Literature DB >> 24961826

A detailed analysis of methylmalonic acid kinetics during hemodialysis and after combined liver/kidney transplantation in a patient with mut (0) methylmalonic acidemia.

Hilary J Vernon1, C John Sperati, Joshua D King, Andrea Poretti, Neil R Miller, Jennifer L Sloan, Andrew M Cameron, Donna Myers, Charles P Venditti, David Valle.   

Abstract

End stage kidney disease is a well-known complication of methylmalonic acidemia (MMA), and can be treated by dialysis, kidney transplant, or combined kidney-liver transplant. While liver and/or kidney transplantation in MMA may reduce the risk of metabolic crisis and end-organ disease, it does not fully prevent disease-related complications. We performed detailed metabolite and kinetic analyses in a 28-year-old patient with mut (0) MMA who underwent hemodialysis for 6 months prior to receiving a combined liver/kidney transplant. A single hemodialysis session led to a 54 % reduction in plasma methylmalonic acid and yielded a plasma clearance of 103 ml/min and VD0.48 L/kg, which approximates the total body free water space. This was followed by rapid reaccumulation of methylmalonic acid over 24 h to the predialysis concentration in the plasma. Following combined liver/kidney transplantation, the plasma methylmalonic acid was reduced to 3 % of pre-dialysis levels (6,965 ± 1,638 (SD) μmol/L and 234 ± 100 (SD) μmol/L) but remained >850× higher than the upper limit of normal (0.27 ± 0.08 (SD) μmol/L). Despite substantial post-operative metabolic improvement, the patient developed significant neurologic complications including acute worsening of vision in the setting of pre-existing bilateral optic neuropathy, generalized seizures, and a transient, focal leukoencephalopathy. Plasma methylmalonic acid was stable throughout the post-operative course. The biochemical parameters exhibited by this patient further define the whole body metabolism of methylmalonic acid in the setting of dialysis and subsequent combined liver/kidney transplant.

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Year:  2014        PMID: 24961826      PMCID: PMC4373418          DOI: 10.1007/s10545-014-9730-7

Source DB:  PubMed          Journal:  J Inherit Metab Dis        ISSN: 0141-8955            Impact factor:   4.982


  42 in total

1.  The management of organic acidaemias: the role of transplantation.

Authors:  J V Leonard; J H Walter; P J McKiernan
Journal:  J Inherit Metab Dis       Date:  2001-04       Impact factor: 4.982

2.  Successful dialysis in a boy with methylmalonic acidemia.

Authors:  Kyung Hoon Paik; Ji Eun Lee; Dong-Kyu Jin
Journal:  Pediatr Nephrol       Date:  2004-02-21       Impact factor: 3.714

3.  Kidney transplantation in a girl with methylmalonic acidemia and end stage renal failure.

Authors:  R Lubrano; P Scoppi; P Barsotti; E Travasso; S Scateni; S Cristaldi; M A Castello
Journal:  Pediatr Nephrol       Date:  2001-11       Impact factor: 3.714

4.  Methylmalonic acidemia treated by continuous peritoneal dialysis.

Authors:  A Moreno-Vega; J M Govantes
Journal:  N Engl J Med       Date:  1985-06-20       Impact factor: 91.245

5.  Total body water volumes for adult males and females estimated from simple anthropometric measurements.

Authors:  P E Watson; I D Watson; R D Batt
Journal:  Am J Clin Nutr       Date:  1980-01       Impact factor: 7.045

6.  Methylmalonic aciduria. An inborn error of metabolism leading to chronic metabolic acidosis.

Authors:  V G Oberholzer; B Levin; E A Burgess; W F Young
Journal:  Arch Dis Child       Date:  1967-10       Impact factor: 3.791

7.  Amino acid transport across the human blood-CSF barrier. An evaluation graph for amino acid concentrations in cerebrospinal fluid.

Authors:  T Kruse; H Reiber; V Neuhoff
Journal:  J Neurol Sci       Date:  1985-09       Impact factor: 3.181

8.  Progressive neurologic disability in methylmalonic acidemia despite transplantation of the liver.

Authors:  William L Nyhan; J Jay Gargus; Karen Boyle; Rick Selby; Richard Koch
Journal:  Eur J Pediatr       Date:  2002-06-05       Impact factor: 3.183

9.  Inherited methylmalonyl CoA mutase apoenzyme deficiency in human fibroblasts: evidence for allelic heterogeneity, genetic compounds, and codominant expression.

Authors:  H F Willard; L E Rosenberg
Journal:  J Clin Invest       Date:  1980-03       Impact factor: 14.808

10.  Living-related liver transplantation for methylmalonic acidemia: report of one case.

Authors:  Jui-Yu Hsui; Yin-Hsiu Chien; Shao-Yin Chu; Frank Leigh Lu; Huey-Ling Chen; Ming-Je Ho; Po-Huang Lee; Wuh-Liang Hwu
Journal:  Acta Paediatr Taiwan       Date:  2003 May-Jun
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  17 in total

Review 1.  Liver involvement in kidney disease and vice versa.

Authors:  Karen Van Hoeve; Djalila Mekahli; Eva Morava; Elena Levtchenko; Peter Witters
Journal:  Pediatr Nephrol       Date:  2017-06-23       Impact factor: 3.714

2.  Multi-omics studies in cellular models of methylmalonic acidemia and propionic acidemia reveal dysregulation of serine metabolism.

Authors:  Arianna Franca Anzmann; Sneha Pinto; Veronica Busa; James Carlson; Susan McRitchie; Susan Sumner; Akhilesh Pandey; Hilary J Vernon
Journal:  Biochim Biophys Acta Mol Basis Dis       Date:  2019-08-23       Impact factor: 5.187

Review 3.  Methylmalonic and propionic acidemias: clinical management update.

Authors:  Jamie L Fraser; Charles P Venditti
Journal:  Curr Opin Pediatr       Date:  2016-12       Impact factor: 2.856

Review 4.  Liver transplantation in propionic and methylmalonic acidemia: A single center study with literature review.

Authors:  Nishitha R Pillai; Bridget M Stroup; Anna Poliner; Linda Rossetti; Brandy Rawls; Brian J Shayota; Claudia Soler-Alfonso; Hari Priya Tunuguntala; John Goss; William Craigen; Fernando Scaglia; V Reid Sutton; Ryan Wallace Himes; Lindsay C Burrage
Journal:  Mol Genet Metab       Date:  2019-11-07       Impact factor: 4.797

5.  Guidelines for the diagnosis and management of methylmalonic acidaemia and propionic acidaemia: First revision.

Authors:  Patrick Forny; Friederike Hörster; Diana Ballhausen; Anupam Chakrapani; Kimberly A Chapman; Carlo Dionisi-Vici; Marjorie Dixon; Sarah C Grünert; Stephanie Grunewald; Goknur Haliloglu; Michel Hochuli; Tomas Honzik; Daniela Karall; Diego Martinelli; Femke Molema; Jörn Oliver Sass; Sabine Scholl-Bürgi; Galit Tal; Monique Williams; Martina Huemer; Matthias R Baumgartner
Journal:  J Inherit Metab Dis       Date:  2021-03-09       Impact factor: 4.750

6.  Factors influencing in-hospital death for pediatric patients with isolated methylmalonic acidemia: a nationwide inpatient database analysis.

Authors:  Yi-Zhou Jiang; Yu Shi; Ying Shi; Lan-Xia Gan; Yuan-Yuan Kong; Li-Ying Sun; Hai-Bo Wang; Zhi-Jun Zhu
Journal:  Orphanet J Rare Dis       Date:  2020-06-19       Impact factor: 4.123

7.  Label-Free Quantitative Proteomics in a Methylmalonyl-CoA Mutase-Silenced Neuroblastoma Cell Line.

Authors:  Michele Costanzo; Armando Cevenini; Emanuela Marchese; Esther Imperlini; Maddalena Raia; Luigi Del Vecchio; Marianna Caterino; Margherita Ruoppolo
Journal:  Int J Mol Sci       Date:  2018-11-13       Impact factor: 5.923

8.  Methylmalonic acidemia/propionic acidemia - the biochemical presentation and comparing the outcome between liver transplantation versus non-liver transplantation groups.

Authors:  Tzu-Hung Chu; Yin-Hsiu Chien; Hsiang-Yu Lin; Hsuan-Chieh Liao; Huey-Jane Ho; Chih-Jou Lai; Chuan-Chi Chiang; Niang-Cheng Lin; Chia-Feng Yang; Wuh-Liang Hwu; Ni-Chung Lee; Shuan-Pei Lin; Chin-Su Liu; Rey-Heng Hu; Ming-Chih Ho; Dau-Ming Niu
Journal:  Orphanet J Rare Dis       Date:  2019-04-02       Impact factor: 4.123

9.  Perioperative characteristics and management of liver transplantation for isolated methylmalonic acidemia-the largest experience in China.

Authors:  Yi-Zhou Jiang; Li-Ying Sun; Zhi-Jun Zhu; Lin Wei; Wei Qu; Zhi-Gui Zeng; Ying Liu; Yu-Le Tan; En-Hui He; Rui-Fang Xu; Liang Zhang; Jun Wang; Xiao-Jie Chen
Journal:  Hepatobiliary Surg Nutr       Date:  2019-10       Impact factor: 7.293

10.  Promoterless, Nuclease-Free Genome Editing Confers a Growth Advantage for Corrected Hepatocytes in Mice With Methylmalonic Acidemia.

Authors:  Randy J Chandler; Leah E Venturoni; Jing Liao; Brandon T Hubbard; Jessica L Schneller; Victoria Hoffmann; Susana Gordo; Shengwen Zang; Chih-Wei Ko; Nelson Chau; Kyle Chiang; Mark A Kay; Adi Barzel; Charles P Venditti
Journal:  Hepatology       Date:  2021-05-21       Impact factor: 17.298

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