Literature DB >> 34617250

Gitelman syndrome with a novel frameshift variant in SLC12A3 gene accompanied by chronic kidney disease and type 2 diabetes mellitus.

Kenichiro Iio1, Takayasu Mori2, Saki Bessho3, Yosuke Imai3, Masaki Hatanaka3, Hiroki Omori3, Haruhiko Kouhara4, Motoko Chiga2, Eisei Sohara2, Shinichi Uchida2, Jun-Ya Kaimori5.   

Abstract

Gitelman syndrome is an autosomal recessive genetic disease caused by pathogenic variants in SLC12A3 resulting in the loss of function of the Na-Cl co-transporter (NCC) in the distal tubules. Hypokalemia and diuretic effects can cause secondary type 2 diabetes and renal function decline. Here, we present the case of a 49-year-old male patient with chronic persistent treatment-resistant hypokalemia for the past 13 years who had been receiving treatment for type 2 diabetes mellitus for 6 years. He was referred to our department due to the presence of urinary protein, impaired renal function, high renin activity, and hyperaldosteronism. Laboratory test results showed hypokalemia, hypomagnesemia, hypocalciuria, and metabolic alkalosis. Using next-generation and Sanger sequencing, we identified a novel stop-gain variant (NM_000339.3:c.137del [p.His47fs]) and a missense variant (NM_000339.3:c.2927C > T [p.Ser976Phe]) in the SLC12A3 gene. This novel pathogenic variant was located at the intracellular N-terminus of the NCC. Based on these findings, the patient was diagnosed with Gitelman syndrome. The use of next-generation sequencing facilitated the exclusion of diseases with similar clinical symptoms.
© 2021. Japanese Society of Nephrology.

Entities:  

Keywords:  Chronic kidney disease; Gitelman syndrome; Hypokalemia; SLC12A3; Type 2 diabetes mellitus

Mesh:

Substances:

Year:  2021        PMID: 34617250      PMCID: PMC9061911          DOI: 10.1007/s13730-021-00652-4

Source DB:  PubMed          Journal:  CEN Case Rep        ISSN: 2192-4449


  22 in total

Review 1.  Mineralocorticoid receptor antagonists and kidney diseases: pathophysiological basis.

Authors:  Jonatan Barrera-Chimal; Sophie Girerd; Frederic Jaisser
Journal:  Kidney Int       Date:  2019-03-13       Impact factor: 10.612

2.  Does hypokalaemia cause nephropathy? An observational study of renal function in patients with Bartter or Gitelman syndrome.

Authors:  S B Walsh; E Unwin; R Vargas-Poussou; P Houillier; R Unwin
Journal:  QJM       Date:  2011-06-25

3.  Gitelman syndrome: consensus and guidance from a Kidney Disease: Improving Global Outcomes (KDIGO) Controversies Conference.

Authors:  Anne Blanchard; Detlef Bockenhauer; Davide Bolignano; Lorenzo A Calò; Etienne Cosyns; Olivier Devuyst; David H Ellison; Fiona E Karet Frankl; Nine V A M Knoers; Martin Konrad; Shih-Hua Lin; Rosa Vargas-Poussou
Journal:  Kidney Int       Date:  2017-01       Impact factor: 10.612

4.  Resistance to Insulin in Patients with Gitelman Syndrome and a Subtle Intermediate Phenotype in Heterozygous Carriers: A Cross-Sectional Study.

Authors:  Anne Blanchard; Marion Vallet; Laurence Dubourg; Marguerite Hureaux; Julien Allard; Jean-Philippe Haymann; Renaud de la Faille; Armelle Arnoux; Aurelie Dinut; Damien Bergerot; Pierre-Hadrien Becker; Pierre-Yves Courand; Stéphanie Baron; Pascal Houillier; Ivan Tack; Olivier Devuyst; Xavier Jeunemaitre; Michel Azizi; Rosa Vargas-Poussou
Journal:  J Am Soc Nephrol       Date:  2019-07-08       Impact factor: 10.121

Review 5.  Nonsense-mediated mRNA decay in humans at a glance.

Authors:  Tatsuaki Kurosaki; Lynne E Maquat
Journal:  J Cell Sci       Date:  2016-01-19       Impact factor: 5.285

6.  Generation and analysis of the thiazide-sensitive Na+ -Cl- cotransporter (Ncc/Slc12a3) Ser707X knockin mouse as a model of Gitelman syndrome.

Authors:  Sung-Sen Yang; Yi-Fen Lo; I-Shing Yu; Shu-Wha Lin; Tai-Hsiang Chang; Yu-Juei Hsu; Tai-Kuang Chao; Huey-Kang Sytwu; Shinichi Uchida; Sei Sasaki; Shih-Hua Lin
Journal:  Hum Mutat       Date:  2010-10-14       Impact factor: 4.878

7.  Cryptic exon activation in SLC12A3 in Gitelman syndrome.

Authors:  Kandai Nozu; Yoshimi Nozu; Keita Nakanishi; Takao Konomoto; Tomoko Horinouchi; Akemi Shono; Naoya Morisada; Shogo Minamikawa; Tomohiko Yamamura; Junya Fujimura; Koichi Nakanishi; Takeshi Ninchoji; Hiroshi Kaito; Ichiro Morioka; Mariko Taniguchi-Ikeda; Igor Vorechovsky; Kazumoto Iijima
Journal:  J Hum Genet       Date:  2016-10-27       Impact factor: 3.172

8.  Abnormal glucose metabolism and insulin sensitivity in Chinese patients with Gitelman syndrome.

Authors:  Hong Ren; Ling Qin; WeiMing Wang; Jun Ma; Wen Zhang; Ping Yan Shen; Hao Shi; Xiao Li; Nan Chen
Journal:  Am J Nephrol       Date:  2013-01-31       Impact factor: 3.754

9.  Standards and guidelines for the interpretation of sequence variants: a joint consensus recommendation of the American College of Medical Genetics and Genomics and the Association for Molecular Pathology.

Authors:  Sue Richards; Nazneen Aziz; Sherri Bale; David Bick; Soma Das; Julie Gastier-Foster; Wayne W Grody; Madhuri Hegde; Elaine Lyon; Elaine Spector; Karl Voelkerding; Heidi L Rehm
Journal:  Genet Med       Date:  2015-03-05       Impact factor: 8.822

10.  A case of hypokalemia and proteinuria with a new mutation in the SLC12A3 Gene.

Authors:  Qin Chen; Yaqin Wu; Jingya Zhao; Ying Jia; Wei Wang
Journal:  BMC Nephrol       Date:  2018-10-19       Impact factor: 2.388

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