Literature DB >> 21291454

Identification of 11 novel mutations in 49 Korean patients with mucopolysaccharidosis type II.

Y B Sohn1, C-S Ki, C-H Kim, A-R Ko, Y-J Yook, S-J Lee, S J Kim, S W Park, S Yeau, E-K Kwon, S J Han, E W Choi, S-Y Lee, J-W Kim, D-K Jin.   

Abstract

Mucopolysaccharidosis type II (MPS II) or Hunter syndrome is a rare lysosomal storage disorder caused by a deficiency of iduronate-2-sulfatase (IDS). As MPS II is X-linked, patients are usually males with heterogeneous mutations ranging from point mutations to gross deletions and recombination. In 2003, we reported a mutation analysis of 25 patients with MPS II. In this study, 31 mutations in another 49 Korean patients (45 families) with MPS II are reported: 12 missense, nine deletions, four splicing, two nonsense, two insertions, one deletion/insertion, and IDS-IDS2 recombination mutations. Among these mutations, 11 were novel ones (4 missense mutations: Ser61Pro, Pro97Arg, Pro228Ala, and Pro261Ala; 5 deletions: c.344delA, c.420delG, c.768delT, c.1112delC and c.1402delC; 1 deletion/insertion: c.1222delinsTA; and 1 insertion mutation: c.359_360insATCC). The IDS-IDS2 recombination mutations were most frequently observed; all patients with this mutation had the severe MPS II phenotype. However, most of the patients (5/7) with the G374G splicing mutation had an attenuated phenotype, except for two sibling cases with the severe phenotype. Except for a few recurrent mutations such as the G374G, R443X, L522P, and recombination mutations, each patient had a unique individual mutation. Therefore, careful interpretation of genotype-phenotype correlations is warranted.
© 2011 John Wiley & Sons A/S.

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Year:  2011        PMID: 21291454     DOI: 10.1111/j.1399-0004.2011.01641.x

Source DB:  PubMed          Journal:  Clin Genet        ISSN: 0009-9163            Impact factor:   4.438


  13 in total

Review 1.  An overview of Korean patients with mucopolysaccharidosis and collaboration through the Asia Pacific MPS Network.

Authors:  Sung Yoon Cho; Young Bae Sohn; Dong-Kyu Jin
Journal:  Intractable Rare Dis Res       Date:  2014-08

2.  Transcriptome-wide discovery of microRNA binding sites in human brain.

Authors:  Ryan L Boudreau; Peng Jiang; Brian L Gilmore; Ryan M Spengler; Rebecca Tirabassi; Jay A Nelson; Christopher A Ross; Yi Xing; Beverly L Davidson
Journal:  Neuron       Date:  2014-01-02       Impact factor: 17.173

3.  Deep Genotyping of the IDS Gene in Colombian Patients with Hunter Syndrome.

Authors:  Johanna Galvis; Jannet González; Alfredo Uribe; Harvy Velasco
Journal:  JIMD Rep       Date:  2015-02-15

4.  Probability of high-risk genetic matching with oocyte and semen donors: complete gene analysis or genotyping test?

Authors:  Marta Molina Romero; Alberto Yoldi Chaure; Miguel Gañán Parra; Purificación Navas Bastida; José Luis Del Pico Sánchez; Ángel Vaquero Argüelles; Paloma de la Fuente Vaquero; Juan Pablo Ramírez López; José Antonio Castilla Alcalá
Journal:  J Assist Reprod Genet       Date:  2022-01-29       Impact factor: 3.412

5.  Impact of enzyme replacement therapy on linear growth in Korean patients with mucopolysaccharidosis type II (Hunter syndrome).

Authors:  Sung Yoon Cho; Rimm Huh; Mi Sun Chang; Jieun Lee; Younghee Kwun; Se Hyun Maeng; Su Jin Kim; Young Bae Sohn; Sung Won Park; Eun-Kyung Kwon; Sun Ju Han; Jooyoun Jung; Dong-Kyu Jin
Journal:  J Korean Med Sci       Date:  2014-01-28       Impact factor: 2.153

6.  A study of the relationship between clinical phenotypes and plasma iduronate-2-sulfatase enzyme activities in Hunter syndrome patients.

Authors:  Ok Jeong Lee; Su-Jin Kim; Young Bae Sohn; Hyung-Doo Park; Soo-Youn Lee; Chi-Hwa Kim; Ah-Ra Ko; Yeon-Joo Yook; Su-Jin Lee; Sung Won Park; Se-Hwa Kim; Sung-Yoon Cho; Eun-Kyung Kwon; Sun Ju Han; Dong-Kyu Jin
Journal:  Korean J Pediatr       Date:  2012-03-16

7.  Identification of 17 novel mutations in 40 Argentinean unrelated families with mucopolysaccharidosis type II (Hunter syndrome).

Authors:  H Amartino; R Ceci; F Masllorens; A Gal; C Arberas; L Bay; R Ilari; J Dipierri; N Specola; A Cabrera; P Rozenfeld
Journal:  Mol Genet Metab Rep       Date:  2014-09-17

8.  Comparative study of idursulfase beta and idursulfase in vitro and in vivo.

Authors:  Chihwa Kim; Jinwook Seo; Yokyung Chung; Hyi-Jeong Ji; Jaehyeon Lee; Jongmun Sohn; Byoungju Lee; Eui-Cheol Jo
Journal:  J Hum Genet       Date:  2016-11-10       Impact factor: 3.172

9.  The first Korean case of mucopolysaccharidosis IIIC (Sanfilippo syndrome type C) confirmed by biochemical and molecular investigation.

Authors:  Hee Jae Huh; Ja Young Seo; Sung Yoon Cho; Chang-Seok Ki; Soo-Youn Lee; Jong-Won Kim; Hyung-Doo Park; Dong-Kyu Jin
Journal:  Ann Lab Med       Date:  2012-12-17       Impact factor: 3.464

10.  Phase I/II clinical trial of enzyme replacement therapy with idursulfase beta in patients with mucopolysaccharidosis II (Hunter syndrome).

Authors:  Young Bae Sohn; Sung Yoon Cho; Sung Won Park; Su Jin Kim; Ah-Ra Ko; Eun-Kyung Kwon; Sun Ju Han; Dong-Kyu Jin
Journal:  Orphanet J Rare Dis       Date:  2013-03-18       Impact factor: 4.123

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