Literature DB >> 18548272

An unusual cause of gastric perforation in childhood: trichobezoar (Rapunzel syndrome). A case report.

Orhan Koç1, Fesih Doğan Yildiz, Adnan Narci, Tolga Altuğ Sen.   

Abstract

Trichobezoars are hair balls found in the stomach and formed following trichitillomania and trichopaghia. Rapunzel syndrome is a rare condition in which the presence of giant trichobezoars causes mechanical obstruction. To date, only two cases of stomach perforation caused by trichobezoars have been reported among pediatric patients. We report a 14-year-old female patient who experienced nausea, vomiting and severe abdominal pain for 1 month. Physical examination revealed diffuse abdominal distension. Palpation detected a mobile and sensitive mass, 15 x 15 cm , which filled the upper quadrant. Urgent surgery revealed that the stomach was perforated by the trichobezoar ball. This trichobezoar mass was totally excised by expanding the perforation area. Conclusion This is the reported third case of gastric perforation caused by trichobezoar in a pediatric patient. Among acute abdominal cases, gastric perforation should remain a possibility in differential diagnosis.

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Year:  2008        PMID: 18548272     DOI: 10.1007/s00431-008-0773-3

Source DB:  PubMed          Journal:  Eur J Pediatr        ISSN: 0340-6199            Impact factor:   3.183


  14 in total

1.  An unusual cause of gastrointestinal obstruction: bezoar.

Authors:  Tanju Acar; Salih Tuncal; Raci Aydin
Journal:  N Z Med J       Date:  2003-05-02

2.  Index of suspicion. Case 3. Diagnosis: trichobezoar.

Authors:  F E Babl; J S Hyams; C J Justinich
Journal:  Pediatr Rev       Date:  1996-03

3.  The Rapunzel syndrome: an unusual trichobezoar.

Authors:  P J Wolfson; R J Fabius; A N Leibowitz
Journal:  Am J Gastroenterol       Date:  1987-04       Impact factor: 10.864

Review 4.  The Rapunzel syndrome (trichobezoar) causing atypical intussusception in a child: a case report.

Authors:  G B Dalshaug; S Wainer; G L Hollaar
Journal:  J Pediatr Surg       Date:  1999-03       Impact factor: 2.545

5.  An unusual case of the trichobezoar: the Rapunzel syndrome.

Authors:  J P Deslypere; M Praet; G Verdonk
Journal:  Am J Gastroenterol       Date:  1982-07       Impact factor: 10.864

Review 6.  Characterization of trichotillomania. A phenomenological model with clinical relevance to obsessive-compulsive spectrum disorders.

Authors:  R L O'Sullivan; C S Mansueto; E A Lerner; E C Miguel
Journal:  Psychiatr Clin North Am       Date:  2000-09

7.  The Rapunzel syndrome (trichobezoar) causing gastric perforation in a child: a case report.

Authors:  N Pul; M Pul
Journal:  Eur J Pediatr       Date:  1996-01       Impact factor: 3.183

8.  Rapunzel syndrome with a fatal outcome in a neglected child.

Authors:  Denise Estefan Ventura; Fernando A Mardiros Herbella; Sergio T Schettini; Carlos Delmonte
Journal:  J Pediatr Surg       Date:  2005-10       Impact factor: 2.545

Review 9.  Rapunzel syndrome reviewed and redefined.

Authors:  Saleem Naik; Vivek Gupta; Swati Naik; Ashwin Rangole; Ashok K Chaudhary; Prashant Jain; Ashok K Sharma
Journal:  Dig Surg       Date:  2007-04-27       Impact factor: 2.588

10.  Cotton Bezoar--a rare cause of intestinal obstruction: case report.

Authors:  Rakesh Durkhure; J P Singh; Vinay Singhal
Journal:  BMC Surg       Date:  2003-09-04       Impact factor: 2.102

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  8 in total

1.  Successful endoscopic resolution of a large gastric bezoar in a child.

Authors:  Sara Azevedo; João Lopes; António Marques; Paula Mourato; Lucília Freitas; Ana Isabel Lopes
Journal:  World J Gastrointest Endosc       Date:  2011-06-16

2.  A novel finding of Rapunzel syndrome.

Authors:  Itaru Iwama; Ryusuke Nambu; Tomoko Hara
Journal:  Clin J Gastroenterol       Date:  2017-10-24

3.  The rapunzel syndrome: an unusual trichobezoar presentation.

Authors:  Luiz Roberto Lopes; Priscilla Sene Portel Oliveira; Eduardo Marcucci Pracucho; Marcelo Amade Camargo; João de Souza Coelho Neto; Nelson Adami Andreollo
Journal:  Case Rep Med       Date:  2010-03-24

4.  Rapunzel syndrome: a rare cause of hypoproteinaemia and review of literature.

Authors:  Waqas Ullah; Kaiser Saleem; Ejaz Ahmad; Faiz Anwer
Journal:  BMJ Case Rep       Date:  2016-09-26

5.  Rapunzel syndrome: a rare postpartum case.

Authors:  Teshome Tegene; Yahia Foda; Omar Hussain; Kolawole Oloniyo; Ngoc-Tram Ha; Geeta Manikonda
Journal:  Case Rep Gastrointest Med       Date:  2013-09-19

6.  Endoscopic retrieval of gastric trichophytobezoar: Case report of a 12-year-old girl with trichophagia.

Authors:  Jiu-Ling Zhao; Wei-Chuan Zhao; Yu-Shui Wang
Journal:  Medicine (Baltimore)       Date:  2017-01       Impact factor: 1.889

7.  Rapunzel syndrome: how to orient the diagnosis.

Authors:  Enrico Finale; Piergiorgio Franceschini; Cesare Danesino; Michelangelo Barbaglia; Andrea Guala
Journal:  Pediatr Rep       Date:  2018-06-27

8.  Rapunzel Syndrome-An Extremely Rare Cause of Digestive Symptoms in Children: A Case Report and a Review of the Literature.

Authors:  Cristina Oana Marginean; Lorena Elena Melit; Maria Oana Sasaran; Razvan Marginean; Zoltan Derzsi
Journal:  Front Pediatr       Date:  2021-06-09       Impact factor: 3.418

  8 in total

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