Literature DB >> 22481662

Clinical variability in dystrophic epidermolysis bullosa and findings with scanning electron microscopy.

Hiram Larangeira de Almeida1, Luciane Maria Alves Monteiro, Fernanda Mendes Goetze, Ricardo Marques e Silva, Nara Moreira Rocha.   

Abstract

In dystrophic epidermolysis bullosa, the genetic defect of anchoring fibrils leads to cleavage beneath the basement membrane and its consequent loss. A 46 year-old female patient presented blisters with a pretibial distribution associated with nail dystrophy. Her two children had hyponychia and anonychia, which affected all toe nails and the thumb, forefinger and middle finger. DNA sequencing identified in exon 75 of COL7A1 gene a pathologic mutation: c.6235G>A (p.Gly2079Arg). Immunomapping of a blister demonstrated collagen IV (basal membrane) in the blister roof and collagen VII in its floor, confirming dystrophic epidermolysis bullosa. Scanning electron microscopy of an inverted blister showed net-forming collagen attached to the blister roof . The variability found in this family has already been reported and confirms, on a clinical basis, the nail subtype as a dystrophic variant.

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Year:  2012        PMID: 22481662     DOI: 10.1590/s0365-05962012000100017

Source DB:  PubMed          Journal:  An Bras Dermatol        ISSN: 0365-0596            Impact factor:   1.896


  2 in total

1.  Pretibial dystrophic epidermolysis bullosa.

Authors:  Elisabeth de Albuquerque Cavalcanti Callegaro; Flavio Nappi; Rosana Lazzarini; Rute Facchini Lellis
Journal:  An Bras Dermatol       Date:  2017       Impact factor: 1.896

2.  Comparative scanning electron microscopy of bullous diseases.

Authors:  Hiram Larangeira de Almeida; Gabriela Rossi; Octavio Ruschel Karam; Nara Moreira Rocha; Ricardo Marques E Silva
Journal:  An Bras Dermatol       Date:  2014 Mar-Apr       Impact factor: 1.896

  2 in total

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