Literature DB >> 29182024

First nationwide survey on systemic wild-type ATTR amyloidosis in Japan.

Yoshiki Sekijima1,2, Masahide Yazaki2, Mitsuharu Ueda3, Haruki Koike4, Masahito Yamada5, Yukio Ando3.   

Abstract

OBJECTIVE: A nationwide survey on systemic wild-type ATTR (ATTRwt) amyloidosis was conducted to elucidate the frequency, clinical picture and possible diagnostic issues of ATTRwt amyloidosis in Japan.
METHODS: A questionnaire was sent to 4629 clinical departments across Japan. A total of 2341 (50.6%) responses were returned completed for further analysis.
RESULTS: Fifty-one patients with ATTRwt amyloidosis (82% male) were identified between January 2012 and December 2014. The study subjects were identified in 11 departments at 10 institutes. The mean age of onset and diagnosis were 71.6 and 73.6 years, respectively. The main clinical findings were cardiac failure (76%), cardiac conduction defects/arrhythmia (59%), renal dysfunction (49%), carpal tunnel syndrome (45%) and spinal canal stenosis (22%).
CONCLUSIONS: ATTRwt amyloidosis is diagnosed in a limited number of institutes in Japan and is therefore considered to be underdiagnosed.

Entities:  

Keywords:  Wild-type ATTR amyloidosis; amyloid; nationwide survey; senile systemic amyloidosis; transthyretin

Mesh:

Year:  2017        PMID: 29182024     DOI: 10.1080/13506129.2017.1409706

Source DB:  PubMed          Journal:  Amyloid        ISSN: 1350-6129            Impact factor:   7.141


  9 in total

1.  The integration of genetically-regulated transcriptomics and electronic health records highlights a pattern of medical outcomes related to increased hepatic transthyretin expression.

Authors:  Gita A Pathak; Antonella De Lillo; Frank R Wendt; Flavio De Angelis; Dora Koller; Brenda Cabrera Mendoza; Daniel Jacoby; Edward J Miller; Joel N Buxbaum; Renato Polimanti
Journal:  Amyloid       Date:  2021-12-22       Impact factor: 6.571

Review 2.  Multidisciplinary Approaches for Transthyretin Amyloidosis.

Authors:  Haruki Koike; Takahiro Okumura; Toyoaki Murohara; Masahisa Katsuno
Journal:  Cardiol Ther       Date:  2021-06-04

3.  Hereditary ATTR Amyloidosis with Cardiomyopathy Caused by the Novel Variant Transthyretin Y114S (p.Y134S).

Authors:  Taku Nakase; Taro Yamashita; Yoshimasa Matsuo; Toshiya Nomura; Keiko Sasada; Teruaki Masuda; Yohei Misumi; Kotaro Takamatsu; Seitaro Oda; Yutaro Furukawa; Konen Obayashi; Hirotaka Matsui; Yukio Ando; Mitsuharu Ueda
Journal:  Intern Med       Date:  2019-06-07       Impact factor: 1.271

4.  Estimating the Prevalence of Transthyretin Amyloid Cardiomyopathy in a Large In-Hospital Database in Japan.

Authors:  Ian Winburn; Tomonori Ishii; Takuma Sumikawa; Kanae Togo; Hideo Yasunaga
Journal:  Cardiol Ther       Date:  2019-08-02

5.  Prevalence and prognostic value of autonomic neuropathy assessed by Sudoscan® in transthyretin wild-type cardiac amyloidosis.

Authors:  Mounira Kharoubi; Fréderic Roche; Mélanie Bézard; David Hupin; Sidney Silva; Silvia Oghina; Coraline Chalard; Amira Zaroui; Arnault Galat; Soulef Guendouz; Florence Canoui-Poitrine; Luc Hittinger; Emmanuel Teiger; Jean-Pascal Lefaucheur; Thibaud Damy
Journal:  ESC Heart Fail       Date:  2020-12-22

6.  Expert opinion on monitoring symptomatic hereditary transthyretin-mediated amyloidosis and assessment of disease progression.

Authors:  David Adams; Vincent Algalarrondo; Michael Polydefkis; Nitasha Sarswat; Michel S Slama; Jose Nativi-Nicolau
Journal:  Orphanet J Rare Dis       Date:  2021-10-03       Impact factor: 4.123

Review 7.  Transthyretin Amyloidosis: Update on the Clinical Spectrum, Pathogenesis, and Disease-Modifying Therapies.

Authors:  Haruki Koike; Masahisa Katsuno
Journal:  Neurol Ther       Date:  2020-09-18

8.  Clinical characteristics and natural history of wild-type transthyretin amyloid cardiomyopathy in Japan.

Authors:  Toshihiro Yamada; Seiji Takashio; Yuichiro Arima; Masato Nishi; Mami Morioka; Kyoko Hirakawa; Shinsuke Hanatani; Koichiro Fujisue; Kenshi Yamanaga; Hisanori Kanazawa; Daisuke Sueta; Satoshi Araki; Hiroki Usuku; Taishi Nakamura; Satoru Suzuki; Eiichiro Yamamoto; Mitsuharu Ueda; Koichi Kaikita; Kenichi Tsujita
Journal:  ESC Heart Fail       Date:  2020-07-16

9.  Wild-type transthyretin amyloid cardiomyopathy complicated by spinal canal stenosis, carpal tunnel syndrome, and rotator cuff tears: a case report.

Authors:  Seiji Takashio; Masato Nishi; Yuichiro Tsuruta; Kenichi Tsujita
Journal:  Eur Heart J Case Rep       Date:  2020-11-06
  9 in total

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