Literature DB >> 2769722

Cone-rod congenital amaurosis associated with congenital hypertrichosis: an autosomal recessive condition.

I K Jalili1.   

Abstract

Two female cousins were found to be affected with severe retinal dystrophy characterised by visual impairment from birth and profound photophobia in the absence of night blindness. Minimal fundus changes with a small foveal atrophy in the older cousin and slight macular pigment epithelial changes suggestive of early bull's eye appearance in the younger were detected, indicative of a cone-rod type of congenital amaurosis. This was associated with trichomegaly, bushy eyebrows with synophyrys, and excessive facial and body hair (including hypertrophied circumareolar hair on the breasts of the older cousin). The mode of inheritance appears to be autosomal recessive.

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Year:  1989        PMID: 2769722      PMCID: PMC1015672          DOI: 10.1136/jmg.26.8.504

Source DB:  PubMed          Journal:  J Med Genet        ISSN: 0022-2593            Impact factor:   6.318


  12 in total

1.  Disc oedema in congenital amaurosis of Leber.

Authors:  J T Flynn; R F Cullen
Journal:  Br J Ophthalmol       Date:  1975-09       Impact factor: 4.638

2.  The syndrome of trichomegaly, tapetoretinal degeneration and growth disturbances.

Authors:  J W Delleman; K Van Walbeek
Journal:  Ophthalmologica       Date:  1975       Impact factor: 3.250

3.  A gold foil electrode: extending the horizons for clinical electroretinography.

Authors:  G B Arden; R M Carter; C Hogg; I M Siegel; S Margolis
Journal:  Invest Ophthalmol Vis Sci       Date:  1979-04       Impact factor: 4.799

4.  A progressive cone-rod dystrophy and amelogenesis imperfecta: a new syndrome.

Authors:  I K Jalili; N J Smith
Journal:  J Med Genet       Date:  1988-11       Impact factor: 6.318

Review 5.  The cone degenerations.

Authors:  A E Krill; A F Deutman; M Fishman
Journal:  Doc Ophthalmol       Date:  1973-04-16       Impact factor: 2.379

6.  Trichomegaly, cataract, and hereditary spherocytosis in two siblings.

Authors:  J H Goldstein; A E Hutt
Journal:  Am J Ophthalmol       Date:  1972-03       Impact factor: 5.258

7.  Clinical picture of congenital diffuse tapetoretinal degeneration in 42 cases.

Authors:  I Karel
Journal:  Acta Univ Carol Med (Praha)       Date:  1969

8.  Congenital trichomegaly, pigmentary retinal degeneration, and short stature.

Authors:  M A Patton; A E Harding; M Baraitser
Journal:  Am J Ophthalmol       Date:  1986-04-15       Impact factor: 5.258

9.  Trichomegaly, pigmentary degeneration of the retina, and growth retardation. A new syndrome originating in utero.

Authors:  D G Corby; R S Lowe; R C Haskins; L M Hebertson
Journal:  Am J Dis Child       Date:  1971-04

10.  A computerised data base for the diagnosis of rare dysmorphic syndromes.

Authors:  R M Winter; M Baraitser; J M Douglas
Journal:  J Med Genet       Date:  1984-04       Impact factor: 6.318

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  3 in total

Review 1.  [Hypertrichosis].

Authors:  R M Trüeb
Journal:  Hautarzt       Date:  2008-04       Impact factor: 0.751

2.  Congenital Generalized Hypertrichosis, Gingival Hyperplasia, a Coarse Facies with Constriction Bands: A Rare Association.

Authors:  Aditya Kumar Bubna; Mahalakshmi Veeraraghavan; Sankarasubramaniam Anandan; Sudha Rangarajan
Journal:  Int J Trichology       Date:  2015 Apr-Jun

Review 3.  Congenital generalized hypertrichosis: the skin as a clue to complex malformation syndromes.

Authors:  Piero Pavone; Andrea D Praticò; Raffaele Falsaperla; Martino Ruggieri; Marcella Zollino; Giovanni Corsello; Giovanni Neri
Journal:  Ital J Pediatr       Date:  2015-08-05       Impact factor: 2.638

  3 in total

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