| Literature DB >> 29552444 |
Yanqin Lu1,2, Yanzhou Wang3, Frank Rauch4, Hu Li1,2, Yao Zhang1,2, Naixiang Zhai1,2, Jian Zhang1,2, Xiuzhi Ren5, Jinxiang Han1,2.
Abstract
Osteogenesis imperfecta (OI) and Ehlers-Danlos syndrome (EDS) are rare genetic disorders that are typically inherited in an autosomal dominant manner. Few cases of OI/EDS overlap syndrome have been documented. Described here is a 30-year-old Chinese male with OI type III and EDS. Sequencing of genomic DNA revealed a heterozygous COL1A1 mutation (c.671G>A, p.Gly224Asp) that affected the N-anchor domain of the alpha 1 chain of collagen type I. Ultrastructural analysis of a skin biopsy specimen revealed thin collagen fibers with irregular alignment of collagen fibers. These findings have expanded the genotypic spectrum of the OI/EDS overlap syndrome.Entities:
Keywords: Ehlers-Danlos syndrome; collagen type I; osteogenesis imperfecta; transmission electron microscopy
Year: 2018 PMID: 29552444 PMCID: PMC5849623 DOI: 10.5582/irdr.2018.01010
Source DB: PubMed Journal: Intractable Rare Dis Res ISSN: 2186-3644