Literature DB >> 8723124

Incidence and spectrum of renal abnormalities in Williams-Beuren syndrome.

R Pankau1, C J Partsch, M Winter, A Gosch, A Wessel.   

Abstract

Kidneys and urinary tract were examined systematically by ultrasonography in 130 patients with Williams-Beuren syndrome (59 females, median age 5.5 years; 71 males, median age 6.4 years). In addition, serum creatinine was determined and an analysis was performed. Creatinine clearance was available in 79 patients. Renal angiographic examinations were done in 18 patients, 8 of whom had renal artery narrowing (44%). The incidence of renal anomalies in Williams-Beuren syndrome was 17.7% vs. around 1.5% in the normal population (P < 0.0003). The spectrum of these anomalies ranged from minor anomalies such as bladder diverticula to more severe malformations such as renal aplasia or hypoplasia (in 5 of 130 patients). In nine patients a duplicated kidney was found. A decreased creatinine clearance (two patients), recurrent symptomatic urinary tract infections (four patients), and hypertension were uncommon. Nephrocalcinosis was not found in our patients. Our data demonstrate that the risk of a structural abnormality of the kidneys and the urinary tract is increased 12- to 36-fold in Williams-Beuren syndrome compared to the normal population. Ultrasound screening of the renal system should be part of the first evaluation of WBS patients.

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Year:  1996        PMID: 8723124     DOI: 10.1002/(SICI)1096-8628(19960503)63:1<301::AID-AJMG49>3.0.CO;2-P

Source DB:  PubMed          Journal:  Am J Med Genet        ISSN: 0148-7299


  10 in total

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Authors:  Benjamin J Landis; David S Cooper; Robert B Hinton
Journal:  Cardiol Young       Date:  2015-09-08       Impact factor: 1.093

Review 2.  Copy number variants at Williams-Beuren syndrome 7q11.23 region.

Authors:  Giuseppe Merla; Nicola Brunetti-Pierri; Lucia Micale; Carmela Fusco
Journal:  Hum Genet       Date:  2010-05-01       Impact factor: 4.132

3.  Prenatal diagnosis of Williams-Beuren syndrome by ultrasound and chromosomal microarray analysis.

Authors:  Ruibin Huang; Hang Zhou; Fang Fu; Ru Li; Tingying Lei; Yingsi Li; Ken Cheng; You Wang; Xin Yang; Lushan Li; Xiangyi Jing; Yongling Zhang; Fucheng Li; Dongzhi Li; Can Liao
Journal:  Mol Cytogenet       Date:  2022-06-28       Impact factor: 1.904

Review 4.  Vesicoureteral reflux and the extracellular matrix connection.

Authors:  Fatima Tokhmafshan; Patrick D Brophy; Rasheed A Gbadegesin; Indra R Gupta
Journal:  Pediatr Nephrol       Date:  2016-05-02       Impact factor: 3.714

5.  Adrenal gland hypertrophy in a case of homolateral renal agenesis: case report with special emphasis on adrenal blood supply.

Authors:  Johann Peltier; Xavier Demondion; Marc Baroncini; Guillaume Wavreille; Christian Fontaine; Antoine Drizencko; Brigitte Mauroy; Daniel Le Gars; Jean-Paul Francke
Journal:  Surg Radiol Anat       Date:  2008-12-24       Impact factor: 1.246

6.  Differing Microdeletion Sizes and Breakpoints in Chromosome 7q11.23 in Williams-Beuren Syndrome Detected by Chromosomal Microarray Analysis.

Authors:  Lin Li; Linhuan Huang; Yanmin Luo; Xuan Huang; Shaobin Lin; Qun Fang
Journal:  Mol Syndromol       Date:  2016-02-02

7.  Uroplakin IIIb, a urothelial differentiation marker, dimerizes with uroplakin Ib as an early step of urothelial plaque assembly.

Authors:  Fang-Ming Deng; Feng-Xia Liang; Liyu Tu; Katheryn A Resing; Ping Hu; Mark Supino; Chih-Chi Andrew Hu; Ge Zhou; Mingxiao Ding; Gert Kreibich; Tung-Tien Sun
Journal:  J Cell Biol       Date:  2002-11-25       Impact factor: 10.539

8.  Williams-Beuren Syndrome: A Clinical Study of 55 Brazilian Patients and the Diagnostic Use of MLPA.

Authors:  Rachel Sayuri Honjo; Roberta Lelis Dutra; Erika Arai Furusawa; Evelin Aline Zanardo; Larissa Sampaio de Athayde Costa; Leslie Domenici Kulikowski; Debora Romeo Bertola; Chong Ae Kim
Journal:  Biomed Res Int       Date:  2015-05-18       Impact factor: 3.411

9.  Prevalence of scoliosis in Williams-Beuren syndrome patients treated at a regional reference center.

Authors:  Marcelo Loquette Damasceno; Alexandre Fogaça Cristante; Raphael Martus Marcon; Tarcísio Eloy Pessoa de Barros Filho
Journal:  Clinics (Sao Paulo)       Date:  2014-07       Impact factor: 2.365

10.  Multiple bladder diverticula with Williams-Beuren syndrome: a case report.

Authors:  Jing Chen; Jianhua Mao; Lezhen Ye; Dongmei Zong; Xiaohui Qiao
Journal:  Transl Pediatr       Date:  2020-12
  10 in total

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