Literature DB >> 20217239

Identification of a recurrent insertion mutation in the LDLR gene in a Pakistani family with autosomal dominant hypercholesterolemia.

Muhammad Ajmal1, Waqas Ahmed, Ahmed Sadeque, Syeda Hafiza Benish Ali, Syed Habib Bokhari, Nuzhat Ahmed, Raheel Qamar.   

Abstract

Familial Hypercholesterolemia (FH) results in elevated levels of blood lipids including total cholesterol (TC) and low density lipoprotein cholesterol (LDL-C) with normal triglycerides (TG). This disease is one of the major contributors towards an early onset of coronary heart disease (CHD). The aim of the present study was to identify the genes responsible for causing FH in Pakistani population, for this purpose a large consanguineous FH family was selected for genetic analysis. Serum lipid levels, including TC, TG, LDL-C and high density lipoprotein cholesterol (HDL-C), were determined in patients and healthy controls. In order to find the causative mutation in this family, direct sequencing of the low density lipoprotein receptor (LDLR) gene was performed. In addition the part of the Apolipoprotein-B (APOB) gene containing the mutations R3500Q and R3500W was also sequenced. Affected individuals of the family were found to have raised TC and LDL-C levels. Sequencing revealed an insertion mutation (c.2416_2417InsG) in exon 17 of the LDLR gene in all the affected individuals of the family. Common FH causing APOB mutations were not present in this family. Heterozygous individuals had TC levels ranging from ~300-500 mg/dl and the only homozygous individual with typical xanthomas had TC levels exceeding 900 mg/dl. This is the first report of a known LDLR gene mutation causing FH in the Pakistani population. Despite a large heterogeneity of LDLR mutations there are still some common mutations which are responsible for FH throughout the world.

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Year:  2010        PMID: 20217239     DOI: 10.1007/s11033-010-0043-0

Source DB:  PubMed          Journal:  Mol Biol Rep        ISSN: 0301-4851            Impact factor:   2.316


  36 in total

Review 1.  The LDL receptor locus in familial hypercholesterolemia: mutational analysis of a membrane protein.

Authors:  H H Hobbs; D W Russell; M S Brown; J L Goldstein
Journal:  Annu Rev Genet       Date:  1990       Impact factor: 16.830

Review 2.  Mechanisms for cellular cholesterol transport: defects and human disease.

Authors:  Elina Ikonen
Journal:  Physiol Rev       Date:  2006-10       Impact factor: 37.312

3.  The molecular basis of familial hypercholesterolemia in The Netherlands.

Authors:  S W Fouchier; J C Defesche; M W Umans-Eckenhausen; J P Kastelein
Journal:  Hum Genet       Date:  2001-11-09       Impact factor: 4.132

Review 4.  A receptor-mediated pathway for cholesterol homeostasis.

Authors:  M S Brown; J L Goldstein
Journal:  Science       Date:  1986-04-04       Impact factor: 47.728

Review 5.  Receptor-mediated endocytosis: concepts emerging from the LDL receptor system.

Authors:  J L Goldstein; M S Brown; R G Anderson; D W Russell; W J Schneider
Journal:  Annu Rev Cell Biol       Date:  1985

6.  The modular adaptor protein autosomal recessive hypercholesterolemia (ARH) promotes low density lipoprotein receptor clustering into clathrin-coated pits.

Authors:  Rita Garuti; Christopher Jones; Wei-Ping Li; Peter Michaely; Joachim Herz; Robert D Gerard; Jonathan C Cohen; Helen H Hobbs
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Authors:  Shazia A Bukhari; Muhammad I Rajoka; Saeed A Nagra; Zia Ur Rehman
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8.  The adaptor protein Dab2 sorts LDL receptors into coated pits independently of AP-2 and ARH.

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9.  A novel splice site mutation of the LDL receptor gene in a Tunisian hypercholesterolemic family.

Authors:  A Jelassi; M Najah; I Jguirim; F Maatouk; S Lestavel; O S Laroussi; M Rouis; C Boileau; J P Rabès; M Varret; M N Slimane
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10.  LDLR promoter variant and exon 14 mutation on the same chromosome are associated with an unusually severe FH phenotype and treatment resistance.

Authors:  Christine L H Snozek; Susan A Lagerstedt; Teck K Khoo; Melvyn Rubenfire; William L Isley; Laura J Train; Linnea M Baudhuin
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