Literature DB >> 25435751

Congenital aniridia: long-term clinical course, visual outcome, and prognostic factors.

Ji Woong Chang1, Jeong Hun Kim2, Seong-Joon Kim2, Young Suk Yu2.   

Abstract

PURPOSE: To describe the clinical course of congenital aniridia and to evaluate prognostic factors for visual outcome after long-term follow-up.
METHODS: The medical records of 120 eyes from 60 patients with congenital aniridia were retrospectively reviewed. The prevalence and clinical course of ophthalmic characteristics, systemic disease, refractive errors, and visual acuity were assessed. Prognostic factors for final visual outcomes were analyzed.
RESULTS: Aniridic keratopathy developed in 82 (69%) of 119 eyes. Macular hypoplasia was observed in 70 eyes of 35 patients (91%). Cataract was observed in 63 of 120 eyes (53%). Nystagmus was present in 41 patients (68% of 60 patients) at the initial visit but decreased in five patients (8% of 60 patients). Ocular hypertension was detected in 19 eyes (20% of 93 eyes), six (32% of 19 eyes) of which developed secondarily after cataract surgery. The mean changes in spherical equivalent and astigmatism during the follow-up period were -1.10 and 1.53 diopter, respectively. The mean final visual acuity was 1.028 logarithm of minimal angle of resolution. Nystagmus and ocular hypertension were identified as prognostic factors for poor visual outcome.
CONCLUSIONS: Identification of nystagmus and ocular hypertension was important to predict final visual outcome. Based on the high rate of secondary ocular hypertension after cataract surgery, careful management is needed.

Entities:  

Keywords:  Aniridia; Eye abnormalities; Prognosis

Mesh:

Year:  2014        PMID: 25435751      PMCID: PMC4239467          DOI: 10.3341/kjo.2014.28.6.479

Source DB:  PubMed          Journal:  Korean J Ophthalmol        ISSN: 1011-8942


  23 in total

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Authors:  Helena Lee; Rizwana Khan; Michael O'Keefe
Journal:  Acta Ophthalmol       Date:  2008-10-06       Impact factor: 3.761

10.  Long-term visual prognosis of corneal and ocular surface surgery in patients with congenital aniridia.

Authors:  María Fideliz de la Paz; Juan Alvarez de Toledo; Rafael Ignacio Barraquer; Joaquín Barraquer
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2.  Clinical outcomes and visual prognostic factors in congenital aniridia.

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3.  Congenital aniridia: etiology, manifestations and management.

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4.  Improving long-term intraocular pressure and visual outcomes in eyes with aniridic glaucoma.

Authors:  Ramanjit Sihota; Harathy Selvan; Kishan Azmira; Tanuj Dada; Ajay Sharma; Amisha Gupta; Ashish Upadhyay
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Review 6.  Clinical and molecular aspects of congenital aniridia - A review of current concepts.

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7.  Congenital aniridia with cataract: case series.

Authors:  Jin Da Wang; Jing Shang Zhang; Ying Xiong; Jing Li; Xiao Xia Li; Xue Liu; Jing Zhao; Frank F Tsai; Jhanji Vishal; Qi Sheng You; Yao Huang; Xiu Hua Wan
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8.  Efficacy of carbonic anhydrase inhibitors in management of cystoid macular edema in retinitis pigmentosa: A meta-analysis.

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9.  Functional outcomes after combined iris and intraocular lens implantation in various iris and lens defects.

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