Literature DB >> 8841184

Genetic heterogeneity of Bartter's syndrome revealed by mutations in the K+ channel, ROMK.

D B Simon1, F E Karet, J Rodriguez-Soriano, J H Hamdan, A DiPietro, H Trachtman, S A Sanjad, R P Lifton.   

Abstract

Mutations in the Na-K-2Cl cotransporter (NKCC2), a mediator of renal salt reabsorption, cause Bartter's syndrome, featuring salt wasting, hypokalaemic alkalosis, hypercalciuria and low blood pressure. NKCC2 mutations can be excluded in some Bartter's kindreds, prompting examination of regulators of cotransporter activity. One regulator is believed to be ROMK, an ATP-sensitive K+ channel that 'recycles' reabsorbed K+ back to the tubule lumen. Examination of the ROMK gene reveals mutations that co-segregate with the disease and disrupt ROMK function in four Bartter's kindreds. Our findings establish the genetic heterogeneity of Bartter's syndrome, and demonstrate the physiologic role of ROMK in vivo.

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Year:  1996        PMID: 8841184     DOI: 10.1038/ng1096-152

Source DB:  PubMed          Journal:  Nat Genet        ISSN: 1061-4036            Impact factor:   38.330


  194 in total

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