Literature DB >> 9222245

Dominant inheritance of optic pits.

S T Stefko1, P Campochiaro, P Wang, Y Li, D Zhu, E I Traboulsi.   

Abstract

PURPOSE: To report the familial occurrence of optic pits and to screen the candidate PAX2 gene for mutations in this family.
METHODS: Clinical family study. Standard mutation analysis of the PAX2 exons.
RESULTS: Unilateral optic pits were present in three generations of one family and were inherited in an autosomal dominant fashion. No mutations in the PAX2 gene, responsible for the renal-optic coloboma syndrome, were found.
CONCLUSION: Unilateral optic pits may be inherited in an autosomal dominant fashion and not in association with mutation in the PAX2 gene.

Entities:  

Mesh:

Substances:

Year:  1997        PMID: 9222245     DOI: 10.1016/s0002-9394(14)71656-3

Source DB:  PubMed          Journal:  Am J Ophthalmol        ISSN: 0002-9394            Impact factor:   5.258


  13 in total

Review 1.  Optic disc pit: a review.

Authors:  Ilias Georgalas; Ioannis Ladas; Gerasimos Georgopoulos; Petros Petrou
Journal:  Graefes Arch Clin Exp Ophthalmol       Date:  2011-06-03       Impact factor: 3.117

2.  Concurrent optic disc pit and retinal cavernous hemangioma.

Authors:  Alec L Amram; Renata Picciani; Jaafar El-Annan
Journal:  Int J Ophthalmol       Date:  2017-01-18       Impact factor: 1.779

Review 3.  [Macular changes in optic disc pits-Optic disc pit maculopathy (ODP-M) : Pathophysiology and possibilities of surgical treatment].

Authors:  J Wachtlin; R G Schumann; M Maier; C Haritoglou
Journal:  Ophthalmologe       Date:  2019-11       Impact factor: 1.059

4.  Optic Pit Maculopathy: Clinical Features and Management Options.

Authors:  Prashanth G Iyer; Harry W Flynn; Kenneth C Fan; Audina M Berrocal; Raquel Goldhardt
Journal:  Curr Ophthalmol Rep       Date:  2021-10-07

Review 5.  Congenital abnormalities of the optic nerve: from gene mutation to clinical expression.

Authors:  Palak B Wall; Elias I Traboulsi
Journal:  Curr Neurol Neurosci Rep       Date:  2013-07       Impact factor: 5.081

6.  The prevalence of PAX2 mutations in patients with isolated colobomas or colobomas associated with urogenital anomalies.

Authors:  H E Cunliffe; L A McNoe; T A Ward; K Devriendt; H G Brunner; M R Eccles
Journal:  J Med Genet       Date:  1998-10       Impact factor: 6.318

7.  Familial cavitary optic disk anomalies: identification of a novel genetic locus.

Authors:  John H Fingert; Robert A Honkanen; Suma P Shankar; Louisa M Affatigato; Mary A Ehlinger; Michael D Moore; Lee M Jampol; Val C Sheffield; Edwin M Stone; Wallace L M Alward
Journal:  Am J Ophthalmol       Date:  2007-03-19       Impact factor: 5.258

8.  Patient with Morning Glory syndrome.

Authors:  Thiago Gonçalves dos Santos Martins; Diogo Gonçalves dos Santos Martins; Ana Luiza Fontes de Azevedo Costa
Journal:  Einstein (Sao Paulo)       Date:  2015-03-03

9.  Familial Optic Disc Pits in 2 Father-Son Pairs: Clinical Features and Genetic Analysis.

Authors:  Devin Betsch; Andrew Orr; Mathew Nightingale; Daniel Gaston; Rishi Gupta
Journal:  Case Rep Ophthalmol       Date:  2021-07-01

10.  Familial Disorders of the Optic Disc: Presentation of a Mother and Daughter and Review of the Literature.

Authors:  Chia Lee Hsu; Christopher J Layton
Journal:  Case Rep Ophthalmol       Date:  2015-07-29
View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.