Literature DB >> 16565852

Lymphocytic hypophysitis with central diabetes insipidus and subsequent hypopituitarism masking a suprasellar germinoma in a 13-year-old girl.

Yoko Mikami-Terao1, Masaharu Akiyama, Takaaki Yanagisawa, Junko Takahashi-Fujigasaki, Kentaro Yokoi, Kohei Fukuoka, Mio Sakuma, Ichiro Miyata, Kohji Fujisawa, Shizuo Oi, Yoshikatsu Eto.   

Abstract

CASE REPORT: We report a case of central diabetes insipidus, hypothyroidism, and subsequent hypopituitarism due to lymphocytic hypophysitis masking a germinoma in a 13-year-old pubertal girl. Magnetic resonance revealed an enlarged pituitary gland and a mass lesion in the pituitary stalk and inferior hypothalamus. Open cranial surgery of the anterior pituitary showed active hypophysitis with lymphocytic infiltrates but without necrosis. Despite prednisolone therapy, 1 year later an enlarged, irregular cystic mass lesion had developed; in the pituitary stalk and inferior hypothalamus, a endoscopic biopsy revealed germinoma.
CONCLUSION: Lymphocytic hypophysitis in children may be the first sign of a host reaction to an occult germinoma. The diagnosis of central diabetes insipidus with a thickened pituitary stalk requires long-term follow-up to establish the underlying cause.

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Year:  2006        PMID: 16565852     DOI: 10.1007/s00381-006-0078-7

Source DB:  PubMed          Journal:  Childs Nerv Syst        ISSN: 0256-7040            Impact factor:   1.475


  17 in total

1.  Diabetes insipidus due to hypophysitis.

Authors:  E Weimann; G Mölenkamp; H J Böhles
Journal:  Horm Res       Date:  1997

2.  Induction chemotherapy followed by low-dose involved-field radiotherapy for intracranial germ cell tumors.

Authors:  Hidefumi Aoyama; Hiroki Shirato; Jun Ikeda; Kenji Fujieda; Kazuo Miyasaka; Yutaka Sawamura
Journal:  J Clin Oncol       Date:  2002-02-01       Impact factor: 44.544

3.  Idiopathic hypothalamic diabetes insipidus, pituitary stalk thickening, and the occult intracranial germinoma in children and adolescents.

Authors:  S L Mootha; A J Barkovich; M M Grumbach; M S Edwards; S E Gitelman; S L Kaplan; F A Conte
Journal:  J Clin Endocrinol Metab       Date:  1997-05       Impact factor: 5.958

Review 4.  Intracranial germ cell tumors.

Authors:  R J Packer; B H Cohen; K Cooney; K Coney
Journal:  Oncologist       Date:  2000

5.  Lymphocytic hypophysitis masking a suprasellar germinoma in a 12-year-old girl--a case report.

Authors:  M Fehn; M Bettendorf; D K Lüdecke; C Sommer; W Saeger
Journal:  Pituitary       Date:  1999-05       Impact factor: 4.107

6.  Thickened pituitary stalk on magnetic resonance imaging in children with central diabetes insipidus.

Authors:  J Leger; A Velasquez; C Garel; M Hassan; P Czernichow
Journal:  J Clin Endocrinol Metab       Date:  1999-06       Impact factor: 5.958

7.  Lymphocytic infundibuloneurohypophysitis as a cause of central diabetes insipidus.

Authors:  H Imura; K Nakao; A Shimatsu; Y Ogawa; T Sando; I Fujisawa; H Yamabe
Journal:  N Engl J Med       Date:  1993-09-02       Impact factor: 91.245

8.  Intensive cisplatin and cyclophosphamide-based chemotherapy without radiotherapy for intracranial germinomas: failure of a primary chemotherapy approach.

Authors:  Stewart J Kellie; Hayden Boyce; Ira J Dunkel; Blanca Diez; Marc Rosenblum; Lynette Brualdi; Jonathan L Finlay
Journal:  Pediatr Blood Cancer       Date:  2004-08       Impact factor: 3.167

Review 9.  Pregnancy in lymphocytic hypophysitis: case report and review.

Authors:  J C Brandes; J M Cerletty
Journal:  Wis Med J       Date:  1989-11

10.  Clinical case seminar: lymphocytic hypophysitis: clinicopathological findings.

Authors:  E Thodou; S L Asa; G Kontogeorgos; K Kovacs; E Horvath; S Ezzat
Journal:  J Clin Endocrinol Metab       Date:  1995-08       Impact factor: 5.958

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  9 in total

Review 1.  Necrotizing infundibuloneurohypophysitis: case report and literature review.

Authors:  Anick Nater; Luis V Syro; Fabio Rotondo; Bernd W Scheithauer; Veronica Abad; Carolina Jaramillo; Kalman Kovacs; Eva Horvath; Michael Cusimano
Journal:  Endocr Pathol       Date:  2012-09       Impact factor: 3.943

Review 2.  [Hypophysitis : Types and differential diagnosis].

Authors:  W Saeger
Journal:  Pathologe       Date:  2016-05       Impact factor: 1.011

3.  An unusual suspect causing behavioural problems and pituitary failure in a child.

Authors:  Adam Charles Heathcote; Justin Conrad Rosen Wormald; Richard Stocks
Journal:  BMJ Case Rep       Date:  2012-12-14

Review 4.  Lymphocytic hypophysitis in the pediatric population.

Authors:  Verena Gellner; Senta Kurschel; Michael Scarpatetti; Michael Mokry
Journal:  Childs Nerv Syst       Date:  2008-02-26       Impact factor: 1.475

5.  Surgical biopsies in patients with central diabetes insipidus and thickened pituitary stalks.

Authors:  Fangfang Jian; Liuguan Bian; Shouyue Sun; Jun Yang; Xiao Chen; Yufan Chen; Qinyun Ma; Fei Miao; Weiqing Wang; Guang Ning; Qingfang Sun
Journal:  Endocrine       Date:  2014-02-16       Impact factor: 3.633

6.  Antibodies Against Hypothalamus and Pituitary Gland in Childhood-Onset Brain Tumors and Pituitary Dysfunction.

Authors:  Giuseppa Patti; Erika Calandra; Annamaria De Bellis; Annalisa Gallizia; Marco Crocco; Flavia Napoli; Anna Maria Elsa Allegri; Hanan F Thiabat; Giuseppe Bellastella; Maria Ida Maiorino; Maria Luisa Garrè; Stefano Parodi; Mohamad Maghnie; Natascia di Iorgi
Journal:  Front Endocrinol (Lausanne)       Date:  2020-02-18       Impact factor: 5.555

7.  Pituitary Stalk Germ Cell Tumors: Retrospective Case Series and Literature Review.

Authors:  Han Chen; Ming Ni; Yun Xu; Li-Yong Zhong
Journal:  Int J Endocrinol       Date:  2022-03-26       Impact factor: 3.257

8.  Pituitary and systemic autoimmunity in a case of intrasellar germinoma.

Authors:  Angelika Gutenberg; Jennifer J Bell; Isabella Lupi; Shey-Cherng Tzou; Melissa A Landek-Salgado; Hiroaki Kimura; Jack Su; Lefkothea P Karaviti; Roberto Salvatori; Patrizio Caturegli
Journal:  Pituitary       Date:  2009-05-26       Impact factor: 4.107

9.  Granulomatous Response in Intracranial Germinomas: Diagnostic Problems.

Authors:  Sree Rekha Jinkala; Elancheran Muthalagan; Bhawana Ashok Badhe
Journal:  Int J Appl Basic Med Res       Date:  2018 Jan-Mar
  9 in total

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