Literature DB >> 30033443

Whole exome sequencing identifies a novel dominant missense mutation underlying leukonychia in a Pakistani family.

Teka Khan1, Manan Khan1, Ayesha Yousaf1, Saadullah Khan2, Muhammad Naeem3, Akram Shah4, Ghulam Murtaza1, Asim Ali1, Nazish Jabeen1, Hafiz Muhammad Jafar Hussain1, Hui Ma1, Yuanwei Zhang1, Muhammad Zubair1, Xiaohua Jiang1, Huan Zhang5.   

Abstract

Hereditary leukonychia (also known as porcelain nails or white nails) is a genetic disorder. It may exist as an isolated feature or associated with other cutaneous or systemic disorders. Although a number of genes have been described to cause leukonychia, still the underlying genetic etiologies of many cases remain unknown. Here, we report a Pakistani family presenting leukonychia and koilonychia nails in mother and five of her kids. All the affected individuals had white to pale nails in appearance exhibiting complete and partial leukonychia, respectively. Similarly, nails of finger and toe appeared brittle and concave, showing the characteristics features of koilonychia. Whole exome sequencing and subsequent Sanger sequencing identified a pathogenic novel missense mutation (c.1390G>A, p.Glu464Lys) in PLCD1, co-segregating with the disorder in an autosomal dominant pattern. In silico prediction tools supported the pathogenicity of the identified mutation. Literature review determined that mutations in PLCD1 only cause leukonychia. Therefore, our findings add another pathogenic variant to the PLCD1 mutation pool causing leukonychia that would help to understand the underlying molecular mechanism.

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Year:  2018        PMID: 30033443     DOI: 10.1038/s10038-018-0491-2

Source DB:  PubMed          Journal:  J Hum Genet        ISSN: 1434-5161            Impact factor:   3.172


  31 in total

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  1 in total

1.  Identification of two novel mutations in the PLCD1 gene in Chinese patients with hereditary leukonychia.

Authors:  Shuzhan Shen; Minhua Shao; Uma Keyal; Xiuli Wang; Ming Li; Guolong Zhang
Journal:  Mol Med Rep       Date:  2021-03-31       Impact factor: 2.952

  1 in total

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