Literature DB >> 1828234

Griscelli disease with cerebral involvement.

A Haraldsson1, C M Weemaes, J A Bakkeren, R Happle.   

Abstract

A 9-month-old Turkish boy was diagnosed as having Griscelli disease (Chediak-Higashi-like syndrome). Clinical signs consisted of silver-grey hair and a relatively light skin colour, recurrent episodes of fever, with or without detectable infections, increasing hepatosplenomegaly, hypotonia and motor retardation. Laboratory studies showed pancytopenia of varying degree but neither inclusion bodies nor vacuoles were seen in his leucocytes. Serum immunoglobulin levels were normal except for a IgG2 deficiency. In the mixed lymphocyte reaction the stimulation capacity of the leucocytes was decreased. Microscopic examination of his hair and electron-microscopic examination of a skin biopsy further confirmed the diagnosis. Shortly before the diagnosis was made, the child developed cerebral symptoms with hemiparesis and convulsions. A CT scan suggested cell infiltration of the brain. A few weeks later the boy died of an infection.

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Year:  1991        PMID: 1828234     DOI: 10.1007/bf02093723

Source DB:  PubMed          Journal:  Eur J Pediatr        ISSN: 0340-6199            Impact factor:   3.183


  21 in total

1.  Protection of phagocytic leukocytes by endogenous glutathione: studies in a family with glutathione reductase deficiency.

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5.  Effect of ascorbate on abnormal neutrophil, platelet and lymphocytic function in a patient with the Chediak-Higashi syndrome.

Authors:  R S Weening; E P Schoorel; D Roos; M L van Schaik; A A Voetman; A A Bot; A M Batenburg-Plenter; C Willems; W P Zeijlemaker; A Astaldi
Journal:  Blood       Date:  1981-05       Impact factor: 22.113

Review 6.  The clinical pharmacology of VM26 and VP16-213. A brief overview.

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Journal:  Cancer Chemother Pharmacol       Date:  1982       Impact factor: 3.333

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Journal:  Ann Dermatol Venereol       Date:  1981       Impact factor: 0.777

8.  Successful treatment of lymphohistiocytic reticulosis with phagocytosis with epipodophyllotoxin VP 16-213.

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Journal:  Cancer       Date:  1980-05-15       Impact factor: 6.860

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Journal:  Anal Biochem       Date:  1985-05-15       Impact factor: 3.365

10.  Distinct features of dendritic cells and anti-Ig activated B cells as stimulators of the primary mixed leukocyte reaction.

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Journal:  J Exp Med       Date:  1989-01-01       Impact factor: 14.307

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  8 in total

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Authors:  J D Huang; V Mermall; M C Strobel; L B Russell; M S Mooseker; N G Copeland; N A Jenkins
Journal:  Genetics       Date:  1998-04       Impact factor: 4.562

2.  Rab18 Collaborates with Rab7 to Modulate Lysosomal and Autophagy Activities in the Nervous System: an Overlapping Mechanism for Warburg Micro Syndrome and Charcot-Marie-Tooth Neuropathy Type 2B.

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Journal:  Mol Neurobiol       Date:  2019-02-05       Impact factor: 5.590

3.  Griscelli disease: genotype-phenotype correlation in an array of clinical heterogeneity.

Authors:  Ozden Sanal; Fúgen Ersoy; Ilhan Tezcan; Ayşe Metin; Leman Yel; Gaël Ménasché; Aytemiz Gürgey; Izzet Berkel; Geneviève de Saint Basile
Journal:  J Clin Immunol       Date:  2002-07       Impact factor: 8.317

4.  Griscelli syndrome.

Authors:  Sanjeev Rath; Vivek Jain; R K Marwaha; Amita Trehan; L S Rajesh; Vijay Kumar
Journal:  Indian J Pediatr       Date:  2004-02       Impact factor: 1.967

5.  A kindred with Griscelli disease: spectrum of neurological involvement.

Authors:  H Hurvitz; R Gillis; S Klaus; A Klar; F Gross-Kieselstein; E Okon
Journal:  Eur J Pediatr       Date:  1993-05       Impact factor: 3.183

6.  Griscelli syndrome: characterization of a new mutation and rescue of T-cytotoxic activity by retroviral transfer of RAB27A gene.

Authors:  João C S Bizario; Jérôme Feldmann; Fabíola A Castro; Gaël Ménasché; Cristina M A Jacob; L Cristofani; Erasmo B Casella; Júlio C Voltarelli; Geneviève de Saint-Basile; Enilza M Espreafico
Journal:  J Clin Immunol       Date:  2004-07       Impact factor: 8.317

7.  The role of the COOH terminus of Sec2p in the transport of post-Golgi vesicles.

Authors:  N B Elkind; C Walch-Solimena; P J Novick
Journal:  J Cell Biol       Date:  2000-04-03       Impact factor: 10.539

8.  Rab27a: A key to melanosome transport in human melanocytes.

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Journal:  J Cell Biol       Date:  2001-02-19       Impact factor: 10.539

  8 in total

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