Literature DB >> 17427031

Mutation analysis and genotype/phenotype relationships of Gaucher disease patients in Spain.

Pilar Alfonso1,2, Sofía Aznarez3,4, Manuel Giralt5, Miguel Pocovi3,4, Pilar Giraldo4,5.   

Abstract

Mutations in the glucocerebrosidase (GBA) gene cause Gaucher disease (GD). The aim of this study was to characterise the GBA mutations and analyze genotype/phenotype relationships in 193 unrelated patients from the Spanish GD Registry. We have identified 98.7% of the mutated GBA alleles, finding 56 different GBA mutations and 66 genotypes causing GD in Spain: 47 previously described mutations and 9 novel mutations (4 missense R395C, R463H, W312R and V398I, 1 nonsense R359X, 4 frameshift c.708delC, c.1214-1215delGC, c.1439-1445del7 and c.42-65del24). The most prevalent mutations were N370S and L444P, accounting for 68.7% of the mutated alleles. A wide phenotypic difference was observed within each genotypic group, and 9% of diagnosed type 1 patients developed neurological involvement including parkisonism, tremor, hypoacusia and eye movements. All of these findings indicate that there is a significant genotypic heterogeneity that explains the huge phenotypic variation among Spanish GD patients.

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Year:  2007        PMID: 17427031     DOI: 10.1007/s10038-007-0135-4

Source DB:  PubMed          Journal:  J Hum Genet        ISSN: 1434-5161            Impact factor:   3.172


  16 in total

Review 1.  The pathophysiology of GD - current understanding and rationale for existing and emerging therapeutic approaches.

Authors:  Derralynn A Hughes; Gregory M Pastores
Journal:  Wien Med Wochenschr       Date:  2010-12

2.  Novel mutations in the glucocerebrosidase gene of brazilian patients with Gaucher disease.

Authors:  Marina Siebert; Hugo Bock; Kristiane Michelin-Tirelli; Janice C Coelho; Roberto Giugliani; Maria Luiza Saraiva-Pereira
Journal:  JIMD Rep       Date:  2012-10-09

3.  Neurological manifestations in patients with Gaucher disease and their relatives, it is just a coincidence?

Authors:  Pilar Giraldo; Jose Luis Capablo; Pilar Alfonso; Beatriz Garcia-Rodriguez; Paz Latre; Pilar Irun; Alicia Saenz de Cabezon; Miguel Pocovi
Journal:  J Inherit Metab Dis       Date:  2011-03-08       Impact factor: 4.982

4.  A rare cause of hydrops fetalis in two Gaucher disease type 2 patients with a novel mutation.

Authors:  Sebile Kılavuz; Murat Basaranoglu; Serdar Epcacan; Derya Bako; Arife Ozer; Yasemin Nuran Donmez; Emine Ipek Ceylan; Ajlan Tukun; Serdar Ceylaner; Hadi Geylani; Halise Neslihan Onenli Mungan
Journal:  Metab Brain Dis       Date:  2022-03-07       Impact factor: 3.584

5.  Novel mutations in the glucocerebrosidase gene of Indian patients with Gaucher disease.

Authors:  Chitra Ankleshwaria; Mehul Mistri; Ashish Bavdekar; Mamta Muranjan; Usha Dave; Parag Tamhankar; Varun Khanna; Eresha Jasinge; Sheela Nampoothiri; Suresh Edayankara Kadangot; Frenny Sheth; Sarita Gupta; Jayesh Sheth
Journal:  J Hum Genet       Date:  2014-02-13       Impact factor: 3.172

Review 6.  Gaucher disease: new developments in treatment and etiology.

Authors:  Ozgur Harmanci; Yusuf Bayraktar
Journal:  World J Gastroenterol       Date:  2008-07-07       Impact factor: 5.742

7.  Novel pathogenic mutations in the glucocerebrosidase locus.

Authors:  Raquel Duran; Alisdair McNeill; Atul Mehta; Derralyn Hughes; Timothy Cox; Patrick Deegan; Anthony H V Schapira; John Hardy
Journal:  Mol Genet Metab       Date:  2012-05-18       Impact factor: 4.797

8.  Parkinsonism associated with glucocerebrosidase mutation.

Authors:  Mun-Kyung Sunwoo; Seung-Min Kim; Sarah Lee; Phil Hyu Lee
Journal:  J Clin Neurol       Date:  2011-06-28       Impact factor: 3.077

9.  Mapping the genetic and clinical characteristics of Gaucher disease in the Iberian Peninsula.

Authors:  Pilar Giraldo; Pilar Alfonso; Pilar Irún; Laura Gort; Amparo Chabás; Lluïsa Vilageliu; Daniel Grinberg; Clara M Sá Miranda; Miguel Pocovi
Journal:  Orphanet J Rare Dis       Date:  2012-03-19       Impact factor: 4.123

10.  Functional and genetic characterization of the non-lysosomal glucosylceramidase 2 as a modifier for Gaucher disease.

Authors:  Yildiz Yildiz; Per Hoffmann; Stefan Vom Dahl; Bernadette Breiden; Roger Sandhoff; Claus Niederau; Mia Horwitz; Stefan Karlsson; Mirella Filocamo; Deborah Elstein; Michael Beck; Konrad Sandhoff; Eugen Mengel; Maria C Gonzalez; Markus M Nöthen; Ellen Sidransky; Ari Zimran; Manuel Mattheisen
Journal:  Orphanet J Rare Dis       Date:  2013-09-26       Impact factor: 4.123

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