Literature DB >> 23583142

The surgical management of Rapunzel syndrome: a case series and literature review.

Sara C Fallon1, Bethany J Slater, Emily L Larimer, Mary L Brandt, Monica E Lopez.   

Abstract

BACKGROUND/
PURPOSE: The surgical removal of a trichobezoar is the rare end complication of the psychiatric disorders trichotillomania and trichophagia. The more severe form of the disease is termed Rapunzel syndrome, where the bezoar extends from the gastric body beyond the pylorus into the duodenum. Traditional therapy has included endoscopy, often with subsequent laparotomy, and associated psychiatric intervention. We present the largest and most recent series of patients with trichobezoars managed in a single institution.
METHODS: A retrospective review of all cases of trichobezoar at our institution from 2003 to 2011 was performed. Demographic data, presenting complaints, imaging, surgical treatment, and subsequent management were collected.
RESULTS: All 7 patients were female, ages 5 to 23 years (mean, 11.5 years). Although multiple imaging modalities were necessary for preoperative diagnosis, most patients were accurately diagnosed without endoscopic evaluation (85%). All patients required an exploratory laparotomy for definitive treatment. At laparotomy, 5 patients were found to have postpyloric extension of the trichobezoar (71%). One of 7 patients had a wound infection postoperatively. There were no other surgical complications or recurrences requiring further exploration.
CONCLUSIONS: Our series of trichobezoar patients appear to have a high rate of Rapunzel syndrome, and perhaps postpyloric extension should be considered the rule rather than the exception. Our series demonstrates that diagnosis can be established with a thorough history combined with radiography, and treatment should be a combination of laparoscopy and/or laparotomy with psychiatric consultation.
Copyright © 2013 Elsevier Inc. All rights reserved.

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Year:  2013        PMID: 23583142     DOI: 10.1016/j.jpedsurg.2012.07.046

Source DB:  PubMed          Journal:  J Pediatr Surg        ISSN: 0022-3468            Impact factor:   2.545


  18 in total

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Authors:  Devin C Flaherty; Francis Aguilar; Basant Pradhan; Harsh Grewal
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9.  Rapunzel Syndrome-An Extremely Rare Cause of Digestive Symptoms in Children: A Case Report and a Review of the Literature.

Authors:  Cristina Oana Marginean; Lorena Elena Melit; Maria Oana Sasaran; Razvan Marginean; Zoltan Derzsi
Journal:  Front Pediatr       Date:  2021-06-09       Impact factor: 3.418

10.  Laparoscopic Management of Acute Pancreatitis Secondary to Rapunzel Syndrome.

Authors:  Bijan Koushk Jalali; Alperen Bingöl; Ashraf Reyad
Journal:  Case Rep Surg       Date:  2016-04-10
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