Literature DB >> 29329938

Pipeline to gene discovery - Analysing familial Parkinsonism in the Queensland Parkinson's Project.

Steven R Bentley1, Stephanie Bortnick2, Ilaria Guella3, Javed Y Fowdar4, Peter A Silburn5, Stephen A Wood6, Matthew J Farrer7, George D Mellick8.   

Abstract

INTRODUCTION: Family based study designs provide an informative resource to identify disease-causing mutations. The Queensland Parkinson's Project (QPP) has been involved in numerous genetic screening studies; however, details of the families enrolled into the register have not been comprehensively reported. This article characterises the families enrolled in the QPP and summarises monogenic forms of hereditary Parkinsonism found in the register.
METHOD: The presence of pathogenic point mutations and copy number variations (CNVs) were, generally, screened in a sample of over 1000 PD patients from the total of 1725. Whole exome sequencing (WES) was performed on eighteen probands from multiplex families.
RESULTS: The QPP contains seventeen incidences of confirmed monogenic forms of PD, including LRRK2 p.G2019S, VPS35 p.D620N, SNCA duplications and PARK2 p.G430D (hom) & exon 4 deletion (hom). Of these seventeen, five belong to multi-incident families, while another eight have a family history of at least one other case of PD. In additional families, WES did not identify known forms of monogenic Parkinsonism; however, three heterozygous mutations in PARK2, p.R275W, p.Q34fs, and a 40bp deletion in exon 3 were identified. Of these three mutations, only the 40bp deletion segregated with disease in a dominant inheritance pattern.
CONCLUSION: Eighteen probands have screened negative for known CNVs and mutations that cause clear monogenic forms of PD. Each family is a candidate for further genetic analysis to identify genetic variants segregating with disease. The families enrolled in the QPP provide a useful resource to aid in identifying novel forms of monogenic PD.
Copyright © 2018 Elsevier Ltd. All rights reserved.

Entities:  

Keywords:  Familial; Genetics; Hereditary; Multi-incident; Whole exome sequencing

Mesh:

Year:  2018        PMID: 29329938     DOI: 10.1016/j.parkreldis.2017.12.033

Source DB:  PubMed          Journal:  Parkinsonism Relat Disord        ISSN: 1353-8020            Impact factor:   4.891


  7 in total

Review 1.  Genetic predispositions of Parkinson's disease revealed in patient-derived brain cells.

Authors:  Jenne Tran; Helena Anastacio; Cedric Bardy
Journal:  NPJ Parkinsons Dis       Date:  2020-04-24

2.  Plasma biomarkers inclusive of α-synuclein/amyloid-beta40 ratio strongly correlate with Mini-Mental State Examination score in Parkinson's disease and predict cognitive impairment.

Authors:  Daniel Kam Yin Chan; Jack Chen; Ren Fen Chen; Jayesh Parikh; Ying Hua Xu; Peter A Silburn; George D Mellick
Journal:  J Neurol       Date:  2022-07-25       Impact factor: 6.682

Review 3.  Genetic predispositions of Parkinson's disease revealed in patient-derived brain cells.

Authors:  Jenne Tran; Helena Anastacio; Cedric Bardy
Journal:  NPJ Parkinsons Dis       Date:  2020-04-24

4.  Australian Parkinson's Genetics Study (APGS): pilot (n=1532).

Authors:  Svetlana Bivol; George D Mellick; Jacob Gratten; Richard Parker; Aoibhe Mulcahy; Philip E Mosley; Peter C Poortvliet; Adrian I Campos; Brittany L Mitchell; Luis M Garcia-Marin; Simone Cross; Mary Ferguson; Penelope A Lind; Danuta Z Loesch; Peter M Visscher; Sarah E Medland; Clemens R Scherzer; Nicholas G Martin; Miguel E Rentería
Journal:  BMJ Open       Date:  2022-02-25       Impact factor: 3.006

5.  Does a rare mutation in PTPRA contribute to the development of Parkinson's disease in an Australian multi-incident family?

Authors:  Melissa A Hill; Steven R Bentley; Tara L Walker; George D Mellick; Stephen A Wood; Alex M Sykes
Journal:  PLoS One       Date:  2022-07-28       Impact factor: 3.752

6.  Hunting for Familial Parkinson's Disease Mutations in the Post Genome Era.

Authors:  Steven R Bentley; Ilaria Guella; Holly E Sherman; Hannah M Neuendorf; Alex M Sykes; Javed Y Fowdar; Peter A Silburn; Stephen A Wood; Matthew J Farrer; George D Mellick
Journal:  Genes (Basel)       Date:  2021-03-17       Impact factor: 4.096

7.  Mitochondrial and Clearance Impairment in p.D620N VPS35 Patient-Derived Neurons.

Authors:  Zoé Hanss; Simone B Larsen; Paul Antony; Pauline Mencke; François Massart; Javier Jarazo; Jens C Schwamborn; Peter A Barbuti; George D Mellick; Rejko Krüger
Journal:  Mov Disord       Date:  2020-11-03       Impact factor: 10.338

  7 in total

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