

3.  Accuracy of the diagnosis of hypertensive nephrosclerosis in African Americans: a report from the African American Study of Kidney Disease (AASK) Trial. AASK Pilot Study Investigators.

Authors:  A Fogo; J A Breyer; M C Smith; W H Cleveland; L Agodoa; K A Kirk; R Glassock
Journal:  Kidney Int       Date:  1997-01       Impact factor: 10.612

4.  Primary focal segmental glomerulosclerosis in Egyptian children: a 10-year single-centre experience.

Authors:  Ahmed M El-Refaey; Ashraf Bakr; Ayman Hammad; Atef Elmougy; Fatma El-Houseeny; Ashraf Abdelrahman; Amr Sarhan
Journal:  Pediatr Nephrol       Date:  2010-03-02       Impact factor: 3.714

5.  Idiopathic collapsing focal segmental glomerulosclerosis: a clinicopathologic study.

Authors:  A Valeri; L Barisoni; G B Appel; R Seigle; V D'Agati
Journal:  Kidney Int       Date:  1996-11       Impact factor: 10.612

6.  Evolution of nephrotic-associated focal segmental glomerulosclerosis and relation to the glomerular tip lesion.

Authors:  Alexander J Howie; Tanya Pankhurst; Sulen Sarioglu; Nesrin Turhan; Dwomoa Adu
Journal:  Kidney Int       Date:  2005-03       Impact factor: 10.612

7.  Clinical and pathologic characteristics of focal segmental glomerulosclerosis pathologic variants.

Authors:  D B Thomas; N Franceschini; S L Hogan; S Ten Holder; C E Jennette; R J Falk; J C Jennette
Journal:  Kidney Int       Date:  2006-03       Impact factor: 10.612

8.  Pathological variants of focal segmental glomerulosclerosis in an adult Dutch population--epidemiology and outcome.

Authors:  Jeroen K J Deegens; Eric J Steenbergen; George F Borm; Jack F M Wetzels
Journal:  Nephrol Dial Transplant       Date:  2007-08-17       Impact factor: 5.992

9.  Presenting features and short-term outcome according to pathologic variant in childhood primary focal segmental glomerulosclerosis.

Authors:  Douglas M Silverstein; Randall Craver
Journal:  Clin J Am Soc Nephrol       Date:  2007-05-18       Impact factor: 8.237

Review 10.  A proposed taxonomy for the podocytopathies: a reassessment of the primary nephrotic diseases.

Authors:  Laura Barisoni; H William Schnaper; Jeffrey B Kopp
Journal:  Clin J Am Soc Nephrol       Date:  2007-04-11       Impact factor: 8.237

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  46 in total

Review 1.  Variations of type IV collagen-encoding genes in patients with histological diagnosis of focal segmental glomerulosclerosis.

Authors:  Erol Demir; Yasar Caliskan
Journal:  Pediatr Nephrol       Date:  2019-06-28       Impact factor: 3.714

2.  Idiopathic collapsing focal segmental glomerulosclerosis in an 81-year-old Japanese woman: a case report and review of the literature.

Authors:  Jun Yamazaki; Eriko Kanehisa; Wakaba Yamaguchi; Jiro Kumagai; Kiyotaka Nagahama; Hajime Fujisawa
Journal:  CEN Case Rep       Date:  2016-06-15

3.  Glomerular disease: association of FSGS histologic variants with patient outcomes.

Authors:  Ellen F Carney
Journal:  Nat Rev Nephrol       Date:  2013-01-08       Impact factor: 28.314

Review 4.  Differentiating Primary, Genetic, and Secondary FSGS in Adults: A Clinicopathologic Approach.

Authors:  An S De Vriese; Sanjeev Sethi; Karl A Nath; Richard J Glassock; Fernando C Fervenza
Journal:  J Am Soc Nephrol       Date:  2018-01-10       Impact factor: 10.121

5.  A patient with nephrotic-range proteinuria and focal global glomerulosclerosis.

Authors:  Fernando C Fervenza
Journal:  Clin J Am Soc Nephrol       Date:  2013-07-25       Impact factor: 8.237

Review 6.  Causes and pathogenesis of focal segmental glomerulosclerosis.

Authors:  Agnes B Fogo
Journal:  Nat Rev Nephrol       Date:  2014-12-02       Impact factor: 28.314

7.  Renal Survival in Patients with Collapsing Compared with Not Otherwise Specified FSGS.

Authors:  Louis-Philippe Laurin; Adil M Gasim; Vimal K Derebail; JulieAnne G McGregor; Jason M Kidd; Susan L Hogan; Caroline J Poulton; Randal K Detwiler; J Charles Jennette; Ronald J Falk; Patrick H Nachman
Journal:  Clin J Am Soc Nephrol       Date:  2016-07-21       Impact factor: 8.237

8.  Reducing mTOR augments parietal epithelial cell density in a model of acute podocyte depletion and in aged kidneys.

Authors:  Bairbre A McNicholas; Diana G Eng; Julia Lichtnekert; Peter S Rabinowitz; Jeffrey W Pippin; Stuart J Shankland
Journal:  Am J Physiol Renal Physiol       Date:  2016-07-20

9.  Collapsing glomerulopathy in a patient with mixed connective tissue disease.

Authors:  Gajapathiraju Chamarthi; William L Clapp; Saraswathi Gopal
Journal:  CEN Case Rep       Date:  2020-10-14

10.  Urinary exosomal Wilms' tumor-1 as a potential biomarker for podocyte injury.

Authors:  Hua Zhou; Hiroshi Kajiyama; Takayuki Tsuji; Xuzhen Hu; Asada Leelahavanichkul; Suzanne Vento; Rachel Frank; Jeffrey B Kopp; Howard Trachtman; Robert A Star; Peter S T Yuen
Journal:  Am J Physiol Renal Physiol       Date:  2013-06-12
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