Literature DB >> 17004069

[Hearing loss in patients with Fabry disease].

A Limberger1, M Beck, S Delgado-Sanchez, A Keilmann.   

Abstract

BACKGROUND: Fabry disease is an X-linked lysosomal storage disease involving deficient activity of alpha-galactosidase A, which leads initially to pain, and later to renal insufficiency, cardiomyopathy and stroke. Until now few details are available on hearing impairment in patients with Fabry disease, and especially few relating to female patients. PATIENTS AND METHODS: We examined 43 female and 29 male patients. In this study we looked into the question of whether and to what extent patients of both genders are affected by hearing impairment.
RESULTS: Hearing loss is characteristic being more severe at high frequencies frequencies. Overall, 22 female and 15 male patients were found to have suffered a hearing loss. Patients with severe symptoms of Fabry disease usually demonstrate more prominent hearing losses.
CONCLUSIONS: Both men and women with Fabry disease are affected by hearing impairment. It seems that the hearing loss is less marked in female than in male patients. Children with Fabry disease complain of tinnitus more frequently than other children and quite early in the course of the disease.

Entities:  

Mesh:

Year:  2007        PMID: 17004069     DOI: 10.1007/s00106-006-1454-z

Source DB:  PubMed          Journal:  HNO        ISSN: 0017-6192            Impact factor:   1.284


  9 in total

1.  Hearing evaluation with distortion-product otoacoustic emissions in young patients undergoing haemodialysis.

Authors:  P Stavroulaki; T P Nikolopoulos; I Psarommatis; N Apostolopoulos
Journal:  Clin Otolaryngol Allied Sci       Date:  2001-06

2.  Otologic histopathology of Fabry's disease.

Authors:  P A Schachern; D A Shea; M M Paparella; T H Yoon
Journal:  Ann Otol Rhinol Laryngol       Date:  1989-05       Impact factor: 1.547

3.  Anderson-Fabry disease: clinical manifestations and impact of disease in a cohort of 98 hemizygous males.

Authors:  K D MacDermot; A Holmes; A H Miners
Journal:  J Med Genet       Date:  2001-11       Impact factor: 6.318

4.  The molecular defect leading to Fabry disease: structure of human alpha-galactosidase.

Authors:  Scott C Garman; David N Garboczi
Journal:  J Mol Biol       Date:  2004-03-19       Impact factor: 5.469

5.  Hearing loss in Fabry disease: the effect of agalsidase alfa replacement therapy.

Authors:  D Hajioff; Y Enever; R Quiney; J Zuckerman; K Mackermot; A Mehta
Journal:  J Inherit Metab Dis       Date:  2003       Impact factor: 4.982

6.  Fabry disease defined: baseline clinical manifestations of 366 patients in the Fabry Outcome Survey.

Authors:  A Mehta; R Ricci; U Widmer; F Dehout; A Garcia de Lorenzo; C Kampmann; A Linhart; G Sunder-Plassmann; M Ries; M Beck
Journal:  Eur J Clin Invest       Date:  2004-03       Impact factor: 4.686

7.  The Mainz Severity Score Index: a new instrument for quantifying the Anderson-Fabry disease phenotype, and the response of patients to enzyme replacement therapy.

Authors:  C Whybra; C Kampmann; F Krummenauer; M Ries; E Mengel; E Miebach; F Baehner; K Kim; M Bajbouj; A Schwarting; A Gal; M Beck
Journal:  Clin Genet       Date:  2004-04       Impact factor: 4.438

8.  Inner ear function in children with Fabry disease.

Authors:  A Keilmann
Journal:  Acta Paediatr Suppl       Date:  2003-12

9.  Auditory and vestibular findings in Fabry disease: a study of hemizygous males and heterozygous females.

Authors:  G Conti; B Sergi
Journal:  Acta Paediatr Suppl       Date:  2003-12
  9 in total
  5 in total

1.  The pulvinar sign: frequency and clinical correlations in Fabry disease.

Authors:  Alessandro P Burlina; Renzo Manara; Catherine Caillaud; Jean-Pierre Laissy; Mariasavina Severino; Isabelle Klein; Alberto Burlina; Olivier Lidove
Journal:  J Neurol       Date:  2008-02-26       Impact factor: 4.849

2.  Ear symptoms in children with Fabry disease: data from the Fabry Outcome Survey.

Authors:  A Keilmann; D Hajioff; U Ramaswami
Journal:  J Inherit Metab Dis       Date:  2009-10-27       Impact factor: 4.982

3.  Cardiac and renal dysfunction is associated with progressive hearing loss in patients with Fabry disease.

Authors:  Maria Köping; Wafaa Shehata-Dieler; Mario Cebulla; Kristen Rak; Daniel Oder; Jonas Müntze; Peter Nordbeck; Christoph Wanner; Rudolf Hagen; Sebastian Schraven
Journal:  PLoS One       Date:  2017-11-21       Impact factor: 3.240

4.  Characterization of vertigo and hearing loss in patients with Fabry disease.

Authors:  Maria Köping; Wafaa Shehata-Dieler; Dieter Schneider; Mario Cebulla; Daniel Oder; Jonas Müntze; Peter Nordbeck; Christoph Wanner; Rudolf Hagen; Sebastian P Schraven
Journal:  Orphanet J Rare Dis       Date:  2018-08-15       Impact factor: 4.123

5.  Hearing loss in children with Fabry disease.

Authors:  E Suntjens; W A Dreschler; J Hess-Erga; R Skrunes; F A Wijburg; G E Linthorst; C Tøndel; M Biegstraaten
Journal:  J Inherit Metab Dis       Date:  2017-05-31       Impact factor: 4.982

  5 in total

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