Literature DB >> 27734839

Clinical evaluation and molecular screening of a large consecutive series of albino patients.

Lucia Mauri1, Emanuela Manfredini1, Alessandra Del Longo2, Emanuela Veniani1, Manuela Scarcello1, Roberta Terrana2, Adriano Egidio Radaelli3, Donata Calò3, Giuseppe Mingoia4, Antonella Rossetti4, Giovanni Marsico2, Marco Mazza2, Giovanni Pietro Gesu1, Maria Cristina Patrosso1, Silvana Penco1, Elena Piozzi2, Paola Primignani2.   

Abstract

Oculocutaneous albinism (OCA) is characterized by hypopigmentation of the skin, hair and eye, and by ophthalmologic abnormalities caused by a deficiency in melanin biosynthesis. In this study we recruited 321 albino patients and screened them for the genes known to cause oculocutaneous albinism (OCA1-4 and OCA6) and ocular albinism (OA1). Our purpose was to detect mutations and genetic frequencies of the main causative genes, offering to albino patients an exhaustive diagnostic assessment within a multidisciplinary approach including ophthalmological, dermatological, audiological and genetic evaluations. We report 70 novel mutations and the frequencies of the major causative OCA genes that are as follows: TYR (44%), OCA2 (17%), TYRP1 (1%), SLC45A2 (7%) and SLC24A5 (<0.5%). An additional 5% of patients had GPR143 mutations. In 19% of cases, a second reliable mutation was not detected, whereas 7% of our patients remain still molecularly undiagnosed. This comprehensive study of a consecutive series of OCA/OA1 patients allowed us to perform a clinical evaluation of the different OCA forms.

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Year:  2016        PMID: 27734839     DOI: 10.1038/jhg.2016.123

Source DB:  PubMed          Journal:  J Hum Genet        ISSN: 1434-5161            Impact factor:   3.172


  48 in total

1.  Mutations in the human orthologue of the mouse underwhite gene (uw) underlie a new form of oculocutaneous albinism, OCA4.

Authors:  J M Newton; O Cohen-Barak; N Hagiwara; J M Gardner; M T Davisson; R A King; M H Brilliant
Journal:  Am J Hum Genet       Date:  2001-09-26       Impact factor: 11.025

2.  MC1R, SLC45A2 and TYR genetic variants involved in melanoma susceptibility in southern European populations: results from a meta-analysis.

Authors:  Maider Ibarrola-Villava; Hui-Han Hu; Mickaël Guedj; Lara P Fernandez; Vincent Descamps; Nicole Basset-Seguin; Martine Bagot; Armand Benssussan; Philippe Saiag; Maria Concetta Fargnoli; Ketty Peris; Jose A Aviles; Ana Lluch; Gloria Ribas; Nadem Soufir
Journal:  Eur J Cancer       Date:  2012-03-28       Impact factor: 9.162

3.  SLC24A5 mutations are associated with non-syndromic oculocutaneous albinism.

Authors:  Fanny Morice-Picard; Eulalie Lasseaux; Stéphane François; Delphine Simon; Caroline Rooryck; Eric Bieth; Estelle Colin; Dominique Bonneau; Hubert Journel; Sophie Walraedt; Bart P Leroy; Francoise Meire; Didier Lacombe; Benoit Arveiler
Journal:  J Invest Dermatol       Date:  2013-08-28       Impact factor: 8.551

Review 4.  Albinism and its implications with vision.

Authors:  Bradley J Kirkwood
Journal:  Insight       Date:  2009 Apr-Jun       Impact factor: 0.878

5.  Quantitative differences in endolymphatic calcium and endocochlear potential between pigmented and albino guinea pigs.

Authors:  S S Gill; A N Salt
Journal:  Hear Res       Date:  1997-11       Impact factor: 3.208

6.  High resolution mapping of OCA2 intragenic rearrangements and identification of a founder effect associated with a deletion in Polish albino patients.

Authors:  Caroline Rooryck; Fanny Morice-Picard; Eulalie Lasseaux; Dorothée Cailley; Hélène Dollfus; Sabine Defoort-Dhellemme; Bénédicte Duban-Bedu; Thomy J L de Ravel; Alain Taieb; Didier Lacombe; Benoît Arveiler
Journal:  Hum Genet       Date:  2010-11-18       Impact factor: 4.132

7.  Melanin precursors prevent premature age-related and noise-induced hearing loss in albino mice.

Authors:  Silvia Murillo-Cuesta; Julio Contreras; Esther Zurita; Rafael Cediel; Marta Cantero; Isabel Varela-Nieto; Lluís Montoliu
Journal:  Pigment Cell Melanoma Res       Date:  2009-10-19       Impact factor: 4.693

8.  Mutations in c10orf11, a melanocyte-differentiation gene, cause autosomal-recessive albinism.

Authors:  Karen Grønskov; Christopher M Dooley; Elsebet Østergaard; Robert N Kelsh; Lars Hansen; Mitchell P Levesque; Kaj Vilhelmsen; Kjeld Møllgård; Derek L Stemple; Thomas Rosenberg
Journal:  Am J Hum Genet       Date:  2013-02-07       Impact factor: 11.025

Review 9.  Increasing the complexity: new genes and new types of albinism.

Authors:  Lluís Montoliu; Karen Grønskov; Ai-Hua Wei; Mónica Martínez-García; Almudena Fernández; Benoît Arveiler; Fanny Morice-Picard; Saima Riazuddin; Tamio Suzuki; Zubair M Ahmed; Thomas Rosenberg; Wei Li
Journal:  Pigment Cell Melanoma Res       Date:  2013-10-17       Impact factor: 4.693

10.  Identification and functional validation of a 5' upstream regulatory sequence in the human tyrosinase gene homologous to the locus control region of the mouse tyrosinase gene.

Authors:  Lucía Regales; Patricia Giraldo; Angel García-Díaz; Alfonso Lavado; Lluís Montoliu
Journal:  Pigment Cell Res       Date:  2003-12
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  6 in total

1.  The contribution of common regulatory and protein-coding TYR variants to the genetic architecture of albinism.

Authors:  Vincent Michaud; Eulalie Lasseaux; David J Green; Dave T Gerrard; Claudio Plaisant; Tomas Fitzgerald; Ewan Birney; Benoît Arveiler; Graeme C Black; Panagiotis I Sergouniotis
Journal:  Nat Commun       Date:  2022-07-08       Impact factor: 17.694

2.  Molecular outcomes, clinical consequences, and genetic diagnosis of Oculocutaneous Albinism in Pakistani population.

Authors:  Mohsin Shahzad; Sairah Yousaf; Yar M Waryah; Hadia Gul; Tasleem Kausar; Nabeela Tariq; Umair Mahmood; Muhammad Ali; Muzammil A Khan; Ali M Waryah; Rehan S Shaikh; Saima Riazuddin; Zubair M Ahmed
Journal:  Sci Rep       Date:  2017-03-07       Impact factor: 4.379

3.  Evidence that the Ser192Tyr/Arg402Gln in cis Tyrosinase gene haplotype is a disease-causing allele in oculocutaneous albinism type 1B (OCA1B).

Authors:  Siying Lin; Aida Sanchez-Bretaño; Joseph S Leslie; Katie B Williams; Helena Lee; N Simon Thomas; Jonathan Callaway; James Deline; J Arjuna Ratnayaka; Diana Baralle; Melanie A Schmitt; Chelsea S Norman; Sheri Hammond; Gaurav V Harlalka; Sarah Ennis; Harold E Cross; Olivia Wenger; Andrew H Crosby; Emma L Baple; Jay E Self
Journal:  NPJ Genom Med       Date:  2022-01-13       Impact factor: 6.083

4.  The Phenotypic and Mutational Spectrum of the FHONDA Syndrome and Oculocutaneous Albinism: Similarities and Differences.

Authors:  Charlotte C Kruijt; Libe Gradstein; Arthur A Bergen; Ralph J Florijn; Benoit Arveiler; Eulalie Lasseaux; Xavier Zanlonghi; Laura Bagdonaite-Bejarano; Anne B Fulton; Claudia Yahalom; Anat Blumenfeld; Yonatan Perez; Ohad S Birk; Gerard C de Wit; Nicoline E Schalij-Delfos; Maria M van Genderen
Journal:  Invest Ophthalmol Vis Sci       Date:  2022-01-03       Impact factor: 4.799

5.  Evident hypopigmentation without other ocular deficits in Dutch patients with oculocutaneous albinism type 4.

Authors:  C C Kruijt; N E Schalij-Delfos; G C de Wit; R J Florijn; M M van Genderen
Journal:  Sci Rep       Date:  2021-06-02       Impact factor: 4.379

6.  SLC45A2 protein stability and regulation of melanosome pH determine melanocyte pigmentation.

Authors:  Linh Le; Iliana E Escobar; Tina Ho; Ariel J Lefkovith; Emily Latteri; Kirk D Haltaufderhyde; Megan K Dennis; Lynn Plowright; Elena V Sviderskaya; Dorothy C Bennett; Elena Oancea; Michael S Marks
Journal:  Mol Biol Cell       Date:  2020-09-23       Impact factor: 4.138

  6 in total

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