Literature DB >> 8281149

Iduronate-2-sulfatase gene mutations in 16 patients with mucopolysaccharidosis type II (Hunter syndrome).

S Bunge1, C Steglich, C Zuther, M Beck, C P Morris, E Schwinger, A Schinzel, J J Hopwood, A Gal.   

Abstract

Mutations of the iduronate-2-sulfatase gene were identified in 16 patients with mucopolysaccharidosis type II (Hunter syndrome). Together with another 10 cases reported by us earlier it emerges that about 20% of the patients have deletions of the whole gene or other major structural alterations. One, two or three base pair deletions are found in about 23% of the cases while the remaining about 57% carry point mutations predicting amino acid replacement, premature termination of translation, or aberrant splicing. Molecular analysis of mRNA in splice site mutants showed that these latter defects frequently resulted in use of cryptic splice sites in exons or introns. 62% of the small deletions and point mutations have occurred in 3 of the 9 iduronate-2-sulfatase gene exons. Knowledge of the primary genetic defect allows fast and reliable carrier detection and prenatal diagnosis as well as insight into the relationship between genotype and phenotype.

Entities:  

Mesh:

Substances:

Year:  1993        PMID: 8281149     DOI: 10.1093/hmg/2.11.1871

Source DB:  PubMed          Journal:  Hum Mol Genet        ISSN: 0964-6906            Impact factor:   6.150


  17 in total

1.  Clinical and Genetic Characteristics of Romanian Patients with Mucopolysaccharidosis Type II.

Authors:  Camelia Alkhzouz; Cecilia Lazea; Simona Bucerzan; Ioana Nascu; Eva Kiss; Carmencita Lucia Denes; Paula Grigorescu-Sido
Journal:  JIMD Rep       Date:  2016-06-29

2.  A general binding mechanism for all human sulfatases by the formylglycine-generating enzyme.

Authors:  Dirk Roeser; Andrea Preusser-Kunze; Bernhard Schmidt; Kathrin Gasow; Julia G Wittmann; Thomas Dierks; Kurt von Figura; Markus Georg Rudolph
Journal:  Proc Natl Acad Sci U S A       Date:  2005-12-20       Impact factor: 11.205

3.  Deep Genotyping of the IDS Gene in Colombian Patients with Hunter Syndrome.

Authors:  Johanna Galvis; Jannet González; Alfredo Uribe; Harvy Velasco
Journal:  JIMD Rep       Date:  2015-02-15

4.  Mutational and structural analysis of Japanese patients with mucopolysaccharidosis type II.

Authors:  Tomomi Kato; Zenichiro Kato; Izumi Kuratsubo; Noboru Tanaka; Tabito Ishigami; Jun-Ichi Kajihara; Kazuko Sukegawa-Hayasaka; Koji Orii; Koji Isogai; Toshiyuki Fukao; Nobuyuki Shimozawa; Tadao Orii; Naomi Kondo; Yasuyuki Suzuki
Journal:  J Hum Genet       Date:  2005-08-30       Impact factor: 3.172

Review 5.  The mucopolysaccharidoses: a clinical review and guide to management.

Authors:  J E Wraith
Journal:  Arch Dis Child       Date:  1995-03       Impact factor: 3.791

6.  Detailed molecular characterization of a novel IDS exonic mutation associated with multiple pseudoexon activation.

Authors:  L Grodecká; T Kováčová; M Kramárek; S Seneca; K Stouffs; C De Laet; F Majer; T Kršjaková; P Hujová; K Hrnčířová; P Souček; W Lissens; E Buratti; Tomas Freiberger
Journal:  J Mol Med (Berl)       Date:  2016-11-12       Impact factor: 4.599

7.  Intrinsic differences between authentic and cryptic 5' splice sites.

Authors:  Xavier Roca; Ravi Sachidanandam; Adrian R Krainer
Journal:  Nucleic Acids Res       Date:  2003-11-01       Impact factor: 16.971

8.  Molecular basis of iduronate-2-sulphatase gene mutations in patients with mucopolysaccharidosis type II (Hunter syndrome).

Authors:  P Li; A B Bellows; J N Thompson
Journal:  J Med Genet       Date:  1999-01       Impact factor: 6.318

9.  Evidence for an iduronate-sulfatase pseudogene near the functional Hunter syndrome gene in Xq27.3-q28.

Authors:  M Rathmann; S Bunge; C Steglich; E Schwinger; A Gal
Journal:  Hum Genet       Date:  1995-01       Impact factor: 4.132

Review 10.  Hunter disease in the Spanish population: molecular analysis in 31 families.

Authors:  L Gort; A Chabás; M J Coll
Journal:  J Inherit Metab Dis       Date:  1998-08       Impact factor: 4.982

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.