| Literature DB >> 24550654 |
Sung Yoon Cho1, Rimm Huh2, Mi Sun Chang2, Jieun Lee2, Younghee Kwun2, Se Hyun Maeng2, Su Jin Kim3, Young Bae Sohn4, Sung Won Park5, Eun-Kyung Kwon2, Sun Ju Han2, Jooyoun Jung2, Dong-Kyu Jin2.
Abstract
Hunter syndrome (or mucopolysaccharidosis type II [MPS II]) arises because of a deficiency in the lysosomal enzyme iduronate-2-sulfatase. Short stature is a prominent and consistent feature in MPS II. Enzyme replacement therapy (ERT) with idursulfase (Elaprase®) or idursulfase beta (Hunterase®) have been developed for these patients. The effect of ERT on the growth of Korean patients with Hunter syndrome was evaluated at a single center. This study comprised 32 patients, who had received ERT for at least 2 yr; they were divided into three groups according to their ages at the start of ERT: group 1 (<6 yr, n=14), group 2 (6-10 yr, n=11), and group 3 (10-20 yr, n=7). The patients showed marked growth retardation as they got older. ERT may have less effect on the growth of patients with the severe form of Hunter syndrome. The height z-scores in groups 2 and 3 revealed a significant change (the estimated slopes before and after the treatment were -0.047 and -0.007, respectively: difference in the slope, 0.04; P<0.001). Growth in response to ERT could be an important treatment outcome or an endpoint for future studies.Entities:
Keywords: Elaprase; Enzyme Replacement Therapy; Growth; Hunter Syndrome; Hunterase; Mucopolysaccharidosis II
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Year: 2014 PMID: 24550654 PMCID: PMC3924006 DOI: 10.3346/jkms.2014.29.2.254
Source DB: PubMed Journal: J Korean Med Sci ISSN: 1011-8934 Impact factor: 2.153