Literature DB >> 27155871

Excess maternal transmission of variants in the THADA gene to offspring with type 2 diabetes.

Rashmi B Prasad1, Anna Lessmark2, Peter Almgren2, Györgyi Kovacs3, Ola Hansson2, Nikolay Oskolkov2, Marta Vitai3, Claes Ladenvall2, Peter Kovacs4,5, Joao Fadista2, Michael Lachmann6, Yuedan Zhou2, Emily Sonestedt2, Wenny Poon2, Claes B Wollheim2,7, Marju Orho-Melander2, Michael Stumvoll4,5, Tiinamaija Tuomi8,9, Svante Pääbo10, Laszlo Koranyi3, Leif Groop11,12.   

Abstract

AIMS/HYPOTHESIS: Genome-wide association studies (GWAS) have identified more than 65 genetic loci associated with risk of type 2 diabetes. However, the contribution of distorted parental transmission of alleles to risk of type 2 diabetes has been mostly unexplored. Our goal was therefore to search for parent-of-origin effects (POE) among type 2 diabetes loci in families.
METHODS: Families from the Botnia study (n = 4,211, 1,083 families) were genotyped for 72 single-nucleotide polymorphisms (SNPs) associated with type 2 diabetes and assessed for POE on type 2 diabetes. The family-based Hungarian Transdanubian Biobank (HTB) (n = 1,463, >135 families) was used to replicate SNPs showing POE. Association of type 2 diabetes loci within families was also tested.
RESULTS: Three loci showed nominal POE, including the previously reported variants in KCNQ1, for type 2 diabetes in families from Botnia (rs2237895: p POE  = 0.037), which can be considered positive controls. The strongest POE was seen for rs7578597 SNP in the THADA gene, showing excess transmission of the maternal risk allele T to diabetic offspring (Botnia: p POE  = 0.01; HTB p POE  = 0.045). These data are consistent with previous evidence of allelic imbalance for expression in islets, suggesting that the THADA gene can be imprinted in a POE-specific fashion. Five CpG sites, including those flanking rs7578597, showed differential methylation between diabetic and non-diabetic donor islets. CONCLUSIONS/
INTERPRETATION: Taken together, the data emphasise the need for genetic studies to consider from which parent an offspring has inherited a susceptibility allele.

Entities:  

Keywords:  Families; Genetic association studies; KCNQ1; Maternal effects; Methylation; Parent-of-origin; Parental transmission; THADA; Type 2 diabetes

Mesh:

Substances:

Year:  2016        PMID: 27155871     DOI: 10.1007/s00125-016-3973-9

Source DB:  PubMed          Journal:  Diabetologia        ISSN: 0012-186X            Impact factor:   10.122


  39 in total

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