Literature DB >> 9059160

Evolving phenotype of Marfan's syndrome.

K J Lipscomb1, J Clayton-Smith, R Harris.   

Abstract

AIM: To examine evolution of the physical characteristics of Marfan's syndrome throughout childhood.
METHODS: 40 children were ascertained during the development of a regional register for Marfan's syndrome. Evolution of the clinical characteristics was determined by repeat evaluation of 10 patients with sporadic Marfan's syndrome and 30 with a family history of the condition. DNA marker studies were used to facilitate diagnosis in those with the familial condition.
RESULTS: Musculoskeletal features predominated and evolved throughout childhood. Gene tracking enabled early diagnosis in children with familial Marfan's syndrome.
CONCLUSIONS: These observations may aid the clinical diagnosis of Marfan's syndrome in childhood, especially in those with the sporadic condition. Gene tracking has a role in the early diagnosis of familial Marfan's syndrome, allowing appropriate follow up and preventive care.

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Year:  1997        PMID: 9059160      PMCID: PMC1717050          DOI: 10.1136/adc.76.1.41

Source DB:  PubMed          Journal:  Arch Dis Child        ISSN: 0003-9888            Impact factor:   3.791


  27 in total

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Authors:  C Phornphutkul; A Rosenthal; A S Nadas
Journal:  Circulation       Date:  1973-03       Impact factor: 29.690

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Journal:  Trans Am Ophthalmol Soc       Date:  1981

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Authors:  H E Sisk; K G Zahka; R E Pyeritz
Journal:  Am J Cardiol       Date:  1983-08       Impact factor: 2.778

9.  Two-dimensional echocardiographic aortic root dimensions in normal children and adults.

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Journal:  Am J Cardiol       Date:  1989-09-01       Impact factor: 2.778

10.  A second locus for Marfan syndrome maps to chromosome 3p24.2-p25.

Authors:  G Collod; M C Babron; G Jondeau; M Coulon; J Weissenbach; O Dubourg; J P Bourdarias; C Bonaïti-Pellié; C Junien; C Boileau
Journal:  Nat Genet       Date:  1994-11       Impact factor: 38.330

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  15 in total

Review 1.  Cardiovascular surgery for Marfan syndrome.

Authors:  T Treasure
Journal:  Heart       Date:  2000-12       Impact factor: 5.994

Review 2.  Management of Marfan syndrome.

Authors:  John C S Dean
Journal:  Heart       Date:  2002-07       Impact factor: 5.994

Review 3.  The molecular genetics of Marfan syndrome and related microfibrillopathies.

Authors:  P N Robinson; M Godfrey
Journal:  J Med Genet       Date:  2000-01       Impact factor: 6.318

4.  [Ocular manifestations and surgical results in patients with Marfan syndrome].

Authors:  M S Ladewig; P N Robinson; L M Neumann; F G Holz; M H Foerster
Journal:  Ophthalmologe       Date:  2006-09       Impact factor: 1.059

5.  Natural history of cardiovascular manifestations in Marfan syndrome.

Authors:  C D van Karnebeek; M S Naeff; B J Mulder; R C Hennekam; M Offringa
Journal:  Arch Dis Child       Date:  2001-02       Impact factor: 3.791

6.  Skeletal evolution in Marfan syndrome: growth curves from a French national cohort.

Authors:  Grégoire Benoist; Florence Tubach; Carine Roy; Sabine Rioux; Marlène Michelon-Jouneaux; Bertrand Chevallier; Guillaume Jondeau; Chantal Stheneur
Journal:  Pediatr Res       Date:  2017-09-27       Impact factor: 3.756

Review 7.  Marfan's syndrome and the heart.

Authors:  Alan Graham Stuart; Andrew Williams
Journal:  Arch Dis Child       Date:  2007-04       Impact factor: 3.791

8.  The diagnostic value of the facial features of Marfan syndrome.

Authors:  Beverlie L Ting; Deepti Mathur; Bart L Loeys; Harry C Dietz; Paul D Sponseller
Journal:  J Child Orthop       Date:  2010-10-31       Impact factor: 1.548

9.  Comparison of clinical characteristics and frequency of adverse outcomes in patients with Marfan syndrome diagnosed in adulthood versus childhood.

Authors:  Lisa Willis; Genie E Roosevelt; Anji T Yetman
Journal:  Pediatr Cardiol       Date:  2009-01-30       Impact factor: 1.655

10.  Marfan syndrome in children and adolescents: predictive and prognostic value of aortic root growth for screening for aortic complications.

Authors:  M Groenink; L Rozendaal; M S Naeff; R C Hennekam; A A Hart; E E van der Wall; B J Mulder
Journal:  Heart       Date:  1998-08       Impact factor: 5.994

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