Literature DB >> 26236414

Photoletter to the editor: Lamellar ichthyosis and arthrogryposis in a premature neonate.

Chiara De Leonibus1, Claudio Lembo2, Alfredo Santantonio1, Tiziana Fioretti3, Silvana Rojo1, Francesco Salvatore4, Massimiliano De Vivo1, Gabriella Esposito5, Paolo Giliberti1.   

Abstract

Lamellar ichthyosis is a rare congenital disorder characterized by collodion membrane at birth and facial anomalies (eclabium and ectropion). The major underlying genetic defect is in TGM1, with mutations of this gene found in 50% of patients. An early diagnosis is fundamental in view of establishing a specific treatment due to the severity of the disease. We report a case of severe lamellar ichthyosis and arthrogryposis, without the typical facial presentation, negative for TGM1 mutations. The clinical improvement was achieved only after treatment with oral retinoids, highlighting the importance of early diagnosis and prompt administration of a specific therapy.

Entities:  

Keywords:  autosomal recessive congenital ichthyoses; congenital ichthyoses; lamellar ichthyosis; oral acitretin; transglutaminase-1 gene mutations

Year:  2015        PMID: 26236414      PMCID: PMC4517804          DOI: 10.3315/jdcr.2015.1202

Source DB:  PubMed          Journal:  J Dermatol Case Rep        ISSN: 1898-7249


  4 in total

1.  Improving outcomes for harlequin ichthyosis.

Authors:  Leonard M Milstone; Keith A Choate
Journal:  J Am Acad Dermatol       Date:  2013-11       Impact factor: 11.527

2.  Different TGM1 mutation spectra in Italian and Portuguese patients with autosomal recessive congenital ichthyosis: evidence of founder effects in Portugal.

Authors:  G Esposito; F De Falco; I Neri; C Graziano; B Toschi; L Auricchio; C Gouveia; A B Sousa; F Salvatore
Journal:  Br J Dermatol       Date:  2013-06       Impact factor: 9.302

3.  Systemic retinoids in the management of ichthyoses and related skin types.

Authors:  John J Digiovanna; Theodora Mauro; Leonard M Milstone; Matthias Schmuth; Jorge R Toro
Journal:  Dermatol Ther       Date:  2013 Jan-Feb       Impact factor: 2.851

Review 4.  Recent advances in the genetics and management of harlequin ichthyosis.

Authors:  Hera Ahmed; Edel A O'Toole
Journal:  Pediatr Dermatol       Date:  2014-06-12       Impact factor: 1.588

  4 in total
  1 in total

1.  Multi-Gene Next-Generation Sequencing for Molecular Diagnosis of Autosomal Recessive Congenital Ichthyosis: A Genotype-Phenotype Study of Four Italian Patients.

Authors:  Tiziana Fioretti; Luigi Auricchio; Angelo Piccirillo; Giuseppina Vitiello; Adelaide Ambrosio; Fabio Cattaneo; Rosario Ammendola; Gabriella Esposito
Journal:  Diagnostics (Basel)       Date:  2020-11-24
  1 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.