| Literature DB >> 31776722 |
Claudia Brogna1, Lara Cristiano1,2, Tommaso Verdolotti3, Anna Pichiecchio4,5, Claudia Cinnante6, Valeria Sansone7, Luca Maria Sconfienza8,9, Angela Berardinelli10, Matteo Garibaldi11, Giovanni Antonini11, Marika Pane12, Maria Carmela Pera1, Laura Antonaci1, Luana Ficociello3, Emilio Albamonte7, Giorgio Tasca13, Chiara Begliuomini14, Tommaso Tartaglione2,15, Lorenzo Maggi16, Alessandra Govoni17, Giacomo Comi17, Cesare Colosimo3,15, Eugenio Mercuri18,19.
Abstract
Only few studies have reported muscle involvement in spinal muscular atrophy using muscle MRI but this has not been systematically investigated in a large cohort of both pediatric and adult patients with type 2 and type 3 spinal muscular atrophy. The aim of the present study was to define possible patterns of muscle involvement on MRI, assessing both fatty replacement and muscle atrophy, in a cohort of type 2 and type 3 spinal muscular atrophy children and adults (age range 2-45 years), including both ambulant and non-ambulant patients. Muscle MRI protocol consisted in T1-weighted sequences acquired on axial plane covering the pelvis, the thigh, and the leg with contiguous slices. Each muscle was examined through its whole extension using a grading system that allows a semiquantitative evaluation of fatty infiltration. Thigh muscles were also grouped in anterior, posterior, and medial compartment for classification of global atrophy. The results showed a large variability in both type 2 and type 3 spinal muscular atrophy, with a various degree of proximal to distal gradient. Some muscles, such us the adductor longus and gracilis were always selectively spared. In all patients, the involvement was a combination of muscle atrophy and muscle infiltration. The variability observed may help to better understand both natural history and response to new treatments.Entities:
Keywords: Fatty infiltration; Magnetic Resonance Imaging; Muscle atrophy; Spinal muscular atrophy
Year: 2019 PMID: 31776722 DOI: 10.1007/s00415-019-09646-w
Source DB: PubMed Journal: J Neurol ISSN: 0340-5354 Impact factor: 4.849