Literature DB >> 31932911

Clinical features and prognosis of late-onset neuromyelitis optica spectrum disorders in a Latin American cohort.

Edgar Carnero Contentti1, Vanessa Daccach Marques2, Ibis Soto de Castillo3, Verónica Tkachuk4, Bustos Ariel4, Maria C Castillo3, Edgardo Cristiano5, Gabriel Braga Diégues Serva2, Antonio Carlos Dos Santos2, Ana Mariel Finkelsteyn4, Pablo A López6, Liliana Patrucco5, Omaira Molina3, Juan Pablo Pettinicchi6, Vanesa Toneguzzo4, Alejandro Caride6, Juan Ignacio Rojas5.   

Abstract

BACKGROUND: We aimed to assess the clinical, paraclinical, imaging and prognostic features of patients with late-onset neuromyelitis optica spectrum disorder (LO-NMOSD; ≥ 50 years at disease onset) LO-NMOSD, compared with early onset-NMOSD (EO-NMOSD, ≤ 49 years at disease onset), in Latin American (LATAM).
METHODS: We retrospectively reviewed the medical records of patients with NMOSD, as defined using the 2015 validated diagnostic criteria. We included patients from Argentina, Brazil and Venezuela. They were divided into: LO-NMOSD and EO-NMOSD and comparison among the groups were performed.
RESULTS: Among these 140 NMOSD patients, 24 (17.1%) were LO-NMOSD; 64% were positive for aquaporin-4 antibodies; and 41.5% of this population cohort was non-Caucasian. Severe disability [expanded disability status scale (EDSS) ≥ 6] at the last follow-up and presence of comorbidities were significantly associated with LO-NMOSD, compared with EO-NMOSD. LO-NMOSD patients had a shorter median time to EDSS ≥ 4 than EO-NMOSD patients (46 vs. 60 months; log-rank test p = 0.0006). Furthermore, we observed a positive correlation between age at onset and EDSS score at the last follow-up (Spearman r = 0.34, p < 0.0001).
CONCLUSION: LO-NMOSD patients from LATAM developed early severe disability, compared with EO-NMOSD. Therefore, age at onset could have important implications for the long-term prognosis of NMOSD patients.

Entities:  

Keywords:  Disability; Late-onset NMOSD; Latin america; Neuromyelitis optica spectrum disorder; Prognosis

Year:  2020        PMID: 31932911     DOI: 10.1007/s00415-020-09699-2

Source DB:  PubMed          Journal:  J Neurol        ISSN: 0340-5354            Impact factor:   4.849


  1 in total

1.  Late Onset of Neuromyelitis Optica Spectrum Disorders.

Authors:  Yara Dadalti Fragoso; Heloisa Helena Ruocco; Ronaldo Maciel Dias; Hideraldo Cabeça; Ricardo Gonçalves; Nise A de Carvalho Sousa; Caroline Vieira Spessotto; Carlos Bernardo Tauil; Soniza Vieira Alves-Leon; Sidney Gomes; Marcus Vinicius M Gonçalves; Suzana C Nunes Machado; Andrea Anacleto; Eber Castro Correa; Maria Lucia V Pimentel; Gutemberg Augusto C Santos
Journal:  Neurol Ther       Date:  2019-07-02
  1 in total
  5 in total

1.  Comparison of Early- and Late-Onset NMOSD-Related Optic Neuritis in Thai Patients: Clinical Characteristics and Long-Term Visual Outcomes.

Authors:  Watcharaporn Thongmee; Chanomporn Narongkhananukul; Tanyatuth Padungkiatsagul; Panitha Jindahra; Kavin Vanikieti
Journal:  Clin Ophthalmol       Date:  2021-02-04

2.  An Abnormally High Neutrophil-to-Lymphocyte Ratio Is Not an Independent Outcome Predictor in AQP4-IgG-Positive NMOSD.

Authors:  Edgar Carnero Contentti; Guillermo Delgado-García; Juan Criniti; Pablo A López; Juan Pablo Pettinicchi; Edgardo Cristiano; Jimena Miguez; Edgar Patricio Correa-Díaz; Marcelo Oswaldo Álvarez Pucha; Joselyn Elizabeth Miño Zambrano; Enrique Gómez-Figueroa; Verónica Rivas-Alonso; José Flores-Rivera; Verónica Tkachuk; Alejandro Caride; Juan Ignacio Rojas
Journal:  Front Immunol       Date:  2021-02-23       Impact factor: 7.561

3.  Assessing attacks and treatment response rates among adult patients with NMOSD and MOGAD: Data from a nationwide registry in Argentina.

Authors:  Edgar Carnero Contentti; Pablo A Lopez; Juan Pablo Pettinicchi; Juan Criniti; Agustín Pappolla; Jimena Miguez; Liliana Patrucco; Edgardo Carnero Contentti; Susana Liwacki; Verónica Tkachuk; María E Balbuena; Carlos Vrech; Norma Deri; Jorge Correale; Mariano Marrodan; María C Ysrraelit; Felisa Leguizamon; Geraldine Luetic; María L Menichini; Darío Tavolini; Carolina Mainella; Gisela Zanga; Marcos Burgos; Javier Hryb; Andrés Barboza; Luciana Lazaro; Ricardo Alonso; Nora Fernández Liguori; Débora Nadur; Aníbal Chercoff; Marina Alonso Serena; Alejandro Caride; Friedemann Paul; Juan I Rojas
Journal:  Mult Scler J Exp Transl Clin       Date:  2021-08-20

4.  Relatively Early and Late-Onset Neuromyelitis Optica Spectrum Disorder in Central China: Clinical Characteristics and Prognostic Features.

Authors:  Jinbei Yu; Shuai Yan; Pengpeng Niu; Junfang Teng
Journal:  Front Neurol       Date:  2022-04-14       Impact factor: 4.003

5.  Ocular Manifestations Related to Antibodies Positivity and Inflammatory Biomarkers in a Rheumatological Cohort.

Authors:  Carlos Cifuentes-González; Pilar Uribe-Reina; Juliana Reyes-Guanes; Juliana Muñoz-Ortiz; Paula Tatiana Muñoz-Vargas; William Rojas-Carabali; Dora Victoria Nova-Florián; Ana Sofía De-Los-Ríos; Rubén Dario Mantilla-Hernández; Alejandra de-la-Torre
Journal:  Clin Ophthalmol       Date:  2022-08-09
  5 in total

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