Literature DB >> 21627495

A template for mutational data analysis of the CFTR gene.

Giampiero Ferraguti1, Silvia Pierandrei, Sabina Maria Bruno, Fabrizio Ceci, Roberto Strom, Marco Lucarelli.   

Abstract

BACKGROUND: Automated DNA sequencing produces large amounts of data that need to be analyzed by appropriate software. Personalization of software can be a difficult and time-consuming task, especially if a large number of mutations have to be analyzed.
METHODS: The Applied BioSystems SeqScape software, based on the KB basecaller algorithm, is a versatile tool that can be used for mutational analysis and for data quality assessment of sequences belonging to any gene of interest. Using this software we analyzed over 1400 sequences of CFTR exons and adjacent intronic zones, representing over 500,000 bases.
RESULTS: We present an up to date specific template and a linked set of instructions for automated labeling of all point mutations and polymorphisms of the CFTR gene, whose mutations cause cystic fibrosis (the most common genetic disease among Caucasian individuals). We also describe our refined software settings for mutational analysis, in order to keep to a minimum the need of manual validation.
CONCLUSIONS: The use of our template greatly simplifies the mutational analysis of the CFTR gene, reducing human intervention. In our opinion, it might not only be useful to researchers that already perform CFTR mutational analysis by sequencing methods but it should also improve the approach in those laboratories that already use ABI PRISM instrumentation for a limited mutational analysis of the CFTR gene. Similar mutational templates can also be used for other disease causing genes, thus improving molecular genetics protocols.

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Year:  2011        PMID: 21627495      PMCID: PMC3337638          DOI: 10.1515/CCLM.2011.604

Source DB:  PubMed          Journal:  Clin Chem Lab Med        ISSN: 1434-6621            Impact factor:   3.694


  12 in total

1.  A 96-well formatted method for exon and exon/intron boundary full sequencing of the CFTR gene.

Authors:  Marco Lucarelli; Lorena Narzi; Rita Piergentili; Giampiero Ferraguti; Francesco Grandoni; Serena Quattrucci; Roberto Strom
Journal:  Anal Biochem       Date:  2006-04-05       Impact factor: 3.365

2.  Molecular diagnosis of cystic fibrosis: comparison of four analytical procedures.

Authors:  Rossella Tomaiuolo; Mariacristina Spina; Giuseppe Castaldo
Journal:  Clin Chem Lab Med       Date:  2003-01       Impact factor: 3.694

Review 3.  Cystic fibrosis.

Authors:  Jane C Davies; Eric W F W Alton; Andrew Bush
Journal:  BMJ       Date:  2007-12-15

4.  Best practice guidelines for molecular genetic diagnosis of cystic fibrosis and CFTR-related disorders--updated European recommendations.

Authors:  Els Dequeker; Manfred Stuhrmann; Michael A Morris; Teresa Casals; Carlo Castellani; Mireille Claustres; Harry Cuppens; Marie des Georges; Claude Ferec; Milan Macek; Pier-Franco Pignatti; Hans Scheffer; Marianne Schwartz; Michal Witt; Martin Schwarz; Emmanuelle Girodon
Journal:  Eur J Hum Genet       Date:  2008-08-06       Impact factor: 4.246

5.  Computer-assisted reading of DNA sequences.

Authors:  Huong Le; Marcus Hinchcliffe; Bing Yu; Ronald J A Trent
Journal:  Methods Mol Med       Date:  2008

6.  A software system for data analysis in automated DNA sequencing.

Authors:  M C Giddings; J Severin; M Westphall; J Wu; L M Smith
Journal:  Genome Res       Date:  1998-06       Impact factor: 9.043

7.  Base-calling of automated sequencer traces using phred. I. Accuracy assessment.

Authors:  B Ewing; L Hillier; M C Wendl; P Green
Journal:  Genome Res       Date:  1998-03       Impact factor: 9.043

Review 8.  Cystic fibrosis: a worldwide analysis of CFTR mutations--correlation with incidence data and application to screening.

Authors:  Joseph L Bobadilla; Milan Macek; Jason P Fine; Philip M Farrell
Journal:  Hum Mutat       Date:  2002-06       Impact factor: 4.878

Review 9.  Emerging DNA sequencing technologies for human genomic medicine.

Authors:  Robert L Strausberg; Samuel Levy; Yu-Hui Rogers
Journal:  Drug Discov Today       Date:  2008-05-22       Impact factor: 7.851

Review 10.  CFTR function and prospects for therapy.

Authors:  John R Riordan
Journal:  Annu Rev Biochem       Date:  2008       Impact factor: 23.643

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  5 in total

1.  Two novel and correlated CF-causing insertions in the (TG)mTn tract of the CFTR gene.

Authors:  Silvia Pierandrei; Giovanna Blaconà; Benedetta Fabrizzi; Giuseppe Cimino; Natalia Cirilli; Nicole Caporelli; Antonio Angeloni; Marco Cipolli; Marco Lucarelli
Journal:  PLoS One       Date:  2019-10-08       Impact factor: 3.240

2.  Next Generation Sequencing in Newborn Screening in the United Kingdom National Health Service.

Authors:  Julia C van Campen; Elizabeth S A Sollars; Rebecca C Thomas; Clare M Bartlett; Antonio Milano; Matthew D Parker; Jennifer Dawe; Peter R Winship; Gerrard Peck; Darren Grafham; Richard J Kirk; James R Bonham; Anne C Goodeve; Ann Dalton
Journal:  Int J Neonatal Screen       Date:  2019-11-05

3.  Quantitative Evaluation of CFTR Pre-mRNA Splicing Dependent on the (TG)mTn Poly-Variant Tract.

Authors:  Manuela Sterrantino; Andrea Fuso; Silvia Pierandrei; Sabina Maria Bruno; Giancarlo Testino; Giuseppe Cimino; Antonio Angeloni; Marco Lucarelli
Journal:  Diagnostics (Basel)       Date:  2021-01-25

4.  Theratyping cystic fibrosis in vitro in ALI culture and organoid models generated from patient-derived nasal epithelial conditionally reprogrammed stem cells.

Authors:  Giovanni Sette; Stefania Lo Cicero; Giovanna Blaconà; Silvia Pierandrei; Sabina Maria Bruno; Valentina Salvati; Germana Castelli; Mario Falchi; Benedetta Fabrizzi; Giuseppe Cimino; Ruggero De Maria; Mauro Biffoni; Adriana Eramo; Marco Lucarelli
Journal:  Eur Respir J       Date:  2021-12-02       Impact factor: 16.671

5.  A Genotypic-Oriented View of CFTR Genetics Highlights Specific Mutational Patterns Underlying Clinical Macrocategories of Cystic Fibrosis.

Authors:  Marco Lucarelli; Sabina Maria Bruno; Silvia Pierandrei; Giampiero Ferraguti; Antonella Stamato; Fabiana Narzi; Annalisa Amato; Giuseppe Cimino; Serenella Bertasi; Serena Quattrucci; Roberto Strom
Journal:  Mol Med       Date:  2015-04-21       Impact factor: 6.354

  5 in total

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