Literature DB >> 21312327

Newborn screening for lysosomal storage disorders.

Kimitoshi Nakamura1, Kiyoko Hattori, Fumio Endo.   

Abstract

Lysosomes are intracellular organelles containing acid hydrolases that degrade biological macromolecules. Lysosomal storage disorders (LSDs) are caused by absent activity of one or more of these enzymes due to mutations of genes encoding lysosomal hydrolases or enzymes that process, target, and transport these enzymes. The specific signs and symptoms of each LSD derive from the type of material accumulated within the lysosome, the site (organ) of accumulation and the response of the body (sometimes in the form of an inflammatory or immune response) to the accumulated material. Interest for inclusion of these disorders in newborn screening programs derives from the availability of effective therapy in the form of enzyme replacement or substrate reduction therapy and bone marrow transplant that may improve long-term outcome especially if started prior to irreversible organ damage. Based on the availability of therapy and suitable screening methods, Gaucher disease, Fabry disease, Pompe disease, mucopolysaccharidosis I and II, Niemann-Pick disease, and Krabbe disease are candidates for newborn screening. Pilot newborn screening projects have been performed for some of these conditions that indicate the feasibility of this approach. This review will provide insight into these screening strategies and discuss their advantages and limitations. © 2011 Wiley-Liss, Inc.
Copyright © 2011 Wiley-Liss, Inc.

Entities:  

Mesh:

Substances:

Year:  2011        PMID: 21312327     DOI: 10.1002/ajmg.c.30291

Source DB:  PubMed          Journal:  Am J Med Genet C Semin Med Genet        ISSN: 1552-4868            Impact factor:   3.908


  13 in total

1.  Newborn screening for lysosomal storage disorders in hungary.

Authors:  Judit Wittmann; Eszter Karg; Sàndor Turi; Elisa Legnini; Gyula Wittmann; Anne-Katrin Giese; Jan Lukas; Uta Gölnitz; Michael Klingenhäger; Olaf Bodamer; Adolf Mühl; Arndt Rolfs
Journal:  JIMD Rep       Date:  2012-03-21

Review 2.  Dangerous and expensive screening and treatment for rare childhood diseases: the case of Krabbe disease.

Authors:  John D Lantos
Journal:  Dev Disabil Res Rev       Date:  2011

3.  Enzyme Replacement Therapy in Mucopolysaccharidosis II Patients Under 1 Year of Age.

Authors:  Christina Lampe; Andrea Atherton; Barbara K Burton; Maria Descartes; Roberto Giugliani; Dafne D G Horovitz; Sandra O Kyosen; Tatiana S P C Magalhães; Ana Maria Martins; Nancy J Mendelsohn; Joseph Muenzer; Laurie D Smith
Journal:  JIMD Rep       Date:  2014-02-11

4.  Molecular testing of 163 patients with Morquio A (Mucopolysaccharidosis IVA) identifies 39 novel GALNS mutations.

Authors:  A Morrone; K L Tylee; M Al-Sayed; A C Brusius-Facchin; A Caciotti; H J Church; M J Coll; K Davidson; M J Fietz; L Gort; M Hegde; F Kubaski; L Lacerda; F Laranjeira; S Leistner-Segal; S Mooney; S Pajares; L Pollard; I Ribeiro; R Y Wang; N Miller
Journal:  Mol Genet Metab       Date:  2014-03-20       Impact factor: 4.797

5.  Dried blood spots for the enzymatic diagnosis of lysosomal storage diseases in dogs and cats.

Authors:  Adrian C Sewell; Mark E Haskins; Urs Giger
Journal:  Vet Clin Pathol       Date:  2012-11-02       Impact factor: 1.180

6.  Expanding rare disease drug trials based on shared molecular etiology.

Authors:  Philip J Brooks; Danilo A Tagle; Steve Groft
Journal:  Nat Biotechnol       Date:  2014-06       Impact factor: 54.908

7.  Reference intervals of α-glycosidase, β-glycosidase, and α-galactosidase in dried blood spot in a Turkish newborn population.

Authors:  Ozan Aldemir; Pelin Ergun; Sezgin Güneş; Ozge Altun Köroğlu; Mehmet Yalaz; Nilgün Kültürsay; Mahmut Coker; Eser Y Sözmen
Journal:  Eur J Pediatr       Date:  2013-05-10       Impact factor: 3.183

Review 8.  Gene therapy approaches for lysosomal storage disease: next-generation treatment.

Authors:  Barry J Byrne; Darin J Falk; Nathalie Clément; Cathryn S Mah
Journal:  Hum Gene Ther       Date:  2012-08       Impact factor: 5.695

9.  Establishment of Cutoff Values for Newborn Screening of Six Lysosomal Storage Disorders by Tandem Mass Spectrometry.

Authors:  Ruotong Li; Liping Tian; Qing Gao; Yuanfang Guo; Gaijie Li; Yulin Li; Meng Sun; Yan Yan; Qing Li; Wenying Nie; Hui Zou
Journal:  Front Pediatr       Date:  2022-03-28       Impact factor: 3.418

10.  Glucosylsphingosine is a highly sensitive and specific biomarker for primary diagnostic and follow-up monitoring in Gaucher disease in a non-Jewish, Caucasian cohort of Gaucher disease patients.

Authors:  Arndt Rolfs; Anne-Katrin Giese; Ulrike Grittner; Daniel Mascher; Deborah Elstein; Ari Zimran; Tobias Böttcher; Jan Lukas; Rayk Hübner; Uta Gölnitz; Anja Röhle; Ales Dudesek; Wolfgang Meyer; Matthias Wittstock; Hermann Mascher
Journal:  PLoS One       Date:  2013-11-20       Impact factor: 3.240

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.