Literature DB >> 9860012

Corneal opacities in Gaucher disease.

A Guemes1, G S Kosmorsky, D S Moodie, B Clark, D Meisler, E I Traboulsi.   

Abstract

PURPOSE: To describe the corneal findings in a variant of Gaucher disease.
METHODS: Case report. In an 18-year-old man, ophthalmic and general clinical evaluation, and enzymatic and molecular genetics studies were performed.
RESULTS: Diffuse, well-defined, small, linear, or dotlike corneal opacities were observed through, out the posterior two thirds of the corneal stroma in both eyes. The patient had calcific valvular heart disease. Enzymatic and ultrastructural studies were consistent with Gaucher disease. Analysis of the glucocerebrosidase gene disclosed homozygosity for a D409H mutation.
CONCLUSION: Corneal opacities are a distinguishing ocular feature of the variant of Gaucher disease associated with the D409H mutation and with calcific cardiac disease.

Entities:  

Mesh:

Year:  1998        PMID: 9860012     DOI: 10.1016/s0002-9394(98)00249-9

Source DB:  PubMed          Journal:  Am J Ophthalmol        ISSN: 0002-9394            Impact factor:   5.258


  4 in total

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Review 3.  Diagnosing neuronopathic Gaucher disease: New considerations and challenges in assigning Gaucher phenotypes.

Authors:  Emily C Daykin; Emory Ryan; Ellen Sidransky
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4.  A comprehensive monocentric ophthalmic study with Gaucher disease type 3 patients: vitreoretinal lesions, retinal atrophy and characterization of abnormal saccades.

Authors:  Susanne Hopf; Norbert Pfeiffer; Matthias Liesenfeld; Karl-Eugen Mengel; Julia B Hennermann; Irene Schmidtmann; Susanne Pitz
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  4 in total

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