| Literature DB >> 28911789 |
Ana Huerta1, Emilia Arjona2, Jose Portoles3, Paula Lopez-Sanchez4, Cristina Rabasco5, Mario Espinosa5, Teresa Cavero6, Miquel Blasco7, Mercedes Cao8, Joaquin Manrique9, Virginia Cabello-Chavez10, Marta Suñer10, Manuel Heras11, Xavier Fulladosa12, Lara Belmar13, Amparo Sempere14, Carmen Peralta15, Lorena Castillo15, Alvaro Arnau16, Manuel Praga6, Santiago Rodriguez de Cordoba17.
Abstract
Pregnancy-associated atypical hemolytic uremic syndrome (aHUS) refers to the thrombotic microangiopathy resulting from uncontrolled complement activation during pregnancy or the postpartum period. Pregnancy-associated aHUS is a devastating disease for which there is a limited clinical understanding and treatment experience. Here we report a retrospective study to analyze the clinical and prognostic data of 22 cases of pregnancy-associated aHUS from the Spanish aHUS Registry under different treatments. Sixteen patients presented during the first pregnancy and as many as nine patients required hemodialysis at diagnosis. Identification of inherited complement abnormalities explained nine of the 22 cases, with CFH mutations and CFH to CFHR1 gene conversion events being the most prevalent genetic alterations associated with this disorder (66%). In thirteen of the cases, pregnancy complications were sufficient to trigger a thrombotic microangiopathy in the absence of genetic or acquired complement alterations. The postpartum period was the time with highest risk to develop the disease and the group shows an association of cesarean section with pregnancy-associated aHUS. Seventeen patients underwent plasma treatments with a positive renal response in only three cases. In contrast, ten patients received eculizumab with an excellent renal response in all, independent of carrying or not inherited complement abnormalities. Although the cohort is relatively small, the data suggest that pregnancy-associated aHUS is not different from other types of aHUS and suggest the efficacy of eculizumab treatment over plasma therapies. This study may be useful to improve prognosis in this group of aHUS patients.Entities:
Keywords: cesarean section; complement; eculizumab; hemolytic uremic syndrome; postpartum
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Year: 2017 PMID: 28911789 DOI: 10.1016/j.kint.2017.06.022
Source DB: PubMed Journal: Kidney Int ISSN: 0085-2538 Impact factor: 10.612