| Literature DB >> 29849040 |
Natsuki Matsunoshita1,2, Kandai Nozu3, Masahide Yoshikane4, Azusa Kawaguchi5, Naoya Fujita5, Naoya Morisada1, Shingo Ishimori1, Tomohiko Yamamura1, Shogo Minamikawa1, Tomoko Horinouchi1, Keita Nakanishi1, Junya Fujimura1, Takeshi Ninchoji1, Ichiro Morioka1, Hiroaki Nagase1, Mariko Taniguchi-Ikeda1, Hiroshi Kaito1, Kazumoto Iijima1.
Abstract
Pseudo-Bartter/Gitelman syndrome (p-BS/GS) encompasses a clinically heterogeneous group of inherited or acquired disorders similar to Bartter syndrome (BS) or Gitelman syndrome (GS), both renal salt-losing tubulopathies. Phenotypic overlap frequently occurs between p-BS/GS and BS/GS, which are difficult to diagnose based on their clinical presentation and require genetic tests for accurate diagnosis. In addition, p-BS/GS can occur as a result of other inherited diseases such as cystic fibrosis, autosomal dominant hypocalcemia, Dent disease, or congenital chloride diarrhea (CCD). However, the detection of the variants in genes other than known BS/GS-causing genes by conventional Sanger sequencing requires substantial time and resources. We studied 27 cases clinically diagnosed with BS/GS, but with negative genetic tests for known BS/GS genes. We conducted targeted sequencing for 22 genes including genes responsible for tubulopathies and other inherited diseases manifesting with p-BS/GS symptoms. We detected the SLC26A3 gene variants responsible for CCD in two patients. In Patient 1, we found the SLC26A3 compound heterozygous variants: c.354delC and c.1008insT. In Patient 2, we identified the compound heterozygous variants: c.877G > A, p.(Glu293Lys), and c.1008insT. Our results suggest that a comprehensive genetic screening system using targeted sequencing is useful for the diagnosis of patients with p-BS/GS with alternative genetic origins.Entities:
Mesh:
Year: 2018 PMID: 29849040 DOI: 10.1038/s10038-018-0470-7
Source DB: PubMed Journal: J Hum Genet ISSN: 1434-5161 Impact factor: 3.172