Literature DB >> 33855622

A novel PSEN2 p.Ser175Phe variant in a family with Alzheimer's disease.

Gamze Guven1, Bedia Samanci2, Cagri Gulec3, Hasmet Hanagasi2, Hakan Gurvit2, Ebru Erzurumluoglu Gokalp4, Fatih Tepgec3, Suleyman Guler5, Oya Uyguner3, Basar Bilgic2.   

Abstract

Alzheimer's disease (AD) can be either sporadic or familial, and familial forms of AD accounts for only 5% of the cases. So far, autosomal dominantly inherited mutations in "Presenilin 1" (PSEN1), "Presenilin 2" (PSEN2), and "Amyloid precursor protein" (APP) genes were associated with familial AD. Amid the others, pathogenic mutations in the PSEN2 gene are less common. In this study, we describe a novel heterozygous PSEN2 (c.524C>T, p.Ser175Phe) alteration identified in a 58-year-old Turkish patient from a family with multiple dementia cases. This variant was further present in the patient's clinically affected maternal cousin as well as in the asymptomatic mother and two maternal aunts who were carriers of the APOE ε2/ε3 genotype. The variant is located in the conserved residue of transmembrane domain III encoded by exon 6 of the major transcript. In silico protein structure analyses predicted that this variant might change the architecture of interaction between the two alpha helixes of PSEN2. We propose that p.Ser175Phe may have a pathogenic effect on protein function and may play a significant role in the molecular pathways leading to Alzheimer's disease in this family.

Entities:  

Keywords:  Alzheimer’s disease; PSEN2; S175F; novel

Mesh:

Substances:

Year:  2021        PMID: 33855622     DOI: 10.1007/s10072-021-05243-w

Source DB:  PubMed          Journal:  Neurol Sci        ISSN: 1590-1874            Impact factor:   3.307


  25 in total

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Review 6.  The genetic architecture of Alzheimer's disease: beyond APP, PSENs and APOE.

Authors:  Rita J Guerreiro; Deborah R Gustafson; John Hardy
Journal:  Neurobiol Aging       Date:  2010-07-01       Impact factor: 4.673

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Journal:  Nucleic Acids Res       Date:  2016-05-10       Impact factor: 16.971

9.  A case of possibly pathogenic PSEN2 R62C mutation in a patient with probable early-onset Alzheimer's dementia supported by structure prediction.

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Journal:  Clin Interv Aging       Date:  2017-02-13       Impact factor: 4.458

10.  CADD: predicting the deleteriousness of variants throughout the human genome.

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Journal:  Nucleic Acids Res       Date:  2019-01-08       Impact factor: 16.971

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