Literature DB >> 20799320

Further characterization of microdeletion syndrome involving 2p15-p16.1.

Têmis Maria Félix1, Aline Lourenço Petrin, Maria Teresa Vieira Sanseverino, Jeffrey C Murray.   

Abstract

We report on a patient presenting with cognitive delay, prenatal and postnatal growth deficiency, microcephaly, ptosis of eyelids, high and broad nasal root, and camptodactyly. Analysis of a dense whole genome single-nucleotide polymorphism (SNP) array showed a de novo 3.35 Mb deletion on 2p15-p16.1. In order to study the parental origin of the deletion we analyzed selected SNPs in the deleted area in the proband and her parents showing Mendelian incompatibilities suggesting a de novo deletion on the chromosome of paternal origin. Based on the five cases described previously in the literature, we have narrowed the critical region responsible for the 2p15-p16.1 microdeletion syndrome phenotype. The critical region does not include the VRK2 gene that had been speculated to have a role in cortical dysplasia. However, the association of the VRK2 gene with cortical dysplasia remains to be determined, as MRI imaging of the brain and gene content of the 2p15-16 deletion becomes established in more patients.
Copyright © 2010 Wiley-Liss, Inc.

Entities:  

Mesh:

Substances:

Year:  2010        PMID: 20799320      PMCID: PMC2946431          DOI: 10.1002/ajmg.a.33612

Source DB:  PubMed          Journal:  Am J Med Genet A        ISSN: 1552-4825            Impact factor:   2.802


  14 in total

1.  Molecular karyotyping in patients with mental retardation using 100K single-nucleotide polymorphism arrays.

Authors:  Juliane Hoyer; Alexander Dreweke; Christian Becker; Ina Göhring; Christian T Thiel; Maarit M Peippo; Ralf Rauch; Michael Hofbeck; Udo Trautmann; Christiane Zweier; Martin Zenker; Ulrike Hüffmeier; Cornelia Kraus; Arif B Ekici; Franz Rüschendorf; Peter Nürnberg; André Reis; Anita Rauch
Journal:  J Med Genet       Date:  2007-06-29       Impact factor: 6.318

2.  A newly recognised microdeletion syndrome of 2p15-16.1 manifesting moderate developmental delay, autistic behaviour, short stature, microcephaly, and dysmorphic features: a new patient with 3.2 Mb deletion.

Authors:  J-S Liang; K Shimojima; K Ohno; C Sugiura; Y Une; K Ohno; T Yamamoto
Journal:  J Med Genet       Date:  2009-09       Impact factor: 6.318

3.  Screening for subtelomeric rearrangements in 210 patients with unexplained mental retardation using multiplex ligation dependent probe amplification (MLPA).

Authors:  D A Koolen; W M Nillesen; M H A Versteeg; G F M Merkx; N V A M Knoers; M Kets; S Vermeer; C M A van Ravenswaaij; C G de Kovel; H G Brunner; D Smeets; B B A de Vries; E A Sistermans
Journal:  J Med Genet       Date:  2004-12       Impact factor: 6.318

4.  Leucodysplasia, microcephaly, cerebral malformation (LMC): a novel recessive disorder linked to 2p16.

Authors:  K E Chandler; A Del Rio; K Rakshi; K Springell; D K Williams; N Stoodley; C G Woods; D T Pilz
Journal:  Brain       Date:  2005-11-04       Impact factor: 13.501

5.  Clinical and molecular cytogenetic characterisation of a newly recognised microdeletion syndrome involving 2p15-16.1.

Authors:  E Rajcan-Separovic; C Harvard; X Liu; B McGillivray; J G Hall; Y Qiao; J Hurlburt; J Hildebrand; E C R Mickelson; J J A Holden; M E S Lewis
Journal:  J Med Genet       Date:  2006-09-08       Impact factor: 6.318

6.  Development and clinical application of an innovative fluorescence in situ hybridization technique which detects submicroscopic rearrangements involving telomeres.

Authors:  S J Knight; S W Horsley; R Regan; N M Lawrie; E J Maher; D L Cardy; J Flint; L Kearney
Journal:  Eur J Hum Genet       Date:  1997 Jan-Feb       Impact factor: 4.246

7.  Mutations in genes encoding fast-twitch contractile proteins cause distal arthrogryposis syndromes.

Authors:  Sandy S Sung; Anna-Marie E Brassington; Kathryn Grannatt; Ann Rutherford; Frank G Whitby; Patrycja A Krakowiak; Lynn B Jorde; John C Carey; Mike Bamshad
Journal:  Am J Hum Genet       Date:  2003-03       Impact factor: 11.025

8.  Emerging patterns of cryptic chromosomal imbalance in patients with idiopathic mental retardation and multiple congenital anomalies: a new series of 140 patients and review of published reports.

Authors:  B Menten; N Maas; B Thienpont; K Buysse; J Vandesompele; C Melotte; T de Ravel; S Van Vooren; I Balikova; L Backx; S Janssens; A De Paepe; B De Moor; Y Moreau; P Marynen; J-P Fryns; G Mortier; K Devriendt; F Speleman; J R Vermeesch
Journal:  J Med Genet       Date:  2006-02-20       Impact factor: 6.318

9.  Microarray based comparative genomic hybridisation (array-CGH) detects submicroscopic chromosomal deletions and duplications in patients with learning disability/mental retardation and dysmorphic features.

Authors:  C Shaw-Smith; R Redon; L Rickman; M Rio; L Willatt; H Fiegler; H Firth; D Sanlaville; R Winter; L Colleaux; M Bobrow; N P Carter
Journal:  J Med Genet       Date:  2004-04       Impact factor: 6.318

10.  Array-based comparative genomic hybridization for the genomewide detection of submicroscopic chromosomal abnormalities.

Authors:  Lisenka E L M Vissers; Bert B A de Vries; Kazutoyo Osoegawa; Irene M Janssen; Ton Feuth; Chik On Choy; Huub Straatman; Walter van der Vliet; Erik H L P G Huys; Anke van Rijk; Dominique Smeets; Conny M A van Ravenswaaij-Arts; Nine V Knoers; Ineke van der Burgt; Pieter J de Jong; Han G Brunner; Ad Geurts van Kessel; Eric F P M Schoenmakers; Joris A Veltman
Journal:  Am J Hum Genet       Date:  2003-11-18       Impact factor: 11.025

View more
  10 in total

1.  2p15-p16.1 microdeletion syndrome: molecular characterization and association of the OTX1 and XPO1 genes with autism spectrum disorders.

Authors:  Xudong Liu; Patrick Malenfant; Chelsea Reesor; Alana Lee; Melissa L Hudson; Chansonette Harvard; Ying Qiao; Antonio M Persico; Ira L Cohen; Albert E Chudley; Cynthia Forster-Gibson; Evica Rajcan-Separovic; M E Suzanne Lewis; Jeanette J A Holden
Journal:  Eur J Hum Genet       Date:  2011-07-13       Impact factor: 4.246

2.  Identifying candidate genes for 2p15p16.1 microdeletion syndrome using clinical, genomic, and functional analysis.

Authors:  Hani Bagheri; Chansonette Badduke; Ying Qiao; Rita Colnaghi; Iga Abramowicz; Diana Alcantara; Christopher Dunham; Jiadi Wen; Robert S Wildin; Malgorzata Jm Nowaczyk; Jennifer Eichmeyer; Anna Lehman; Bruno Maranda; Sally Martell; Xianghong Shan; Suzanne Me Lewis; Mark O'Driscoll; Cheryl Y Gregory-Evans; Evica Rajcan-Separovic
Journal:  JCI Insight       Date:  2016-03-17

3.  De novo 2p16.1 microdeletion with metastatic esophageal adenocarcinoma.

Authors:  Don Chamil Codipilly; Ralitza H Gavrilova; Eric G Tangalos
Journal:  BMJ Case Rep       Date:  2017-01-20

4.  Chromosomal contacts connect loci associated with autism, BMI and head circumference phenotypes.

Authors:  M N Loviglio; M Leleu; K Männik; M Passeggeri; G Giannuzzi; I van der Werf; S M Waszak; M Zazhytska; I Roberts-Caldeira; N Gheldof; E Migliavacca; A A Alfaiz; L Hippolyte; A M Maillard; A Van Dijck; R F Kooy; D Sanlaville; J A Rosenfeld; L G Shaffer; J Andrieux; C Marshall; S W Scherer; Y Shen; J F Gusella; U Thorsteinsdottir; G Thorleifsson; E T Dermitzakis; B Deplancke; J S Beckmann; J Rougemont; S Jacquemont; A Reymond
Journal:  Mol Psychiatry       Date:  2016-05-31       Impact factor: 15.992

5.  Haploinsufficiency of BCL11A associated with cerebellar abnormalities in 2p15p16.1 deletion syndrome.

Authors:  Hiroko Shimbo; Takayuki Yokoi; Noriko Aida; Seiji Mizuno; Hiroshi Suzumura; Junichi Nagai; Kazumi Ida; Yumi Enomoto; Chihiro Hatano; Kenji Kurosawa
Journal:  Mol Genet Genomic Med       Date:  2017-05-22       Impact factor: 2.183

6.  Genitourinary defects associated with genomic deletions in 2p15 encompassing OTX1.

Authors:  Carolina J Jorgez; Jill A Rosenfeld; Nathan R Wilken; Hima V Vangapandu; Aysegul Sahin; Dung Pham; Claudia M B Carvalho; Anne Bandholz; Amanda Miller; David D Weaver; Barbara Burton; Deepti Babu; John S Bamforth; Timothy Wilks; Daniel P Flynn; Elizabeth Roeder; Ankita Patel; Sau W Cheung; James R Lupski; Dolores J Lamb
Journal:  PLoS One       Date:  2014-09-09       Impact factor: 3.240

7.  Genetic Candidate Variants in Two Multigenerational Families with Childhood Apraxia of Speech.

Authors:  Beate Peter; Ellen M Wijsman; Alejandro Q Nato; Mark M Matsushita; Kathy L Chapman; Ian B Stanaway; John Wolff; Kaori Oda; Virginia B Gabo; Wendy H Raskind
Journal:  PLoS One       Date:  2016-04-27       Impact factor: 3.240

8.  BCL11A Haploinsufficiency Causes an Intellectual Disability Syndrome and Dysregulates Transcription.

Authors:  Cristina Dias; Sara B Estruch; Sarah A Graham; Jeremy McRae; Stephen J Sawiak; Jane A Hurst; Shelagh K Joss; Susan E Holder; Jenny E V Morton; Claire Turner; Julien Thevenon; Kelly Mellul; Gabriela Sánchez-Andrade; Ximena Ibarra-Soria; Pelagia Deriziotis; Rui F Santos; Song-Choon Lee; Laurence Faivre; Tjitske Kleefstra; Pentao Liu; Mathew E Hurles; Simon E Fisher; Darren W Logan
Journal:  Am J Hum Genet       Date:  2016-07-21       Impact factor: 11.025

9.  BCL11A frameshift mutation associated with dyspraxia and hypotonia affecting the fine, gross, oral, and speech motor systems.

Authors:  Julie Soblet; Ivan Dimov; Clemens Graf von Kalckreuth; Julie Cano-Chervel; Simon Baijot; Karin Pelc; Martine Sottiaux; Catheline Vilain; Guillaume Smits; Nicolas Deconinck
Journal:  Am J Med Genet A       Date:  2017-09-27       Impact factor: 2.802

10.  Microduplication in the 2p16.1p15 chromosomal region linked to developmental delay and intellectual disability.

Authors:  Luca Lovrecic; Chiara Gnan; Federica Baldan; Alessandra Franzoni; Sara Bertok; Giuseppe Damante; Bertrand Isidor; Borut Peterlin
Journal:  Mol Cytogenet       Date:  2018-06-20       Impact factor: 2.009

  10 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.