Literature DB >> 19473361

Prevalence and clinical features of LRRK2 mutations in patients with Parkinson's disease in southern Spain.

L Gao1, P Gómez-Garre, F J Díaz-Corrales, F Carrillo, M Carballo, A Palomino, J Díaz-Martín, R Mejías, P J Vime, J López-Barneo, P Mir.   

Abstract

BACKGROUND AND
PURPOSE: Mutations in leucine-rich repeat kinase 2 (LRRK2) gene are associated with both familial and idiopathic Parkinson's disease (PD), whereas mutations in PARK2 (PARKIN) gene result in early onset recessive PD. Here, the objectives were to determine the frequency of LRRK2 G2019S and R1441G mutations in a PD population from southern Spain; to search for LRRK2 mutations in familial PD cases and to study the effect of PARKIN mutations on clinical features of LRRK2-associated; PD.
METHODS: We included 187 PD patients (172 idiopathic, 15 familial) and 287 control subjects from southern Spain. LRRK2 and PARKIN mutations were screened, and clinical features of LRRK2-associated PD were examined.
RESULTS: Three (1.7%) idiopathic PD patients carried the G2019S, whereas another three (1.7%) had the R1441G. A novel polymorphism D1420N was found in two (13.3%) familial PD patients. One G2019S carrier also had a homozygous PARKIN deletion, who had early onset PD with clinical symptoms similar to those with PARKIN-associated PD. The remaining LRRK2-asscociated patients had clinical manifestations similar to those with idiopathic PD.
CONCLUSIONS: G2019S and R1441G are common LRRK2 mutations in PD patients in this region. PARKIN mutations override clinical features in LRRK2-associated PD.

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Year:  2009        PMID: 19473361     DOI: 10.1111/j.1468-1331.2009.02620.x

Source DB:  PubMed          Journal:  Eur J Neurol        ISSN: 1351-5101            Impact factor:   6.089


  13 in total

Review 1.  The LRRK2 G2019S mutation as the cause of Parkinson's disease in Ashkenazi Jews.

Authors:  Avner Thaler; Elissa Ash; Ziv Gan-Or; Avi Orr-Urtreger; Nir Giladi
Journal:  J Neural Transm (Vienna)       Date:  2009-11       Impact factor: 3.575

2.  Disclosure of research results in genetic studies of Parkinson's disease caused by LRRK2 mutations.

Authors:  Claustre Pont-Sunyer; Susan Bressman; Deborah Raymond; Amanda Glickman; Eduardo Tolosa; Rachel Saunders-Pullman
Journal:  Mov Disord       Date:  2015-05-07       Impact factor: 10.338

3.  Type II kinase inhibitors show an unexpected inhibition mode against Parkinson's disease-linked LRRK2 mutant G2019S.

Authors:  Min Liu; Samantha A Bender; Gregory D Cuny; Woody Sherman; Marcie Glicksman; Soumya S Ray
Journal:  Biochemistry       Date:  2013-03-01       Impact factor: 3.162

Review 4.  Genetic etiology of Parkinson disease associated with mutations in the SNCA, PARK2, PINK1, PARK7, and LRRK2 genes: a mutation update.

Authors:  Karen Nuytemans; Jessie Theuns; Marc Cruts; Christine Van Broeckhoven
Journal:  Hum Mutat       Date:  2010-07       Impact factor: 4.878

5.  Variable frequency of LRRK2 variants in the Latin American research consortium on the genetics of Parkinson's disease (LARGE-PD), a case of ancestry.

Authors:  Mario Cornejo-Olivas; Luis Torres; Mario R Velit-Salazar; Miguel Inca-Martinez; Pilar Mazzetti; Carlos Cosentino; Federico Micheli; Claudia Perandones; Elena Dieguez; Victor Raggio; Vitor Tumas; Vanderci Borges; Henrique B Ferraz; Carlos R M Rieder; Artur Shumacher-Schuh; Carlos Velez-Pardo; Marlene Jimenez-Del-Rio; Francisco Lopera; Jorge Chang-Castello; Brennie Andreé-Munoz; Sarah Waldherr; Dora Yearout; Cyrus P Zabetian; Ignacio F Mata
Journal:  NPJ Parkinsons Dis       Date:  2017-06-02

Review 6.  Modelling Parkinson's Disease: iPSCs towards Better Understanding of Human Pathology.

Authors:  Sahar Avazzadeh; Jara Maria Baena; Cameron Keighron; Yajaira Feller-Sanchez; Leo R Quinlan
Journal:  Brain Sci       Date:  2021-03-14

7.  The Genetic Architecture of Parkinson Disease in Spain: Characterizing Population-Specific Risk, Differential Haplotype Structures, and Providing Etiologic Insight.

Authors:  Sara Bandres-Ciga; Sarah Ahmed; Marya S Sabir; Cornelis Blauwendraat; Astrid D Adarmes-Gómez; Inmaculada Bernal-Bernal; Marta Bonilla-Toribio; Dolores Buiza-Rueda; Fátima Carrillo; Mario Carrión-Claro; Pilar Gómez-Garre; Silvia Jesús; Miguel A Labrador-Espinosa; Daniel Macias; Carlota Méndez-Del-Barrio; Teresa Periñán-Tocino; Cristina Tejera-Parrado; Laura Vargas-González; Monica Diez-Fairen; Ignacio Alvarez; Juan Pablo Tartari; Mariateresa Buongiorno; Miquel Aguilar; Ana Gorostidi; Jesús Alberto Bergareche; Elisabet Mondragon; Ana Vinagre-Aragon; Ioana Croitoru; Javier Ruiz-Martínez; Oriol Dols-Icardo; Jaime Kulisevsky; Juan Marín-Lahoz; Javier Pagonabarraga; Berta Pascual-Sedano; Mario Ezquerra; Ana Cámara; Yaroslau Compta; Manel Fernández; Rubén Fernández-Santiago; Esteban Muñoz; Eduard Tolosa; Francesc Valldeoriola; Isabel Gonzalez-Aramburu; Antonio Sanchez Rodriguez; María Sierra; Manuel Menéndez-González; Marta Blazquez; Ciara Garcia; Esther Suarez-San Martin; Pedro García-Ruiz; Juan Carlos Martínez-Castrillo; Lydia Vela-Desojo; Clara Ruz; Francisco Javier Barrero; Francisco Escamilla-Sevilla; Adolfo Mínguez-Castellanos; Debora Cerdan; Cesar Tabernero; Maria Jose Gomez Heredia; Francisco Perez Errazquin; Manolo Romero-Acebal; Cici Feliz; Jose Luis Lopez-Sendon; Marina Mata; Irene Martínez Torres; Jonggeol Jeffrey Kim; Clifton L Dalgard; Janet Brooks; Sara Saez-Atienzar; J Raphael Gibbs; Rafael Jorda; Juan A Botia; Luis Bonet-Ponce; Karen E Morrison; Carl Clarke; Manuela Tan; Huw Morris; Connor Edsall; Dena Hernandez; Javier Simon-Sanchez; Mike A Nalls; Sonja W Scholz; Adriano Jimenez-Escrig; Jacinto Duarte; Francisco Vives; Raquel Duran; Janet Hoenicka; Victoria Alvarez; Jon Infante; Maria José Marti; Jordi Clarimón; Adolfo López de Munain; Pau Pastor; Pablo Mir; Andrew Singleton
Journal:  Mov Disord       Date:  2019-10-29       Impact factor: 10.338

8.  Serum lipid profile among sporadic and familial forms of Parkinson's disease.

Authors:  Daniel Macías-García; María Teresa Periñán; Laura Muñoz-Delgado; María Valle Jimenez-Jaraba; Miguel Ángel Labrador-Espinosa; Silvia Jesús; Dolores Buiza-Rueda; Carlota Méndez-Del Barrio; Astrid Adarmes-Gómez; Pilar Gómez-Garre; Pablo Mir
Journal:  NPJ Parkinsons Dis       Date:  2021-07-16

Review 9.  LRRK 2 gene mutations in the pathophysiology of the ROCO domain and therapeutic targets for Parkinson's disease: a review.

Authors:  Meng-Ling Chen; Ruey-Meei Wu
Journal:  J Biomed Sci       Date:  2018-06-14       Impact factor: 8.410

Review 10.  Genetic perspective on the synergistic connection between vesicular transport, lysosomal and mitochondrial pathways associated with Parkinson's disease pathogenesis.

Authors:  Stefanie Smolders; Christine Van Broeckhoven
Journal:  Acta Neuropathol Commun       Date:  2020-05-06       Impact factor: 7.801

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