Literature DB >> 26436900

Human mutant huntingtin disrupts vocal learning in transgenic songbirds.

Wan-Chun Liu1, Jessica Kohn1, Sarah K Szwed1, Eben Pariser1, Sharon Sepe1, Bhagwattie Haripal1, Naoki Oshimori2, Martin Marsala3, Atsushi Miyanohara4, Ramee Lee5.   

Abstract

Speech and vocal impairments characterize many neurological disorders. However, the neurogenetic mechanisms of these disorders are not well understood, and current animal models do not have the necessary circuitry to recapitulate vocal learning deficits. We developed germline transgenic songbirds, zebra finches (Taneiopygia guttata) expressing human mutant huntingtin (mHTT), a protein responsible for the progressive deterioration of motor and cognitive function in Huntington's disease (HD). Although generally healthy, the mutant songbirds had severe vocal disorders, including poor vocal imitation, stuttering, and progressive syntax and syllable degradation. Their song abnormalities were associated with HD-related neuropathology and dysfunction of the cortical-basal ganglia (CBG) song circuit. These transgenics are, to the best of our knowledge, the first experimentally created, functional mutant songbirds. Their progressive and quantifiable vocal disorder, combined with circuit dysfunction in the CBG song system, offers a model for genetic manipulation and the development of therapeutic strategies for CBG-related vocal and motor disorders.

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Year:  2015        PMID: 26436900     DOI: 10.1038/nn.4133

Source DB:  PubMed          Journal:  Nat Neurosci        ISSN: 1097-6256            Impact factor:   24.884


  40 in total

1.  Adult neurogenesis is associated with the maintenance of a stereotyped, learned motor behavior.

Authors:  Carolyn L Pytte; Shanu George; Shoshana Korman; Eva David; Diane Bogdan; John R Kirn
Journal:  J Neurosci       Date:  2012-05-16       Impact factor: 6.167

2.  A comparative study of the behavioral deficits following lesions of various parts of the zebra finch song system: implications for vocal learning.

Authors:  C Scharff; F Nottebohm
Journal:  J Neurosci       Date:  1991-09       Impact factor: 6.167

3.  Rudimentary substrates for vocal learning in a suboscine.

Authors:  Wan-chun Liu; Kazuhiro Wada; Erich D Jarvis; Fernando Nottebohm
Journal:  Nat Commun       Date:  2013       Impact factor: 14.919

4.  RNA interference improves motor and neuropathological abnormalities in a Huntington's disease mouse model.

Authors:  Scott Q Harper; Patrick D Staber; Xiaohua He; Steven L Eliason; Inês H Martins; Qinwen Mao; Linda Yang; Robert M Kotin; Henry L Paulson; Beverly L Davidson
Journal:  Proc Natl Acad Sci U S A       Date:  2005-04-05       Impact factor: 11.205

5.  Aggregation of huntingtin in neuronal intranuclear inclusions and dystrophic neurites in brain.

Authors:  M DiFiglia; E Sapp; K O Chase; S W Davies; G P Bates; J P Vonsattel; N Aronin
Journal:  Science       Date:  1997-09-26       Impact factor: 47.728

6.  Expression analysis of the speech-related genes FoxP1 and FoxP2 and their relation to singing behavior in two songbird species.

Authors:  Qianqian Chen; Jonathan B Heston; Zachary D Burkett; Stephanie A White
Journal:  J Exp Biol       Date:  2013-10-01       Impact factor: 3.312

Review 7.  Knock-in mouse models of Huntington's disease.

Authors:  Liliana B Menalled
Journal:  NeuroRx       Date:  2005-07

Review 8.  Dopaminergic system in birdsong learning and maintenance.

Authors:  Lubica Kubikova; Lubor Kostál
Journal:  J Chem Neuroanat       Date:  2009-11-10       Impact factor: 3.052

9.  Widespread expression of Huntington's disease gene (IT15) protein product.

Authors:  A H Sharp; S J Loev; G Schilling; S H Li; X J Li; J Bao; M V Wagster; J A Kotzuk; J P Steiner; A Lo
Journal:  Neuron       Date:  1995-05       Impact factor: 17.173

10.  Vocal experimentation in the juvenile songbird requires a basal ganglia circuit.

Authors:  Bence P Olveczky; Aaron S Andalman; Michale S Fee
Journal:  PLoS Biol       Date:  2005-03-29       Impact factor: 8.029

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  14 in total

Review 1.  Advantages of comparative studies in songbirds to understand the neural basis of sensorimotor integration.

Authors:  Karagh Murphy; Logan S James; Jon T Sakata; Jonathan F Prather
Journal:  J Neurophysiol       Date:  2017-03-22       Impact factor: 2.714

Review 2.  Avian genomics lends insights into endocrine function in birds.

Authors:  C V Mello; P V Lovell
Journal:  Gen Comp Endocrinol       Date:  2017-06-17       Impact factor: 2.822

Review 3.  Insights into the Neural and Genetic Basis of Vocal Communication.

Authors:  Genevieve Konopka; Todd F Roberts
Journal:  Cell       Date:  2016-03-10       Impact factor: 41.582

4.  Focal expression of mutant huntingtin in the songbird basal ganglia disrupts cortico-basal ganglia networks and vocal sequences.

Authors:  Masashi Tanaka; Jonnathan Singh Alvarado; Malavika Murugan; Richard Mooney
Journal:  Proc Natl Acad Sci U S A       Date:  2016-03-07       Impact factor: 11.205

5.  Neurogenomic insights into the behavioral and vocal development of the zebra finch.

Authors:  Mark E Hauber; Matthew Im Louder; Simon C Griffith
Journal:  Elife       Date:  2021-06-09       Impact factor: 8.140

Review 6.  Gene editing in birds takes flight.

Authors:  Mark E Woodcock; Alewo Idoko-Akoh; Michael J McGrew
Journal:  Mamm Genome       Date:  2017-06-13       Impact factor: 2.957

Review 7.  Primordial germ cell-mediated transgenesis and genome editing in birds.

Authors:  Jae Yong Han; Young Hyun Park
Journal:  J Anim Sci Biotechnol       Date:  2018-01-31

8.  A reliable and flexible gene manipulation strategy in posthatch zebra finch brain.

Authors:  Somayeh Ahmadiantehrani; Sarah E London
Journal:  Sci Rep       Date:  2017-02-24       Impact factor: 4.379

Review 9.  To transduce a zebra finch: interrogating behavioral mechanisms in a model system for speech.

Authors:  Jonathan B Heston; Stephanie A White
Journal:  J Comp Physiol A Neuroethol Sens Neural Behav Physiol       Date:  2017-03-07       Impact factor: 1.836

10.  Efficient gene transfer into zebra finch germline-competent stem cells using an adenoviral vector system.

Authors:  Kyung Min Jung; Young Min Kim; Jin Lee Kim; Jae Yong Han
Journal:  Sci Rep       Date:  2021-07-20       Impact factor: 4.379

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