Literature DB >> 28911234

Mucopolysaccharidosis IIIB (Sanfilippo syndrome B) in a commercial emu (Dromaius novaehollandiae) flock.

Seiche C Genger1, Keijiro Mizukami2, Michael P Martin1, Jeffrey R Applegate3, H John Barnes1, Urs Giger2.   

Abstract

Clinicopathological diagnosis of mucopolysaccharidosis type IIIB (MPS IIIB; Sanfilippo syndrome B), an inherited autosomal recessive lysosomal storage disease, as a cause of losses in a commercial emu flock and screening breeders using a mutation-specific DNA test are described. Between 2012 and 2015, ∼5-10 juvenile emus from a few weeks to several months of age developed progressive neurological signs and died while others in the flock remained healthy. Necropsy of two affected siblings revealed multiple sites of haemorrhage, cytoplasmic periodic acid-Schiff and Luxol fast blue-positive inclusions in neurons, and aggregates of foamy macrophages in visceral organs. Affected emus were homozygous for the two-base deletion in the α-N-acetylglucosaminidase gene that causes MPS IIIB in emus. Mutation-specific DNA tests for MPS IIIB in emus were developed. Screening blood samples from 78 breeding emus revealed 14 (18%; 9 males, 4 females, and 1 unknown gender) carriers; an overall 0.09 mutant α-N-acetylglucosaminidase allele frequency. A "test and cull male carriers" programme, in which carrier males are culled but carrier females are retained, was proposed to avoid breeding affected emus together, ultimately eliminating the disease from future broods, and preserving the gene pool with as much breeding stock as possible. Molecular genetic diagnostic tests are simple, precise, and permit screening of all breeders for the mutant allele in any flock and can be used to eliminate MPS IIIB-related emu losses through informed breeding.

Entities:  

Keywords:  Hereditary diseases; lysosomes; neurologic disease; ratite; storage diseases

Mesh:

Substances:

Year:  2017        PMID: 28911234      PMCID: PMC5762256          DOI: 10.1080/03079457.2017.1380293

Source DB:  PubMed          Journal:  Avian Pathol        ISSN: 0307-9457            Impact factor:   3.378


  17 in total

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Journal:  Aust Vet J       Date:  1993-09       Impact factor: 1.281

9.  Emu oil(s): a source of non-toxic transdermal anti-inflammatory agents in aboriginal medicine.

Authors:  M W Whitehouse; A G Turner; C K Davis; M S Roberts
Journal:  Inflammopharmacology       Date:  1998       Impact factor: 5.093

10.  Pathological and biochemical studies of mucopolysaccharidosis type IIIB (Sanfilippo syndrome type B) in juvenile emus (Dromaius novaehollandiae).

Authors:  C Palmieri; U Giger; P Wang; M Pizarro; H L Shivaprasad
Journal:  Vet Pathol       Date:  2014-04-10       Impact factor: 3.157

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Journal:  Stem Cell Res       Date:  2019-03-23       Impact factor: 2.020

2.  Temporospatial Development of Neuropathologic Findings in a Canine Model of Mucopolysaccharidosis IIIB.

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Review 3.  Molecular Bases of Neurodegeneration and Cognitive Decline, the Major Burden of Sanfilippo Disease.

Authors:  Rachel Heon-Roberts; Annie L A Nguyen; Alexey V Pshezhetsky
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