| Literature DB >> 25126051 |
Floriana Licitra1, Hélène Puccio1.
Abstract
Coenzyme Q (CoQ), also known as ubiquinone, is an essential lipophilic molecule present in all cellular membranes and involved in a variety of cellular functions, in particular as an electron carrier in the mitochondrial respiratory chain and as a potent antioxidant. CoQ is synthesized endogenously through a complex metabolic pathway involving over 10 different components. Primary CoQ10 deficiency in humans, due to mutations in genes involved in CoQ biosynthesis, is a heterogeneous group of rare disorders presenting severe and complex clinical symptoms. The generation of mouse models deficient in CoQ is important to further clarify the cellular function of CoQ and to unravel the complexity in the pathophysiological consequences of CoQ deficiency. This review summarizes the current knowledge on mouse models of primary CoQ deficiency.Entities:
Keywords: Cerebellar ataxia; Coenzyme Q; Encephalopathy; Knockout; Mouse models; Nephrotic syndrome
Year: 2014 PMID: 25126051 PMCID: PMC4112528 DOI: 10.1159/000362942
Source DB: PubMed Journal: Mol Syndromol ISSN: 1661-8769